نتایج جستجو برای: progeroid syndrome

تعداد نتایج: 622026  

2012
Maureen Bowles John Lally Andrew J. Fadden Stephane Mouilleron Timothy Hammonds Neil Q. McDonald

The structure-specific endonuclease activity of the human XPF-ERCC1 complex is essential for a number of DNA processing mechanisms that help to maintain genomic integrity. XPF-ERCC1 cleaves DNA structures such as stem-loops, bubbles or flaps in one strand of a duplex where there is at least one downstream single strand. Here, we define the minimal substrate requirements for cleavage of stem-loo...

2014
Bidisha Saha Alexander Cypro George M Martin Junko Oshima

Werner syndrome (WS), caused by mutations at the WRN helicase gene, is a progeroid syndrome characterized by multiple features consistent with accelerated aging. Aberrant double-strand DNA damage repair leads to genomic instability and reduced replicative lifespan of somatic cells. We observed increased autophagy in WRN knockdown cells; this was further increased by short-term rapamycin treatme...

Journal: :Lancet 2003
Lishan Chen Lin Lee Brian A Kudlow Heloisa G Dos Santos Olav Sletvold Yousef Shafeghati Eleanor G Botha Abhimanyu Garg Nancy B Hanson George M Martin I Saira Mian Brian K Kennedy Junko Oshima

BACKGROUND Werner's syndrome is a progeroid syndrome caused by mutations at the WRN helicase locus. Some features of this disorder are also present in laminopathies caused by mutant LMNA encoding nuclear lamin A/C. Because of this similarity, we sequenced LMNA in individuals with atypical Werner's syndrome (wild-type WRN). METHODS Of 129 index patients referred to our international registry f...

2017
Raghavendra A Shamanna Deborah L Croteau Jong-Hyuk Lee Vilhelm A Bohr

Aging, the universal phenomenon, affects human health and is the primary risk factor for major disease pathologies. Progeroid diseases, which mimic aging at an accelerated rate, have provided cues in understanding the hallmarks of aging. Mutations in DNA repair genes as well as in telomerase subunits are known to cause progeroid syndromes. Werner syndrome (WS), which is characterized by acceler...

2014
Sander Barnhoorn Lieneke M. Uittenboogaard Dick Jaarsma Wilbert P. Vermeij Maria Tresini Michael Weymaere Hervé Menoni Renata M. C. Brandt Monique C. de Waard Sander M. Botter Altaf H. Sarker Nicolaas G. J. Jaspers Gijsbertus T. J. van der Horst Priscilla K. Cooper Jan H. J. Hoeijmakers Ingrid van der Pluijm Laura J. Niedernhofer

As part of the Nucleotide Excision Repair (NER) process, the endonuclease XPG is involved in repair of helix-distorting DNA lesions, but the protein has also been implicated in several other DNA repair systems, complicating genotype-phenotype relationship in XPG patients. Defects in XPG can cause either the cancer-prone condition xeroderma pigmentosum (XP) alone, or XP combined with the severe ...

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