نتایج جستجو برای: jarcho levin

تعداد نتایج: 2796  

Journal: :Human molecular genetics 2006
Sven Fischer Hermann-Josef Lüdecke Dagmar Wieczorek Stefan Böhringer Gabriele Gillessen-Kaesbach Bernhard Horsthemke

The oculo-auriculo-vertebral spectrum (OAVS) (OMIM % 164210) is a common developmental disorder characterized by hemifacial microsomia, epibulbar tumours, ear malformation and vertebral anomalies. Although rare familial cases suggest that OAVS has a genetic basis, no genetic defect has been identified so far. In a patient with OAVS and a chromosomal translocation t(4;8) we have found that the c...

1998
RUTH WYNNE-DAVIES

The diagnosis of idiopathic scoliosis is made after other known causes of the deformity have been excluded. This paper does not deal with scoliosis resulting from vertebral anomalies, nor with that associated with conditions of known genetic etiology, such as neurofibromatosis, Marfan’s syndrome or muscular dystrophy. Also, the diagnosis of idiopathic scoliosis is only made when the curve is st...

Journal: :Proceedings of the National Academy of Sciences 2014

Journal: :Revista Multidisciplinar em Saúde 2023

Introdução: A síndrome de Kleine-Levin (SKL) é uma condição neurológica rara que afeta principalmente adolescentes e jovens adultos. Caracteriza-se por episódios sono excessivamente prolongados, alterações comportamentais aumento do apetite. causa exata dessa ainda desconhecida, o diagnóstico baseado na observação dos sintomas clínicos característicos. Métodos: Pesquisadores conduziram revisões...

Journal: :American Journal of Public Health 1984

Journal: :Journal of evolutionary biology 2011
R J Asher K H Lin N Kardjilov L Hautier

Patterns of vertebral variation across mammals have seldom been quantified, making it difficult to test hypotheses of covariation within the axial skeleton and mechanisms behind the high level of vertebral conservatism among mammals. We examined variation in vertebral counts within 42 species of mammals, representing monotremes, marsupials and major clades of placentals. These data show that xe...

Journal: :The Journal of bone and joint surgery. British volume 1988
A P Roberts A N Conner J L Tolmie J M Connor

Two siblings with spondylothoracic dysostosis, and two siblings and three unrelated children with spondylocostal dysostosis are described. Both conditions are inherited and characterised by malformed thoracic and lumbar vertebrae. Spondylothoracic dysostosis produces "crab-like" deformities of the ribs, and is usually fatal during early infancy due to respiratory failure. Spondylocostal dysosto...

2017
Vinay Jasani

Congenital scoliosis is a scoliosis that occurs as a result of bony abnormalities that arise between 4 to 16 weeks of gestation. There are genetic and environmental factors involved in etio­ logy. The majority of congenital vertebral anomalies are in the thoracic spine (64%). The patients often have associated skeletal anomalies and can also be part of a syndrome. Skeletal, cardiac, genitourina...

Journal: :Human molecular genetics 2009
Mika Asai-Coakwell Curtis R French Ming Ye Kamal Garcha Karin Bigot Anoja G Perera Karen Staehling-Hampton Silvina C Mema Bhaskar Chanda Arcady Mushegian Steven Bamforth Michael R Doschak Guang Li Matthew B Dobbs Philip F Giampietro Brian P Brooks Perumalsamy Vijayalakshmi Yves Sauvé Marc Abitbol Periasamy Sundaresan Veronica van Heyningen Olivier Pourquié T Michael Underhill Andrew J Waskiewicz Ordan J Lehmann

Proteins of the bone morphogenetic protein (BMP) family are known to have a role in ocular and skeletal development; however, because of their widespread expression and functional redundancy, less progress has been made identifying the roles of individual BMPs in human disease. We identified seven heterozygous mutations in growth differentiation factor 6 (GDF6), a member of the BMP family, in p...

Journal: :Human molecular genetics 2011
Gavin Chapman Duncan B Sparrow Elisabeth Kremmer Sally L Dunwoodie

Mutations in the DELTA-LIKE 3 (DLL3) gene cause the congenital abnormal vertebral segmentation syndrome, spondylocostal dysostosis (SCD). DLL3 is a divergent member of the DSL family of Notch ligands that does not activate signalling in adjacent cells, but instead inhibits signalling when expressed in the same cell as the Notch receptor. Targeted deletion of Dll3 in the mouse causes a developme...

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