نتایج جستجو برای: optic atrophy

تعداد نتایج: 78319  

Journal: :Investigative ophthalmology 1971
A E Krill V C Smith J Pokorny

Dominant inherited optic atrophy is usually a stationary disorder with typical findings of temporal optic nerve pallor, abnormal distance acuity, minimal visual-field defects, and characteristic color confusions in the blue-green region of the spectrum. Variability in the severity of these abnormalities is common, even within the same family. In patients with minimal disease, distance acuity ma...

2015
Alexander J. Abrams Robert B. Hufnagel Adriana Rebelo Claudia Zanna Neville Patel Michael A. Gonzalez Ion J. Campeanu Laurie B. Griffin Saskia Groenewald Alleene V. Strickland Feifei Tao Fiorella Speziani Lisa Abreu Rebecca Schüle Leonardo Caporali Chiara La Morgia Alessandra Maresca Rocco Liguori Raffaele Lodi Zubair M. Ahmed Kristen L. Sund Xinjian Wang Laura A. Krueger Yanyan Peng Carlos E. Prada Cynthia A. Prows Kevin Bove Elizabeth K. Schorry Anthony Antonellis Holly H. Zimmerman Omar A. Abdul-Rahman Yaping Yang Susan M. Downes Jeffery Prince Flavia Fontanesi Antonio Barrientos Andrea H. Nemeth Valerio Carelli Taosheng Huang Stephan Zuchner Julia E. Dallman

Dominant optic atrophy (DOA)1,2 and axonal peripheral neuropathy (Charcot-Marie-Tooth Type 2 or CMT2)3 are hereditary neurodegenerative disorders most commonly caused by mutations in the canonical mitochondrial fusion genes OPA1 and MFN2, respectively4. In yeast, homologs of OPA1(Mgm1) and MFN2(Fzo1) work in concert with Ugo15,6, which has no human equivalent to date7. By whole exome sequencing...

Journal: :QJM: An International Journal of Medicine 2020

Journal: :British Journal of Ophthalmology 1970

Journal: :Proceedings of the Royal Society of Medicine 1927

Journal: :British Journal of Ophthalmology 1968

Journal: :Archives of neurology 2011
Raffaele Lodi Caterina Tonon Maria Lucia Valentino David Manners Claudia Testa Emil Malucelli Chiara La Morgia Piero Barboni Michele Carbonelli Simone Schimpf Bernd Wissinger Massimo Zeviani Agostino Baruzzi Rocco Liguori Bruno Barbiroli Valerio Carelli

OBJECTIVE To assess whether impaired energy metabolism in skeletal muscle is a hallmark feature of patients with dominant optic atrophy due to several different mutations in the OPA1 gene. DESIGN We used phosphorus 31 magnetic resonance spectroscopy to assess calf muscle oxidative metabolism in subjects with molecularly defined dominant optic atrophy carrying different mutations in the OPA1 g...

Journal: :Japanese journal of ophthalmology 2002
May-Yung Yen An-Guor Wang Wei-Ling Chang Wen-Ming Hsu Jorn-Hon Liu Yau-Huei Wei

PURPOSE To investigate the spectrum of mitochondrial DNA (mtDNA) mutations in Chinese patients with Leber's hereditary optic neuropathy (LHON), optic atrophy of unknown etiology, and optic neuropathy of known etiology. METHODS Twenty-seven patients from 25 LHON pedigrees, 22 patients with bilateral optic atrophy of unknown etiology, 21 patients with optic neuropathy of known etiology, and 25 ...

2014
Chiara La Morgia Michele Carbonelli Piero Barboni Alfredo Arrigo Sadun Valerio Carelli

Hereditary optic neuropathies are diseases affecting the optic nerve. The most common are mitochondrial hereditary optic neuropathies, i.e., the maternally inherited Leber's hereditary optic neuropathy (LHON) and dominant optic atrophy (DOA). They both share a mitochondrial pathogenesis that leads to the selective loss of retinal ganglion cells and axons, in particular of the papillo-macular bu...

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