نتایج جستجو برای: pyridoxine dependent epilepsy

تعداد نتایج: 745226  

Journal: :Journal of Pediatric Neurology 2015

Journal: :JIMD reports 2014
Clara D M van Karnebeek Sylvia Stockler-Ipsiroglu Sravan Jaggumantri Birgit Assmann Peter Baxter Daniela Buhas Levinus A Bok Barbara Cheng Curtis R Coughlin Anibh M Das Alette Giezen Wahla Al-Hertani Gloria Ho Uta Meyer Philippa Mills Barbara Plecko Eduard Struys Keiko Ueda Monique Albersen Nanda Verhoeven Sidney M Gospe Renata C Gallagher Johan K L Van Hove Hans Hartmann

BACKGROUND Seventy-five percent of patients with pyridoxine-dependent epilepsy (PDE) due to Antiquitin (ATQ) deficiency suffer from developmental delay and/or intellectual disability (IQ < 70) despite seizure control. An observational study showed that adjunct treatment with a lysine-restricted diet is safe, results in partial normalization of lysine intermediates in body fluids, and may have b...

Journal: :American journal of physiology. Renal physiology 2002
Hamid M Said Alvaro Ortiz Nike D Vaziri

The kidneys play an important role in regulating vitamin B(6) body homeostasis, but limited information exists regarding the mechanism of pyridoxine uptake by renal epithelial cells, and no study exists on its regulation. To address these issues, we used the renal opossum-derived tubular epithelial (opossum kidney; OK) cells and found pyridoxine uptake to 1) be temperature and energy dependent,...

Journal: :Epilepsy & behavior : E&B 2011
Aravindhan Veerapandiyan Sara A Winchester William B Gallentine Edward C Smith Sujay Kansagra Keith Hyland Mohamad A Mikati

We describe the electroencephalographic and clinical seizure manifestations of pyridoxal 5'-phosphate-dependent epilepsy (PLP-DE) in two patients [diagnosis confirmed by low cerebrospinal fluid (CSF) PLP, complete resolution of previously intractable seizures with PLP supplementation, negative pyridoxine-dependent epilepsy CSF biomarkers, and/or positive disease causing pyridox(am)ine 5'-phosph...

Journal: :Blood 1949
A GELLHORN L O JONES

By ALFRED GELLHORN, M.D., AND LOGAN 0. JONES, M.D. E VIDENCE from animal experimentation indicates that pyridoxine, a cornponent of the vitamin B complex, is an essential factor for the maintenance and function of hematopoietic tissue. Severe anemia has been induced in dogs’ and swine2 on a pyridoxine deficient diet and the integrity of lymphoid tissue in rats has also been demonstrated to be d...

Journal: :The Tohoku journal of experimental medicine 1971
K Iinuma K Narisawa N Yamauchi T Yoshida T Mizuno

IINUMA, K., NARISAWA, K., YAMAUCHI, N., YOSHIDA, T. and MIZUNO, T. Pyridoxine Dependent Convulsion: Effect of Pyridoxine Therapy on Electro encephalograms. Tohoku J. exp. Med., 1971, 105 (1), 19-26 In a 7-month old boy with vitamin B6 dependent convulsion it was found that distribution of energy % of the EEG basic waves as well as an auto-correlogram of EEG remained abnormal 24 hours after an i...

Journal: :Pediatrics 2014
Shailly Jain-Ghai Navin Mishra Cecil Hahn Susan Blaser Saadet Mercimek-Mahmutoglu

Pyridoxine dependent epilepsy (PDE) is caused by mutations in the ALDH7A1 gene encoding α-aminoadipic semialdehyde dehydrogenase. The classic clinical presentation is neonatal seizures responsive only to pyridoxine therapy. White matter abnormalities, corpus callosum agenesis or hypoplasia, megacisterna magna, cortical dysplasia, neuronal heterotopias, intracerebral hemorrhage, and hydrocephalu...

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