نتایج جستجو برای: clc

تعداد نتایج: 2349  

2015
Yi-An Chen Yi-Jheng Peng Meng-Chun Hu Jing-Jia Huang Yun-Chia Chien June-Tai Wu Tsung-Yu Chen Chih-Yung Tang

Voltage-gated CLC-1 chloride channels play a critical role in controlling the membrane excitability of skeletal muscles. Mutations in human CLC-1 channels have been linked to the hereditary muscle disorder myotonia congenita. We have previously demonstrated that disease-associated CLC-1 A531V mutant protein may fail to pass the endoplasmic reticulum quality control system and display enhanced p...

Journal: :The Journal of General Physiology 1999
Chiara Saviane Franco Conti Michael Pusch

Single-channel recordings of the currents mediated by the muscle Cl- channel, ClC-1, expressed in Xenopus oocytes, provide the first direct evidence that this channel has two equidistant open conductance levels like the Torpedo ClC-0 prototype. As for the case of ClC-0, the probabilities and dwell times of the closed and conducting states are consistent with the presence of two independently ga...

2012
Elena Jeworutzki Tania López-Hernández Xavier Capdevila-Nortes Sònia Sirisi Luiza Bengtsson Marisol Montolio Giovanni Zifarelli Tanit Arnedo Catrin S. Müller Uwe Schulte Virginia Nunes Albert Martínez Thomas J. Jentsch Xavier Gasull Michael Pusch Raúl Estévez

Ion fluxes mediated by glial cells are required for several physiological processes such as fluid homeostasis or the maintenance of low extracellular potassium during high neuronal activity. In mice, the disruption of the Cl(-) channel ClC-2 causes fluid accumulation leading to myelin vacuolation. A similar vacuolation phenotype is detected in humans affected with megalencephalic leukoencephalo...

2010
Anita A. C. Reed Nellie Y. Loh Sara Terryn Jonathan D. Lippiat Chris Partridge Juris Galvanovskis Siân E. Williams Francois Jouret Fiona T. F. Wu Pierre J. Courtoy M. Andrew Nesbit Patrik Rorsman Olivier Devuyst Frances M. Ashcroft Rajesh V. Thakker

Renal tubular reabsorption is important for extracellular fluid homeostasis and much of this occurs via the receptor-mediated endocytic pathway. This pathway is disrupted in Dent's disease, an X-linked renal tubular disorder that is characterized by low-molecular-weight proteinuria, hypercalciuria, nephrolithiasis, and renal failure. Dent's disease is due to mutations of CLC-5, a chloride/proto...

Journal: :Nucleic acids research 1997
S Chu P L Zeitlin

The ClC-2 epithelial cell chloride channel is a voltage-, tonicity- and pH-regulated member of the ClC super family. We have previously shown that rat lung ClC-2 (rClC-2) is down-regulated at birth, and molecular diversity is generated by alternative splicing [Murray et al. (1995) Am. J. Respir. Cell Mol. Biol. 12, 597-604; Murray et al. (1996) Am. J. Physiol. 271, L829-L837; Chu et al . (1996)...

2010
Antonella Gradogna Michael Pusch

CLC-K channels belong to the CLC gene family, which comprises both Cl(-) channels and Cl(-)/H(+) antiporters. They form homodimers which additionally co-assemble with the small protein barttin. In the kidney, they are involved in NaCl reabsorption; in the inner ear they are important for endolymph production. Mutations in CLC-Kb lead to renal salt loss (Bartter's syndrome); mutations in barttin...

Journal: :American journal of physiology. Cell physiology 2014
John Cuppoletti Jayati Chakrabarti Kirti P Tewari Danuta H Malinowska

It has been difficult to separate/identify the roles of ClC-2 and CFTR in Cl(-) transport studies. Using pharmacological agents, we aimed to differentiate functionally between ClC-2 and CFTR Cl(-) channel currents. Effects of CFTR inhibitor 172 (CFTRinh172), N-(4-methylphenylsulfonyl)-N'-(4-trifluoromethylphenyl)urea (DASU-02), and methadone were examined by whole cell patch clamp on Cl(-) curr...

Journal: :Molecular pharmacology 2002
Antonella Liantonio Alessio Accardi Giuseppe Carbonara Giuseppe Fracchiolla Fulvio Loiodice Paolo Tortorella Sonia Traverso Patrizia Guida Sabata Pierno Annamaria De Luca Diana Conte Camerino Michael Pusch

CLC channels are a gene family of Cl(-) channels that serve a variety of functions, several of which are involved in genetic diseases. Few specific ligands of CLC channels are known that could be useful as pharmacological tools or potential drugs. We synthesized various derivatives of 2-(p-chlorophenoxy)propionic acid, the S(-)-enantiomer of which is a specific blocker of the muscle channel CLC...

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