نتایج جستجو برای: sideroblastic anemia

تعداد نتایج: 56367  

Journal: :Blood 2013
Daniel H Wiseman Alison May Stephen Jolles Philip Connor Colin Powell Matthew M Heeney Patricia J Giardina Robert J Klaassen Pranesh Chakraborty Michael T Geraghty Nathalie Major-Cook Caroline Kannengiesser Isabelle Thuret Alexis A Thompson Laura Marques Stephen Hughes Denise K Bonney Sylvia S Bottomley Mark D Fleming Robert F Wynn

Congenital sideroblastic anemias (CSAs) are a heterogeneous group of inherited disorders identified by pathological erythroid precursors with perinuclear mitochondrial iron deposition in bone marrow. An international collaborative group of physicians and laboratory scientists collated clinical information on cases of CSA lacking known causative mutations, identifying a clinical subgroup of CSA ...

Journal: :The Journal of biological chemistry 2012
David F Bishop Vassili Tchaikovskii A Victor Hoffbrand Marie E Fraser Steven Margolis

Mutations in the erythroid-specific aminolevulinic acid synthase gene (ALAS2) cause X-linked sideroblastic anemia (XLSA) by reducing mitochondrial enzymatic activity. Surprisingly, a patient with the classic XLSA phenotype had a novel exon 11 mutation encoding a recombinant enzyme (p.Met567Val) with normal activity, kinetics, and stability. Similarly, both an expressed adjacent XLSA mutation, p...

2017
Yingchi Zhang Jingliao Zhang Wenbin An Yang Wan Shihui Ma Jie Yin Xichuan Li Jie Gao Weiping Yuan Ye Guo James Douglas Engel Lihong Shi Tao Cheng Xiaofan Zhu

The first intronic mutations in the intron 1 GATA site (int-1-GATA) of 5-aminolevulinate synthase 2 (ALAS2) have been identified in X-linked sideroblastic anemia (XLSA) pedigrees, strongly suggesting it could be causal mutations of XLSA. However, the function of this int-1-GATA site during in vivo development remains largely unknown. Here, we generated mice lacking a 13 bp fragment, including t...

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