نتایج جستجو برای: ullrich congenital muscular dystrophy

تعداد نتایج: 169567  

Journal: :Journal of neuromuscular diseases 2015
Céline Bouchet-Séraphin Sandrine Vuillaumier-Barrot Nathalie Seta

Dystroglycanopathies are neuromuscular disorders due to abnormal glycosylation of dystroglycan which is a cell-surface glycoprotein that acts as a receptor for extracellular matrix proteins containing laminin-G domains. The reduced ability of abnormally glycosylated α-DG to bind laminin is associated with abnormal neuronal migration and muscular dystrophy. Clinical manifestations are extremely ...

Journal: :Annals of neurology 2006
Terumi Murakami Yukiko K Hayashi Satoru Noguchi Megumu Ogawa Ikuya Nonaka Yuzo Tanabe Mieko Ogino Fumio Takada Makoto Eriguchi Norihiko Kotooka Kevin P Campbell Makiko Osawa Ichizo Nishino

OBJECTIVE The fukutin gene (FKTN) is the causative gene for Fukuyama-type congenital muscular dystrophy, characterized by rather homogeneous clinical features of severe muscle wasting and hypotonia from early infancy with mental retardation. In contrast with the severe dystrophic involvement of skeletal muscle, cardiac insufficiency is quite rare. Fukuyama-type congenital muscular dystrophy is ...

Journal: :The New England journal of medicine 1996
R Fadic Y Sunada A J Waclawik S Buck P J Lewandoski K P Campbell B P Lotz

C ARDIAC muscle is commonly affected in muscular dy~trophies.l-~ X-linked Duchenne's inuscular dystrophy and Becker's muscular dystrophy are caused by mutations in the gene encoding dystrophin,5,6 a membrane cytoskeletal p r ~ t e i n . ~ In skeletal and cardiac muscle, dystrophin is associated with a large oligomeric complex of sarcolemmal g lycopr~te ins .~~~ This dystrophin-glycoprotein comp...

Journal: :Seminars in respiratory and critical care medicine 2002
Anita K Simonds

Pulmonary complications including chest infections, atelectasis, pulmonary hypoplasia and ventilatory failure are the leading cause of death in the muscular dystrophies and atrophies. Ventilatory insufficiency is virtually inevitable in Duchenne muscular dystrophy and type 1 spinal muscular atrophy (SMA), but more variable in limb-girdle, congenital, and facioscapulohumeral muscular dystrophy. ...

2017
Kristin L. Fraser Scott Wong A. Reghan Foley Sameer Chhibber Carsten G. Bönnemann Daniel J. Lesser Carla Grosmann Anne Rutkowski

Collagen VI-related dystrophy (collagen VI-RD) is a rare neuromuscular condition caused by mutations in the COL6A1, COL6A2 or COL6A3 genes. The phenotypic spectrum includes early-onset Ullrich congenital muscular dystrophy, adult-onset Bethlem myopathy and an intermediate phenotype. The disorder is characterised by distal hyperlaxity and progressive muscle weakness, joint contractures and respi...

Journal: :Neuromuscular disorders : NMD 2003
Pervin Dinçer Burcu Balci Yeliz Yuva Beril Talim Martin Brockington Deniz Dinçel Silvia Torelli Sue Brown Gülsev Kale Göknur Haliloglu Filiz Ozbas Gerçeker Rengül Cetin Atalay Cengiz Yakicier Cheryl Longman Francesco Muntoni Haluk Topaloglu

The limb girdle muscular dystrophies are a heterogeneous group of conditions characterized by proximal muscle weakness and disease onset ranging from infancy to adulthood. We report here eight patients from seven unrelated families affected by a novel and relatively mild form of autosomal recessive limb girdle muscular dystrophy (LGMD2) with onset in the first decade of life and characterized b...

2013
Joshua J.A. Lee Toshifumi Yokota

Antisense therapy is an approach to fighting diseases using short DNA-like molecules called antisense oligonucleotides. Recently, antisense therapy has emerged as an exciting and promising strategy for the treatment of various neurodegenerative and neuromuscular disorders. Previous and ongoing pre-clinical and clinical trials have provided encouraging early results. Spinal muscular atrophy (SMA...

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