نتایج جستجو برای: hereditary deafness

تعداد نتایج: 91403  

Journal: :Human molecular genetics 1997
F Denoyelle D Weil M A Maw S A Wilcox N J Lench D R Allen-Powell A H Osborn H H Dahl A Middleton M J Houseman C Dodé S Marlin A Boulila-ElGaïed M Grati H Ayadi S BenArab P Bitoun G Lina-Granade J Godet M Mustapha J Loiselet E El-Zir A Aubois A Joannard J Levilliers E N Garabédian R F Mueller R J Gardner C Petit

Prelingual non-syndromic (isolated) deafness is the most frequent hereditary sensory defect. In >80% of the cases, the mode of transmission is autosomal recessive. To date, 14 loci have been identified for the recessive forms (DFNB loci). For two of them, DFNB1 and DFNB2, the genes responsible have been characterized; they encode connexin 26 and myosin VIIA, respectively. In order to evaluate t...

Journal: :Sheng li xue bao : [Acta physiologica Sinica] 2012
Ling-Zhi Liang Bin-Jiao Zheng Jing Zheng Fang Fang Yue Wu Min-Xin Guan

Although the basic principles for the function of peripheral auditory system have been known for many years, the molecular mechanisms which affect deafness are not clear. In recent years, the study of hereditary deafness associated mouse models has revealed the molecular basis which is related with the formation and function of the hair bundle and the mechanosensory organelle of hair cell. This...

Journal: :Journal of Deaf Studies and Deaf Education 2015

Mutations in the connexin 26 (Cx26) gene at the DFNB1 locus on chromosome 13q12 are associated with autosomal recessive non-syndromic hearing loss (ARNSHL). There are many known mutations in this gene that cause hearing loss. A single frameshift, at position 35 (35delG) accounts for 50% of mutations in the Caucasian population with carrier frequencies of 1.5-2.5%. In this study we investigated ...

Armin Attaranzadeh Isa Jahanzad Sakineh Amoueian,

Introduction and Objective: Alport’s syndrome (hereditary nephritis with deafness) is a familial uncommon disease that ultra-structural studies are gold standard method of its diagnosis. Materials and Methods:We studied 26 Iranian patients suspicious of Alport’s syndrome by electron microscopy. We examin...

2013
Kerry A. Miller Louise H. Williams Hans-Henrik M. Dahl Shehnaaz S. M. Manji

Animal models that recapitulate human disease are proving to be an invaluable tool in the identification of novel disease-associated genes. These models can improve our understanding of the complex genetic mechanisms involved in disease and provide a basis to guide therapeutic strategies to combat these conditions. We have identified a novel mouse model of non-syndromic sensorineural hearing lo...

2016
Kari L. Green Donald L. Swiderski Diane M. Prieskorn Susan J. DeRemer Lisa A. Beyer Josef M. Miller Glenn E. Green Yehoash Raphael

Dietary supplements consisting of beta-carotene (precursor to vitamin A), vitamins C and E and the mineral magnesium (ACEMg) can be beneficial for reducing hearing loss due to aminoglycosides and overstimulation. This regimen also slowed progression of deafness for a boy with GJB2 (CONNEXIN 26) mutations. To assess the potential for treating GJB2 and other forms of hereditary hearing loss with ...

2016
Tongchao Li Nikolaos Giagtzoglou Daniel F Eberl Sonal Nagarkar Jaiswal Tiantian Cai Dorothea Godt Andrew K Groves Hugo J Bellen

Myosins play essential roles in the development and function of auditory organs and multiple myosin genes are associated with hereditary forms of deafness. Using a forward genetic screen in Drosophila, we identified an E3 ligase, Ubr3, as an essential gene for auditory organ development. Ubr3 negatively regulates the mono-ubiquitination of non-muscle Myosin II, a protein associated with hearing...

2011
Masoud Motasaddi Zarandy Mersedeh Rohanizadegan Hojjat Salmasian Nooshin Nikzad Niloofar Bazazzadegan Mahdi Malekpour

Clinical application of mutation screening and its effect on the outcome of cochlear implantation is widely debated. We investigated the effect of mutations in GJB2 gene on the outcome of cochlear implantation in a population with a high rate of consanguineous marriage and autosomal recessive nonsyndromic hearing loss. Two hundred and one children with profound prelingual sensorineural hearing ...

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