نتایج جستجو برای: scn1a mutations

تعداد نتایج: 173129  

2009
Sin-Young Jang Myeong-Kyu Kim Seong-Min Choi Seung-Han Lee Man-Seok Park Byeong-Chae Kim

Background: Voltage-gated sodium channels are responsible for the initial-depolarization component of action potentials in brain neurons, and hence they are the target for widely used antiepileptic drugs such as carbamazepine (CBZ). With the working hypothesis that genetic defect in voltage-gated sodium channels can alter the response to CBZ, this study was performed to elucidate the relationsh...

2017
Yiqing Huang Hai Xiao Xingyue Qin Yuan Nong Donghua Zou Yuan Wu

Epilepsy and migraine are common diseases of the nervous system and share genetic and pathophysiological mechanisms. Familial hemiplegic migraine is an autosomal dominant disease. It is often used as a model of migraine. Four genes often contain one or more mutations in both epilepsy and hemiplegic migraine patients (ie, CACNA1A, ATP1A2, SCN1A, and PRRT2). A better understanding of the shared g...

2017
Brian P Grone Tiange Qu Scott C Baraban

Loss-of-function mutations in SCN1A cause Dravet syndrome (DS), a catastrophic childhood epilepsy in which patients experience comorbid behavioral conditions, including movement disorders, sleep abnormalities, anxiety, and intellectual disability. To study the functional consequences of voltage-gated sodium channel mutations, we use zebrafish with a loss-of-function mutation in scn1lab, a zebra...

Journal: :Experimental neurology 2016
Christopher D Makinson Karoni Dutt Frank Lin Ligia A Papale Anupama Shankar Arthur J Barela Robert Liu Alan L Goldin Andrew Escayg

Understanding the role of SCN8A in epilepsy and behavior is critical in light of recently identified human SCN8A epilepsy mutations. We have previously demonstrated that Scn8a(med) and Scn8a(med-jo) mice carrying mutations in the Scn8a gene display increased resistance to flurothyl and kainic acid-induced seizures; however, they also exhibit spontaneous absence seizures. To further investigate ...

Journal: :The Journal of neuroscience : the official journal of the Society for Neuroscience 2004
Kazusaku Kamiya Makoto Kaneda Takashi Sugawara Emi Mazaki Nami Okamura Mauricio Montal Naomasa Makita Masaki Tanaka Katsuyuki Fukushima Tateki Fujiwara Yushi Inoue Kazuhiro Yamakawa

Mutations, exclusively missense, of voltage-gated sodium channel alpha subunit type 1 (SCN1A) and type 2 (SCN2A) genes were reported in patients with idiopathic epilepsy: generalized epilepsy with febrile seizures plus. Nonsense and frameshift mutations of SCN1A, by contrast, were identified in intractable epilepsy: severe myoclonic epilepsy in infancy (SMEI). Here we describe a first nonsense ...

Journal: :Neurology. Genetics 2015
Tommaso Pippucci Laura Licchetta Sara Baldassari Flavia Palombo Veronica Menghi Romina D'Aurizio Chiara Leta Carlotta Stipa Giovanni Boero Giuseppe d'Orsi Alberto Magi Ingrid Scheffer Marco Seri Paolo Tinuper Francesca Bisulli

OBJECTIVE To identify novel genes implicated in epilepsy with auditory features (EAF) in phenotypically heterogeneous families with unknown molecular basis. METHODS We identified 15 probands with EAF in whom an LGI1 mutation had been excluded. We performed electroclinical phenotyping on all probands and available affected relatives. We used whole-exome sequencing (WES) in 20 individuals with ...

Journal: :Proceedings of the National Academy of Sciences of the United States of America 2012
Sung Han Frank H Yu Michael D Schwartz Jonathan D Linton Martha M Bosma James B Hurley William A Catterall Horacio O de la Iglesia

Na(V)1.1 is the primary voltage-gated Na(+) channel in several classes of GABAergic interneurons, and its reduced activity leads to reduced excitability and decreased GABAergic tone. Here, we show that Na(V)1.1 channels are expressed in the suprachiasmatic nucleus (SCN) of the hypothalamus. Mice carrying a heterozygous loss of function mutation in the Scn1a gene (Scn1a(+/-)), which encodes the ...

Journal: :The Journal of physiology 2000
A Alekov M M Rahman N Mitrovic F Lehmann-Horn H Lerche

Generalized epilepsy with febrile seizures plus (GEFS+) is a benign epileptic syndrome of humans. It is characterized by febrile and afebrile generalized seizures that occur predominantly in childhood and respond well to standard antiepileptic therapy. A mutation in the b1-subunit of the voltage-gated sodium channel, linked to chromosome 19q13 (GEFS+ type 1) has been found in one family. For fo...

نمودار تعداد نتایج جستجو در هر سال

با کلیک روی نمودار نتایج را به سال انتشار فیلتر کنید