نتایج جستجو برای: lissencephaly

تعداد نتایج: 686  

Journal: :The Journal of Cell Biology 2004
Teruyuki Tanaka Finley F. Serneo Christine Higgins Michael J. Gambello Anthony Wynshaw-Boris Joseph G. Gleeson

Humans with mutations in either DCX or LIS1 display nearly identical neuronal migration defects, known as lissencephaly. To define subcellular mechanisms, we have combined in vitro neuronal migration assays with retroviral transduction. Overexpression of wild-type Dcx or Lis1, but not patient-related mutant versions, increased migration rates. Dcx overexpression rescued the migration defect in ...

Journal: :AJNR. American journal of neuroradiology 2001
N Sato S Hatakeyama N Shimizu A Hikima J Aoki K Endo

BACKGROUND AND PURPOSE Developmental changes in hippocampal formations (HFs) have been reported in association with agenesis of the corpus callosum, lissencephaly, and holoprosencephaly. The purpose of this study was to evaluate the developmental changes in HFs in patients with a variety of other congenital brain malformations. METHODS MR images of 44 patients with congenital brain malformati...

Journal: :Biochemical Society transactions 2013
Joanna Lipka Marijn Kuijpers Jacek Jaworski Casper C Hoogenraad

Neurons are highly specialized for the processing and transmission of electrical signals and use cytoskeleton-based motor proteins to transport different vesicles and cellular materials. Abnormalities in intracellular transport are thought to be a critical factor in the degeneration and death of neurons in both the central and peripheral nervous systems. Several recent studies describe disrupti...

Journal: :Proceedings of the National Academy of Sciences of the United States of America 2003
Wei Yan Amir H Assadi Anthony Wynshaw-Boris Gregor Eichele Martin M Matzuk Gary D Clark

Platelet-activating factor (PAF) has been shown to affect sperm motility and acrosomal function, thereby altering fertility. PAF acetylhydrolase 1b (PAFAH1B) hydrolyzes PAF and is composed of three subunits [the lissencephaly (LIS1) protein and alpha1 and alpha2 subunits] and structurally resembles a GTP-hydrolyzing protein. Besides the brain, transcripts for Lis1, alpha1, and alpha2 are locali...

Journal: :Human molecular genetics 2005
Kazuhito Toyo-Oka Shinji Sasaki Yoshihisa Yano Daisuke Mori Takuya Kobayashi Yoko Y Toyoshima Suzumi M Tokuoka Satoshi Ishii Takao Shimizu Masami Muramatsu Noriko Hiraiwa Atsushi Yoshiki Anthony Wynshaw-Boris Shinji Hirotsune

LIS1 is mutated in the human neuronal migration defect lissencephaly and along with NDEL1 (formerly NUDEL) participates in the regulation of cytoplasmic dynein function during neuronal development. Targeted disruption of Ndel1 suggested that NDEL1 could have other molecular targets that regulate microtubule organization for proper neuronal migration. To further understanding the molecular mecha...

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