نتایج جستجو برای: spastic paraplegia 18

تعداد نتایج: 361983  

2017
Leila Dardour Filip Roelens Valerie Race Erika Souche Maureen Holvoet Koen Devriendt

Troyer syndrome (MIM#275900) is an autosomal recessive form of complicated hereditary spastic paraplegia. It is characterized by progressive lower extremity spasticity and weakness, dysarthria, distal amyotrophy, developmental delay, short stature, and subtle skeletal abnormalities. It is caused by deleterious mutations in the SPG20 gene, encoding spartin, on Chromosome 13q13. Until now, six un...

Journal: :Journal of Neurology, Neurosurgery & Psychiatry 1983

Journal: :Brain : a journal of neurology 1996
A Dürr C S Davoine C Paternotte J von Fellenberg S Cogilinicean P Coutinho C Lamy S Bourgeois J F Prud'homme C Penet J L Mas J M Burgunder J Hazan J Weissenbach A Brice B Fontaine

We report the clinical features of 12 families with autosomal dominant spastic paraplegia (ADSP) linked to the SPG4 locus on chromosome 2p, the major locus for this disorder that accounts for approximately 40% of the families. Among 93 gene carriers, 32 (34%) were unaware of symptoms but were clinically affected. Haplotype reconstruction showed that 90% of the asymptomatic gene carriers present...

Journal: :Brain : a journal of neurology 2018
Cecilia Marelli Foudil Lamari Dominique Rainteau Alexandre Lafourcade Guillaume Banneau Lydie Humbert Marie-Lorraine Monin Elodie Petit Rabab Debs Giovanni Castelnovo Elisabeth Ollagnon Julie Lavie Julie Pilliod Isabelle Coupry Patrick J Babin Claire Guissart Imen Benyounes Urielle Ullmann Gaetan Lesca Christel Thauvin-Robinet Pierre Labauge Sylvie Odent Claire Ewenczyk Claude Wolf Giovanni Stevanin David Hajage Alexandra Durr Cyril Goizet Fanny Mochel

The hereditary spastic paraplegias are an expanding and heterogeneous group of disorders characterized by spasticity in the lower limbs. Plasma biomarkers are needed to guide the genetic testing of spastic paraplegia. Spastic paraplegia type 5 (SPG5) is an autosomal recessive spastic paraplegia due to mutations in CYP7B1, which encodes a cytochrome P450 7α-hydroxylase implicated in cholesterol ...

Journal: :Journal of neurology, neurosurgery, and psychiatry 1994
W Schady C M Smith

A large kinship is reported with dominantly inherited spastic paraplegia starting in the first decade of life; its clinical evolution was indistinguishable from that of "pure" hereditary spastic paraplegia (HSP). However, all patients studied had electrophysiological evidence of a predominantly sensory polyneuropathy, which was confirmed on nerve biopsy in three. The histological findings indic...

Journal: :Journal of the neurological sciences 2014
Yingying Luo Bin Jiao Junling Wang Juan Du Xinxiang Yan Kun Xia Beisha Tang Lu Shen

BACKGROUND Recently, a hexanucleotide repeat expansion in the C9orf72 gene has been identified to cause frontotemporal dementia, amyotrophic lateral sclerosis families and many other neurodegenerative diseases. Owing to the overlapping phenotypes among HSP, frontotemporal dementia and amyotrophic lateral sclerosis we hypothesized that C9orf72 expansions might be a genetic risk factor or modifie...

Journal: :Journal of neurology, neurosurgery, and psychiatry 1991
W Schady J P Dick A Sheard S Crampton

Central motor conduction (CMC) studies were carried out in 25 patients with hereditary spastic paraplegia (HSP). Responses evoked in the lower limbs by transcranial magnetic stimulation of the motor cortex were bilaterally absent in 33% of the patients and, when recordable, were delayed in 75% of cases. Responses in the upper limbs were mostly normal except for those from the five members of on...

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