نتایج جستجو برای: craniofacial anomalies

تعداد نتایج: 52309  

2014
Maisa Seppala Guilherme M. Xavier Chen-Ming Fan Martyn T. Cobourne

Holoprosencephaly is a heterogeneous developmental malformation of the central nervous system characterized by impaired forebrain cleavage, midline facial anomalies and wide phenotypic variation. Indeed, microforms represent the mildest manifestation, associated with facial anomalies but an intact central nervous system. In many cases, perturbations in sonic hedgehog signaling are responsible f...

Journal: :Pediatric dentistry 1994
P Pokala G Acs

A case is reported of a patient with deletion of the long arm of chromosome 7 at a highly specific locus (7q32). In addition to significant craniofacial stigmata and global developmental delay, the patient presented with numerous clinical and radiographic dental anomalies observed over a 10-year period. Hypodontia, accessory roots, dens invaginatus, hypoplastic enamel, and numerous pulpal anoma...

Journal: :Blood cells, molecules & diseases 2012
Dagmar Pospisilova Jana Cmejlova Barbora Ludikova Jan Stary Zdena Cerna Jiri Hak Pavel Timr Kvetoslava Petrtylova Jan Blatny Samuel Vokurka Radek Cmejla

Diamond-Blackfan anemia is a rare inherited bone marrow failure syndrome diagnosed in early infancy that is characterized by a (a) macrocytic anemia with no other significant cytopenia, (b) reticulocytopenia, and (c) normal bone marrow cellularity with a paucity of erythroid precursors. Physical anomalies are often present. Mutations in several ribosomal proteins have been associated with the d...

Journal: :Journal of medical genetics 1991
C Braegger A Bottani F Hallé A Giedion E Leumann R Seger U Willi A Schinzel

We report a 6 year old male with a pattern of malformations and anomalies including intrauterine growth retardation, microcephaly, psychomotor retardation, a pattern of craniofacial anomalies (flat face, hypertelorism, epicanthic folds, strabismus, short nose, low set ears), hypospadias and cryptorchidism, bilateral partial cutaneous syndactyly between fingers 2 to 5 and toes 2 to 4, postaxial ...

2017
Erin Conboy Filippo Vairo Darrel Waggoner Carole Ober Soma Das Radhika Dhamija Eric W Klee Pavel Pichurin

ACTB encodes the β-actin, and pathogenic variations in this gene have typically been associated with Baraitser-Winter cerebrofrontofacial syndrome, a congenital malformation syndrome characterized by short stature, craniofacial anomalies, and cerebral anomalies. Here, we describe the third case with the p.Arg183Trp variant in ACTB causing juvenile-onset dystonia. Our patient has severe, intract...

2014
Virginie Laugel-Haushalter Marie Paschaki Pauline Marangoni Coralie Pilgram Arnaud Langer Thibaut Kuntz Julie Demassue Supawich Morkmued Philippe Choquet André Constantinesco Fabien Bornert Matthieu Schmittbuhl Solange Pannetier Laurent Viriot André Hanauer Pascal Dollé Agnès Bloch-Zupan

BACKGROUND The RSK2 gene is responsible for Coffin-Lowry syndrome, an X-linked dominant genetic disorder causing mental retardation, skeletal growth delays, with craniofacial and digital abnormalities typically associated with this syndrome. Craniofacial and dental anomalies encountered in this rare disease have been poorly characterized. METHODOLOGY/PRINCIPAL FINDINGS We examined, using X-Ra...

Journal: :Human molecular genetics 2012
Ryan Humphreys Wei Zheng Lawrence S Prince Xianghu Qu Christopher Brown Kathleen Loomes Stacey S Huppert Scott Baldwin Steven Goudy

JAGGED1 mutations cause Alagille syndrome, comprising a constellation of clinical findings, including biliary, cardiac and craniofacial anomalies. Jagged1, a ligand in the Notch signaling pathway, has been extensively studied during biliary and cardiac development. However, the role of JAGGED1 during craniofacial development is poorly understood. Patients with Alagille syndrome have midface hyp...

2016
Nadège Gouignard Marco Maccarana Ina Strate Kristoffer von Stedingk Anders Malmström Edgar M Pera

Of all live births with congenital anomalies, approximately one-third exhibit deformities of the head and face. Most craniofacial disorders are associated with defects in a migratory stem and progenitor cell population, which is designated the neural crest (NC). Musculocontractural Ehlers-Danlos syndrome (MCEDS) is a heritable connective tissue disorder with distinct craniofacial features; this...

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