نتایج جستجو برای: microdeletion

تعداد نتایج: 1516  

2011
Roberta Lelis Dutra Patrícia de Campos Pieri Ana Carolina Dias Teixeira Rachel Sayuri Honjo Debora Romeo Bertola Chong Ae Kim

INTRODUCTION Williams-Beuren syndrome (WBS; OMIM 194050) is caused by a hemizygous contiguous gene microdeletion at 7q11.23. Supravalvular aortic stenosis, mental retardation, overfriendliness, and ocular and renal abnormalities comprise typical symptoms in WBS. Although fluorescence in situ hybridization is widely used for diagnostic confirmation, microsatellite DNA markers are considered high...

2015
Rachel Sayuri Honjo Roberta Lelis Dutra Erika Arai Furusawa Evelin Aline Zanardo Larissa Sampaio de Athayde Costa Leslie Domenici Kulikowski Debora Romeo Bertola Chong Ae Kim

Williams-Beuren syndrome (WBS) is a genetic disease caused by a microdeletion in the 7q11.23 region. It is characterized by congenital heart disease, mainly supravalvular aortic stenosis, mental retardation, mild short stature, facial dysmorphisms, and variable abnormalities in different systems. Objectives. To report the clinical findings of 55 Brazilian patients confirmed by multiplex ligatio...

2013
Xiaohui Gong Xi Wu Xiaojing Ma Dandan Wu Ting Zhang Li He Shengying Qin Xiaotian Li

OBJECTIVE The current study aimed to develop a reliable targeted array comparative genomic hybridization (aCGH) to detect microdeletions and microduplications in congenital conotruncal defects (CTDs), especially on 22q11.2 region, and for some other chromosomal aberrations, such as 5p15-5p, 7q11.23 and 4p16.3. METHODS Twenty-seven patients with CTDs, including 12 pulmonary atresia (PA), 10 do...

Journal: :The Laryngoscope 2014
Brendan P O'Connell Allison M Dobbie Samuel L Oyer Melissa Montiel Kathryn Hufnagle Krishna G Patel Christopher M Discolo Shaun A Nguyen David R White

OBJECTIVES/HYPOTHESIS Determine the impact of adenoid size and prior adenoidectomy on outcomes of sphincter pharyngoplasty. STUDY DESIGN Retrospective review. METHODS Retrospective review of patients 18 years of age or younger, who underwent sphincter pharyngoplasty for velopharyngeal insufficiency (VPI) from 2007 to 2012. Nasal endoscopy and nasometry testing were administered pre- and pos...

2013
Heike Vogel Dirk Montag Timo Kanzleiter Wenke Jonas Daniela Matzke Stephan Scherneck Alexandra Chadt Jonas Töle Reinhart Kluge Hans-Georg Joost Annette Schürmann

A region on mouse distal chromosome 1 (Chr. 1) that is highly enriched in quantitative trait loci (QTLs) controlling neural and behavioral phenotypes overlaps with the peak region of a major obesity QTL (Nob3.38), which we identified in an intercross of New Zealand Obese (NZO) mice with C57BL/6J (B6). By positional cloning we recently identified a microdeletion within this locus causing the dis...

Journal: :Indonesian Andrology and Biomedical Journal 2022

Background: Around 10 % of infertile men and 1 percent all males have azoospermia. There are two types azoospermia, which obstructive non-obstructive Non-obstructive azoospermia's main mechanism is because the testes fail to produce sex hormone induce spermatogenesis (primary testicular failure).
 Case: A patient 28 years old has a job as car paint worker. He came with chief complaint infe...

Journal: :Journal of medical genetics 1999
M C Digilio B Marino P Bagolan A Giannotti B Dallapiccola

Oesophageal atresia (OA) is a congenital defect associated with additional malformations in 30-70% of the cases. In particular, OA is a component of the VACTERL association. Since some major features of the VACTERL association, including conotruncal heart defect, radial aplasia, and anal atresia, have been found in patients with microdeletion 22q11.2 (del(22q11.2)), we have screened for del(22q...

Journal: :Clinical genetics 2012
A L Mosca-Boidron S Bouquillon L Faivre P Callier J Andrieux N Marle C Bonnet C Vincent-Delorme M Berri G Plessis S Manouvrier-Hanu A Dieux-Coeslier C Thauvin-Robinet E Pipiras A Delahaye M Payet C Ragon A Masurel-Paulet E Questiaux B Benzacken P Jonveaux F Mugneret M Holder-Espinasse

Most microdeletion syndromes identified before the implementation of array-comparative genomic hybridization (array-CGH) were presumed to be well-defined clinical entities. However, the introduction of whole-genome screening led not only to the description of new syndromes but also to the recognition of a broader spectrum of features for well-known syndromes. Here, we report on 10 patients pres...

2014
Julián Nevado Rafaella Mergener María Palomares-Bralo Karen Regina Souza Elena Vallespín Rocío Mena Víctor Martínez-Glez María Ángeles Mori Fernando Santos Sixto García-Miñaur Fé García-Santiago Elena Mansilla Luis Fernández María Luisa de Torres Mariluce Riegel Pablo Lapunzina

Several new microdeletion and microduplication syndromes are emerging as disorders that have been proven to cause multisystem pathologies frequently associated with intellectual disability (ID), multiple congenital anomalies (MCA), autistic spectrum disorders (ASD) and other phenotypic findings. In this paper, we review the "new" and emergent microdeletion and microduplication syndromes that ha...

Journal: :European journal of medical genetics 2005
Thomas Liehr Elke Brude Gabriele Gillessen-Kaesbach Rainer König Kristin Mrasek Ferdinand von Eggeling Heike Starke

Prader-Willi (PWS) and Angelman (AS) are syndromes of developmental impairment that can result either from a 15q11-q13 deletion, paternal uniparental disomy (UPD), imprinting, or UBE3A mutations. A small cytogenetic subset of PWS and AS patients are carriers of a so-called small supernumerary marker chromosome (sSMC). Here, we report on an previously unreported PWS case with a karyotype 47,XY,+...

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