نتایج جستجو برای: premature craniosynostosis

تعداد نتایج: 62797  

2017
Anup Patel

The “functional” morbidity in nonsyndromic craniosynostosis is not obvious. Because of this disconnect between cranial deformity and “functional” disability, cranial reconstructive surgery in patients with single-suture sagittal craniosynostosis has been regarded as a “cosmetic” intervention. However, it has been observed in a preliminary study that children with simple craniosynostosis often h...

2017
Saïd C. Azoury Sashank Reddy Vivek Shukla Chu-Xia Deng

Craniosynostosis results from the premature fusion of cranial sutures, with an incidence of 1 in 2,100-2,500 live births. The majority of cases are non-syndromic and involve single suture fusion, whereas syndromic cases often involve complex multiple suture fusion. The fibroblast growth factor receptor 2 (FGFR2) gene is perhaps the most extensively studied gene that is mutated in various cranio...

Journal: :Genes & diseases 2014
Maureen Beederman Evan M Farina Russell R Reid

The normal growth and development of the skull is a tightly regulated process that occurs along the osteogenic interfaces of the cranial sutures. Here, the borders of the calvarial bones and neighboring tissues above and below, function as a complex. Through coordinated remodeling efforts of bone deposition and resorption, the cranial sutures maintain a state of patency from infancy through ear...

2011
Lisenka E. L. M. Vissers Timothy C. Cox A. Murat Maga Kieran M. Short Fenny Wiradjaja Irene M. Janssen Fernanda Jehee Debora Bertola Jia Liu Garima Yagnik Kiyotoshi Sekiguchi Daiji Kiyozumi Hans van Bokhoven Carlo Marcelis Michael L. Cunningham Peter J. Anderson Simeon A. Boyadjiev Maria Rita Passos-Bueno Joris A. Veltman Ian Smyth Michael F. Buckley Tony Roscioli

The premature fusion of the paired frontal bones results in metopic craniosynostosis (MC) and gives rise to the clinical phenotype of trigonocephaly. Deletions of chromosome 9p22.3 are well described as a cause of MC with variably penetrant midface hypoplasia. In order to identify the gene responsible for the trigonocephaly component of the 9p22.3 syndrome, a cohort of 109 patients were assesse...

Journal: :Seminars in plastic surgery 2012
Rebecca M Garza Rohit K Khosla

Nonsyndromic craniosynostosis is more commonly encountered than syndromic cases in pediatric craniofacial surgery. Affected children display characteristic phenotypes according to the suture or sutures involved. Restricted normal growth of the skull can lead to increased intracranial pressure and changes in brain morphology, which in turn may contribute to neurocognitive deficiency. Management ...

Journal: :European Journal of Medical Genetics 2021

This article reviews the development of research in field craniosynostosis from a bibliometric standpoint. Craniosynostosis is malformation occurring during early skull, when one or more sutures close too early, causing problems with normal brain and skull growth. Research this has developed clinical case descriptions, to genetic discoveries responsible for malformations onwards developing soph...

Journal: :Development 2005
Hsiao-Man Ivy Yu Boris Jerchow Tzong-Jen Sheu Bo Liu Frank Costantini J Edward Puzas Walter Birchmeier Wei Hsu

Axin1 and its homolog Axin2/conductin/Axil are negative regulators of the canonical Wnt pathway that suppress signal transduction by promoting degradation of beta-catenin. Mice with deletion of Axin1 exhibit defects in axis determination and brain patterning during early embryonic development. We show that Axin2 is expressed in the osteogenic fronts and periosteum of developing sutures during s...

Journal: :Turkish neurosurgery 2017
Tufan Hicdonmez

AIM The premature closure of the metopic suture results in metopic synostosis, also known as trigonocephaly. However, there is a group of children who have only a frontal metopic ridge, obvious with inspection and fingertip palpation, without the clinical features of trigonocephaly. This study aims to report a group of children with metopic ridge with a special emphasis on the definition and th...

2016
Simon Pius Halima Abubakar Ibrahim Mustapha Bello Kefas Mbaya Jose Pwavimbo Ambe

Apert syndrome, also known as acrocephalosyndactyly, is one of the causes of craniofacial syndrome or deformity. It is a rare congenital disorder characterized by premature fusion of cranial sutures (craniosynostosis), malformation of skull, hands, face and feet. This congenital deformity has incidence of 1/50,000 to 1/80,000 live births and is an autosomal dominant in inheritance. Apert syndro...

Journal: :The Journal of craniofacial surgery 2007
Peter J Anderson Timothy C Cox Tony Roscioli George Elakis Lisa Smithers David J David Barry Powell

Pathogenic mutations in FGFR2 and TWIST genes are detected in the majority of individuals with Crouzon, Pfeiffer, Apert, and Saethre-Chotzen syndromes. In contrast, mutations have been identified rarely in cases of nonsyndromic, single suture craniosynostosis. Recently, two studies confirming somatic mosaicism with local expression of an FGFR mutation have been reported. This study investigates...

نمودار تعداد نتایج جستجو در هر سال

با کلیک روی نمودار نتایج را به سال انتشار فیلتر کنید