نتایج جستجو برای: pantothenate kinase

تعداد نتایج: 227686  

Journal: :Proceedings of the National Academy of Sciences of the United States of America 2007
Roberta Leonardi Charles O Rock Suzanne Jackowski Yong-Mei Zhang

The human isoform 2 of pantothenate kinase (PanK2) is localized to the mitochondria, and mutations in this protein are associated with a progressive neurodegenerative disorder. PanK2 inhibition by acetyl-CoA is so stringent (IC50 < 1 microM) that it is unclear how the enzyme functions in the presence of intracellular CoA concentrations. Palmitoylcarnitine was discovered to be a potent activator...

2015
Pedro J. Garcia-Ruiz Joaquin Ayerbe Lydia Vela Desojo Cici E. Feliz Javier del Val Fernandez

Pantothenate kinase-associated neurodegeneration (PKAN) is usually associated with dystonia, which is typically severe and progressive over time. Pallidal stimulation (GPi DBS) has been carried out in selected cases of PKAN with drug-resistant dystonia with variable results. We report a 30-month follow-up study of a 30-year-old woman with PKAN-related dystonia treated with GPi DBS. Postoperativ...

Journal: :Molecular genetics and metabolism 2017
Penelope Hogarth Manju A Kurian Allison Gregory Barbara Csányi Tamara Zagustin Tomasz Kmiec Patricia Wood Angelika Klucken Natale Scalise Francesca Sofia Thomas Klopstock Giovanna Zorzi Nardo Nardocci Susan J Hayflick

a Department of Molecular & Medical Genetics, Oregon Health & Science University, Portland, USA b Department of Neurology, Oregon Health & Science University, Portland, USA c Molecular Neurosciences, Developmental Neurosciences Programme, UCL Institute of Child Health, London, UK d Department of Physiatry, Children's Healthcare of Atlanta, GA, USA e Department of Child Neurology, The Children's...

Journal: :Journal of Biological Chemistry 1952

Journal: :Journal of intellectual disability research : JIDR 2007
K Freeman A Gregory A Turner P Blasco P Hogarth S Hayflick

BACKGROUND Pantothenate kinase-associated neurodegeneration (PKAN), an extremely rare autosomal recessive disorder resulting in iron accumulation in the brain, has a diverse phenotypic expression. Based on limited case studies of one or two patients, intellectual impairment is considered part of PKAN. Investigations of cognitive functioning have utilized specific neuropsychological tests, witho...

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