نتایج جستجو برای: agammaglobulinemia

تعداد نتایج: 619  

Journal: :Blood 2004
Carla E Blanco-Betancourt Anne Moncla Michèle Milili Yun Liang Jiang Evani M Viegas-Péquignot Bertrand Roquelaure Isabelle Thuret Claudine Schiff

Immunodeficiency, centromeric region instability, and facial anomalies (ICF) syndrome is a rare autosomal recessive disease. Mutations in the DNA methyltransferase 3B (DNMT3B) gene are responsible for most ICF cases reported. We investigated the B-cell defects associated with agammaglobulinemia in this syndrome by analyzing primary B cells from 4 ICF patients. ICF peripheral blood (PB) contains...

Journal: :Frontiers in Immunology 2023

The transcription factor interferon regulatory 4 (IRF4) belongs to the IRF family and has several important functions for adaptive immune response. Mutations affecting members IRF1, IRF3, IRF7, IRF8, or IRF9 have been described in patients presenting with inborn errors of immunity (IEI) highlighting importance these factors cellular host defense against mycobacterial and/or viral infections. IR...

Journal: :Nucleic acids research 1996
Mauno Vihinen Tsutomu Iwata Christine Kinnon Sau-Ping Kwan Hans D. Ochs Igor Vorechovsky C. I. Edvard Smith

X-linked agammaglobulinemia (XLA) is an immunodeficiency caused by mutations in the gene coding for Bruton's agammaglobulinemia tyrosine kinase (BTK). A database (BTKbase) of BTK mutations has been compiled and the recent update lists 368 entries from 318 unrelated families showing 228 unique molecular events. In addition to mutations the database lists also some polymorphisms and site-directed...

2012
Jung Woo Rhim Kyung Hyo Kim Dong Soo Kim Bong Seong Kim Jung Soo Kim Chang Hwi Kim Hwang Min Kim Hee Ju Park Ki Soo Pai Byong Kwan Son Kyung Sue Shin Moo Young Oh Young Jong Woo Young Yoo Kun Soo Lee Kyung Yil Lee Chong Guk Lee Joon Sung Lee Eun Hee Chung Eun Hwa Choi Youn Soo Hahn Hyun Young Park Joong Gon Kim

This study represents the first epidemiological study based on the national registry of primary immunodeficiencies (PID) in Korea. Patient data were collected from 23 major hospitals. A total of 152 patients with PID (under 19 yr of age), who were observed from 2001 to 2005, have been entered in this registry. The period prevalence of PID in Korea in 2005 is 11.25 per million children. The foll...

Journal: :Journal of immunology 2001
E K Jo H Kanegane S Nonoyama S Tsukada J H Lee K Lim M Shong C H Song H J Kim J K Park T Miyawaki

In this report, we describe seven mutations, including a novel single base pair substitution in intron 1, of the Bruton's tyrosine kinase (Btk) gene found in 12 Korean patients with X-linked agammaglobulinemia. Various mutations, including three novel genetic alterations, were discovered using single-strand conformation polymorphism analysis and direct DNA sequencing. The effect of the intron 1...

2017
Patuzzo Giuseppe Tinazzi Elisa Puccetti Antonio Lunardi Claudio

X-linked agammaglobulinemia (XLA) or Bruton’s disease is a rare inherited disorder of the immune system: XLA is a primary immunodeficiency, occurring in 1 of 190,000 male births in the United States [1,2]. XLA represents nearly 85% of agammaglobulinemia cases, and is caused by a defect in gene, located on the X chromosome, coding for Bruton’s tyrosine kinase (BTK). BTK gene mutation causes a fa...

2016
Xia-Fang Chen Wei-Fan Wang Yi-Dan Zhang Wei Zhao Jing Wu Tong-Xin Chen

X-linked agammaglobulinemia (XLA) is a humoral primary immunodeficiency. XLA patients typically present with very low numbers of peripheral B cells and a profound deficiency of all immunoglobulin isotypes. Most XLA patients carry mutations in Bruton tyrosine kinase (BTK) gene.The genetic background and clinical features of 174 Chinese patients with XLA were investigated. The relationship betwee...

Journal: :The Journal of clinical investigation 1973
L Y Wu A R Lawton M D Cooper

Peripheral blood lymphocytes from 27 healthy individuals and from 18 patients with a diverse spectrum of defects in humoral immunity were examined for their capacity to undergo terminal differentiation in vitro. Pokeweed mitogen induced cells from normal persons to synthesize and secrete IgM. IgG, and IgA as detected by Immunofluorescence and incorporation of [(14)C]amino acids, Lymphocytes fro...

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