نتایج جستجو برای: cerebellar ataxias

تعداد نتایج: 26906  

2013
Yuting Shi Junling Wang Jia-Da Li Haigang Ren Wenjuan Guan Miao He Weiqian Yan Ying Zhou Zhengmao Hu Jianguo Zhang Jingjing Xiao Zheng Su Meizhi Dai Jun Wang Hong Jiang Jifeng Guo Yafang Zhou Fufeng Zhang Nan Li Juan Du Qian Xu Yacen Hu Qian Pan Lu Shen Guanghui Wang Kun Xia Zhuohua Zhang Beisha Tang

Autosomal recessive cerebellar ataxias are a group of neurodegenerative disorders that are characterized by complex clinical and genetic heterogeneity. Although more than 20 disease-causing genes have been identified, many patients are still currently without a molecular diagnosis. In a two-generation autosomal recessive cerebellar ataxia family, we mapped a linkage to a minimal candidate regio...

Journal: :Journal of neurophysiology 2016
Polina A Egorova Olga A Zakharova Olga L Vlasova Ilya B Bezprozvanny

Cerebellar Purkinje cells (PCs) are primarily affected in many spinocerebellar ataxias (SCA). In this study we investigated functional activity of PCs in transgenic mouse model of SCA2, a polyglutamine neurodegenerative hereditary disorder. In our studies we used extracellular single-unit recording method to compare spontaneous activity of PCs in age-matched wild-type mice and SCA2-58Q transgen...

2014
Erin Sandford Margit Burmeister

Ataxia is a neurological cerebellar disorder characterized by loss of coordination during muscle movements affecting walking, vision, and speech. Genetic ataxias are very heterogeneous, with causative variants reported in over 50 genes, which can be inherited in classical dominant, recessive, X-linked, or mitochondrial fashion. A common mechanism of dominant ataxias is repeat expansions, where ...

2017
Mohsen JAVADZADEH Masoud HASSANVAND AMOUZADEH Shaghayegh SADAT ESMAIL NEJAD Ezatollah ABASI Abbas ALIPOUR Mohsen MOLLAMOHAMMADI

OBJECTIVE This study was conducted on the demographic data, clinical characteristics, electroencephalography, neuroradiological findings, and their impact on the recurrence of ataxia. MATERIALS & METHODS A 3-yr retrospective review of 49 children with ataxia in Mofid Children Hospital, Tehran, Iran was conducted from Apr 2013 to Apr 2016. The demographic, clinical and paraclinical data were r...

2013
N. Tirada

What are Hereditary Ataxias? Ataxia is a neurologic disorder in which there is loss of coordination of movement. It can result from dysfunction of the cerebellum and brain stem and their afferent or efferent pathways. The etiology of ataxia can be divided into 3 main categories: acquired, sporadic, and hereditary. Hereditary ataxias are one of the largest groups of hereditary progressive neurod...

Journal: :Archives of neurology 1999
E Storey S M Forrest J H Shaw P Mitchell R J Gardner

BACKGROUND Spinocerebellar ataxia type 2 (SCA2) is a recently delineated cause of autosomal dominant cerebellar ataxia type I. The basic clinical neurologic features of SCA2 have been described in the literature, but neuropsychological features have not, despite statements that some patients became demented. OBJECTIVE To describe the clinical and neuropsychological features of patients from a...

2017
Hiroshi Mitoma Mario Manto Christiane S Hampe

Reports suggesting a pathogenic role of autoantibodies directed against glutamic acid decarboxylase 65 (GAD65Abs) in cerebellar ataxias (CAs) are reviewed, and debatable issues such as internalization of antibodies by neurons and roles of epitopes are discussed. GAD65 is one of two enzymes that catalyze the conversion of glutamate to the inhibitory neurotransmitter gamma-aminobutyric acid (GABA...

Journal: :American journal of human genetics 2001
M C Moreira C Barbot N Tachi N Kozuka P Mendonça J Barros P Coutinho J Sequeiros M Koenig

Ataxia with oculomotor apraxia (AOA) is characterized by early-onset cerebellar ataxia, ocular apraxia, early areflexia, late peripheral neuropathy, slow progression, severe motor handicap, and absence of both telangiectasias and immunodeficiency. We studied 13 Portuguese families with AOA and found that the two largest families show linkage to 9p, with LOD scores of 4.13 and 3.82, respectively...

Journal: :American journal of human genetics 2015
Marie Coutelier Iulia Blesneac Arnaud Monteil Marie-Lorraine Monin Kunie Ando Emeline Mundwiller Alfredo Brusco Isabelle Le Ber Mathieu Anheim Anna Castrioto Charles Duyckaerts Alexis Brice Alexandra Durr Philippe Lory Giovanni Stevanin

Hereditary cerebellar ataxias (CAs) are neurodegenerative disorders clinically characterized by a cerebellar syndrome, often accompanied by other neurological or non-neurological signs. All transmission modes have been described. In autosomal-dominant CA (ADCA), mutations in more than 30 genes are implicated, but the molecular diagnosis remains unknown in about 40% of cases. Implication of ion ...

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