نتایج جستجو برای: link recessive

تعداد نتایج: 212740  

Journal: :Kidney international 2005
Patrick S Parfrey

Journal: :Trends in genetics : TIG 2014
Luciana Musante H Hilger Ropers

Most severe forms of intellectual disability (ID) have specific genetic causes. Numerous X chromosome gene defects and disease-causing copy-number variants have been linked to ID and related disorders, and recent studies have revealed that sporadic cases are often due to dominant de novo mutations with low recurrence risk. For autosomal recessive ID (ARID) the recurrence risk is high and, in po...

Journal: :Proceedings of the National Academy of Sciences of the United States of America 2017
Kristina M Rapuano Amanda L Zieselman William M Kelley James D Sargent Todd F Heatherton Diane Gilbert-Diamond

Obesity is a major public health concern that involves an interaction between genetic susceptibility and exposure to environmental cues (e.g., food marketing); however, the mechanisms that link these factors and contribute to unhealthy eating are unclear. Using a well-known obesity risk polymorphism (FTO rs9939609) in a sample of 78 children (ages 9-12 y), we observed that children at risk for ...

Journal: :Journal of medical genetics 2012
Hanan E Shamseldin Mohamed Elfaki Fowzan S Alkuraya

Background Fanconi anaemia (FA) is a group of disorders characterised by progressive bone marrow failure and a characteristic but variable craniofacial and skeletal involvement. Recessive mutations in any of 15 genes linked to FA lead to the pathognomonic increased susceptibility to double-strand DNA breaks. Methods Autozygome and exome analysis of a patient with classic FA phenotype Results ...

Journal: :The Journal of clinical investigation 2014
Jaerak Chang Seongju Lee Craig Blackstone

Autophagy allows cells to adapt to changes in their environment by coordinating the degradation and recycling of cellular components and organelles to maintain homeostasis. Lysosomes are organelles critical for terminating autophagy via their fusion with mature autophagosomes to generate autolysosomes that degrade autophagic materials; therefore, maintenance of the lysosomal population is essen...

2008
Alexander Edo Tondas

Hemophilia is a hereditaty coagulation disorder which is inherited as an X-link recessive trait. Disorder happens in the intrinsic hemostasis pathway, in which there is a deficiency or defect of coagulation factor VIII (Hemophilia A) or IX (Hemophilia B). Hemophilia is comnron in male, though occurrence in female has also been reported. Female usually are carries. Immunologically, there are sev...

Journal: :Cell 2011
Liyun Sang Julie J. Miller Kevin C. Corbit Rachel H. Giles Matthew J. Brauer Edgar A. Otto Lisa M. Baye Xiaohui Wen Suzie J. Scales Mandy Kwong Erik G. Huntzicker Mindan K. Sfakianos Wendy Sandoval J. Fernando Bazan Priya Kulkarni Francesc R. Garcia-Gonzalo Allen D. Seol John F. O'Toole Susanne Held Heiko M. Reutter William S. Lane Muhammad Arshad Rafiq Abdul Noor Muhammad Ansar Akella Radha Rama Devi Val C. Sheffield Diane C. Slusarski John B. Vincent Daniel A. Doherty Friedhelm Hildebrandt Jeremy F. Reiter Peter K. Jackson

Nephronophthisis (NPHP), Joubert (JBTS), and Meckel-Gruber (MKS) syndromes are autosomal-recessive ciliopathies presenting with cystic kidneys, retinal degeneration, and cerebellar/neural tube malformation. Whether defects in kidney, retinal, or neural disease primarily involve ciliary, Hedgehog, or cell polarity pathways remains unclear. Using high-confidence proteomics, we identified 850 inte...

Journal: :American journal of human genetics 2009
Nicolas Grillet Martin Schwander Michael S Hildebrand Anna Sczaniecka Anand Kolatkar Janice Velasco Jennifer A Webster Kimia Kahrizi Hossein Najmabadi William J Kimberling Dietrich Stephan Melanie Bahlo Tim Wiltshire Lisa M Tarantino Peter Kuhn Richard J H Smith Ulrich Müller

Hearing loss is the most common form of sensory impairment in humans and is frequently progressive in nature. Here we link a previously uncharacterized gene to hearing impairment in mice and humans. We show that hearing loss in the ethylnitrosourea (ENU)-induced samba mouse line is caused by a mutation in Loxhd1. LOXHD1 consists entirely of PLAT (polycystin/lipoxygenase/alpha-toxin) domains and...

Journal: :Journal of Biomedicine and Biotechnology 2002
Alexander J. R. Bishop Robert H. Schiestl

Cancer develops when cells no longer follow their normal pattern of controlled growth. In the absence or disregard of such regulation, resulting from changes in their genetic makeup, these errant cells acquire a growth advantage, expanding into precancerous clones. Over the last decade, many studies have revealed the relevance of genomic mutation in this process, be it by misreplication, enviro...

2016
Karl Patterson Lovleen Arya Sarah Bottomley Susan Morgan Angela Cox James Catto Helen E. Bryant

RECQ helicases are a family of enzymes with both over lapping and unique functions. Functional autosomal recessive loss of three members of the family BLM, WRN and RECQL4, results in hereditary human syndromes characterized by cancer predisposition and premature aging, but despite the finding that RECQL5 deficient mice are cancer prone, no such link has been made to human RECQL5. Here we demons...

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