نتایج جستجو برای: congenital generalized lipodystrophy

تعداد نتایج: 286938  

2010
Todd Roth Sri Nair Anıl Kumar

A 14-year-old female from Yemen presented with intense abdominal pain and headache. She was born at term to distant cousins, developmentally delayed and significantly dysmorphic. Four years ago, she was diagnosed with diabetes mellitus and undiagnosed hepatic, cardiac, genetic, neurologic, endocrine, musculoskeletal, and gastrointestinal disorders. No therapy was prescribed. Admission laborator...

2015
Lia Beatriz de Azevedo Souza Karbage Ana Paula Dias Rangel Montenegro Luciana Felipe Férrer Aragão Izabella Tamira Galdino Farias Vasconcelos Virgínia Oliveira Fernandes Annelise Barreto de Carvalho Clarisse Mourão Melo Ponte Catarina Brasil D'Alva Carla Soraya Costa Maia Synara Cavalcante Lopes Marivaldo Loyola Aragão Carla Antoniana Ferreira de Almeida Vieira Ana Paula Germano Lopes Cavalcante Renan Magalhães Montenegro

Lia Beatriz de Azevedo Souza Karbage, Ana Paula Dias Rangel Montenegro, Luciana Felipe Férrer Aragão, Izabella Tamira Galdino Farias Vasconcelos, Virgínia Oliveira Fernandes, Annelise Barreto de Carvalho, Clarisse Mourão Melo Ponte, Catarina Brasil D'Alva, Carla Soraya Costa Maia, Synara Cavalcante Lopes, Marivaldo Loyola Aragão, Carla Antoniana Ferreira de Almeida Vieira, Ana Paula Germano Lop...

Journal: :Seizure 2016
Roberta Opri Gian Maria Fabrizi Gaetano Cantalupo Moreno Ferrarini Alessandro Simonati Bernardo Dalla Bernardina Francesca Darra

PURPOSE A small case series with a neurodegenerative disorder involving central nervous system and related to Seipin mutations was recently reported. Herein we describe clinical and EEG features of three patients presenting with Progressive Myoclonus Epilepsy (PME) and Congenital Generalized Lipodystrophy type 2 (CGL2) related to novel Seipin mutations. METHODS The EEG-clinical picture was ev...

Journal: :European journal of medical genetics 2009
B Friguls W Coroleu R del Alcazar P Hilbert L Van Maldergem G Pintos-Morell

Berardinelli-Seip congenital lipodystrophy (BSCL) is a rare autosomal recessive condition associating insulin resistance, absence of subcutaneous fat and muscular hypertrophy. Disease-causing mutations have been described in AGPAT2 and BSCL2 genes. Hypertrophic cardiomyopathy is a classical late (third decade) complication which has only been occasionally described in childhood. We report on a ...

Journal: :Diabetes 2000
C Vigouroux J Magré M C Vantyghem C Bourut O Lascols S Shackleton D J Lloyd B Guerci G Padova P Valensi A Grimaldi R Piquemal P Touraine R C Trembath J Capeau

Missense mutations of the lamin A/C gene, LMNA, have been recently identified in Dunnigan-type familial partial lipodystrophy (FPLD), which belongs to a heterogeneous group of rare disorders affecting adipose tissue distribution and metabolism. In this study, we sequenced the LMNA coding region from patients presenting with FPLD or other forms of lipodystrophy. We identified two heterozygous mu...

2013
Sucharita Datta Isita Tripathy

Berardinelli–Seip Congenital Lipodystrophy( BSCL) also called Congenital Generalised Lipodystrophy (CGL) is a very rare autosomal recessive metabolic syndrome with a prevalence of less than1 case in 12 million. About 200 cases have been reported so far world-wide. BSCL2 ,the more severe form of the disease with onset in the neonatal period or early infancy is present in Lebanon, Portugal, Norwa...

2014
Víctor A. Cortés Susan V. Smalley Denisse Goldenberg Carlos F. Lagos María I. Hodgson José L. Santos

Congenital generalized lipodystrophy (CGL) is a rare autosomal recessive disorder characterized by extreme reduction of white adipose tissue (WAT) mass. CGL type 1 is the most frequent form and is caused by mutations in AGPAT2. Genetic and clinical studies were performed in two affected sisters of a Chilean family. These patients have notoriously dissimilar metabolic abnormalities that correlat...

2013
Wenjie Qiu Kenneth Wee Kosuke Takeda Xuemei Lim Shigeki Sugii George K. Radda Weiping Han

BACKGROUND While pathogenic mutations in BSCL2/Seipin cause congenital generalized lipodystrophy, the underlying mechanism is largely unknown. In this study, we investigated whether and how the pathogenic missense A212P mutation of Seipin (Seipin-A212P) inhibits adipogenesis. METHODOLOGY/RESULTS We analyzed gene expression and lipid accumulation in stable 3T3-L1 cell lines expressing wild typ...

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