نتایج جستجو برای: poly syndactyly

تعداد نتایج: 81139  

Journal: :Developmental cell 2009
Daniel R McCulloch Courtney M Nelson Laura J Dixon Debra L Silver James D Wylie Volkhard Lindner Takako Sasaki Marion A Cooley W Scott Argraves Suneel S Apte

We show that combinatorial mouse alleles for the secreted metalloproteases Adamts5, Adamts20 (bt), and Adamts9 result in fully penetrant soft-tissue syndactyly. Interdigital webs in Adamts5(-/-);bt/bt mice had reduced apoptosis and decreased cleavage of the proteoglycan versican; however, the BMP-FGF axis, which regulates interdigital apoptosis was unaffected. BMP4 induced apoptosis, but withou...

Journal: :Circulation 2008
Barry London

Timothy syndrome is a rare genetic disorder characterized by QT prolongation (designated LQT8), arrhythmias and sudden death, structural heart disease, cognitive defects with autism, syndactyly (webbed fingers and toes), hypoglycemia, and immune deficiencies.1,2 A single mutation (G406R) in exon 8a of the cardiac L-type calcium channel (CACNA1C, Cav1.2, 1c) was shown to cause Timothy syndrome i...

Journal: :Journal of medical genetics 1993
I E Järvelä M K Salo P Santavuori R K Salonen

We report a 20 month old female patient with diploid-triploid mixoploidy (46,XX/69,XXX) syndrome with hypothyroidism and precocious puberty. The triploid cell line was only expressed in the fibroblast culture and comprised the majority (95%) of the cells. Chromosome analysis of the fetal blood sample and peripheral blood sample were normal. The patient shows typical features of full triploidy (...

Journal: :Journal of medical genetics 1998
M R Passos-Bueno A Richieri-Costa A L Sertié A Kneppers

Apert syndrome, characterised by craniosynostosis, craniofacial anomalies, and symmetrical syndactyly of the digits (cutaneous and bony fusion), has been associated with two canonical mutations in the FGFR2 gene (S252W, P253R) in the great majority of cases. Since these two alterations have been observed exclusively among these patients, it has been suggested that the S252W and P253R changes ma...

Journal: :Indian Journal of Dermatology, Venereology and Leprology 2008

Journal: :Proceedings of the National Academy of Sciences of the United States of America 1997
F R Goodman S Mundlos Y Muragaki D Donnai M L Giovannucci-Uzielli E Lapi F Majewski J McGaughran C McKeown W Reardon J Upton R M Winter B R Olsen P J Scambler

Synpolydactyly (SPD) is a dominantly inherited congenital limb malformation. Typical cases have 3/4 finger and 4/5 toe syndactyly, with a duplicated digit in the syndactylous web, but incomplete penetrance and variable expressivity are common. The condition has recently been shown to be caused by expansions of an imperfect trinucleotide repeat sequence encoding a 15-residue polyalanine tract in...

2015
Moon-Yeon Oh Jun Suk Kim Ja Hye Kim Ja Hyang Cho Beom Hee Lee Gu-Hwan Kim Jin-Ho Choi Han-Wook Yoo

Smith-Lemli-Opitz syndrome (SLOS) is a rare autosomal recessive disorder caused by 7-dehydrocholesterol reductase deficiency. The characteristic clinical features are syndactyly of the second and third toes, facial dysmorphism, multiple malformations, and intellectual disability. Few cases of SLOS have been reported in Korea. We observed a male patient with SLOS who presented with typical facia...

Journal: :Annales Academiae Medicae Stetinensis 2008
Aleksandra Gawlikowska-Sroka

Polydactyly is a common hereditary disorder in which extra or vestigial digits are present on the one or both sides of the extremities. It is ten times more frequent in Blacks than in Whites. Polydactyly occurs both in a sporadic form and in a hereditary form. In polydactyly type A, the extra digits contains phalanges, in polydactyly type B, there is no skeletal structure. The extra digit is ma...

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