نتایج جستجو برای: episodic ataxia type 2

تعداد نتایج: 3480788  

Journal: :Neurobiology of disease 2008
Tracey D Graves Paola Imbrici Esther E Kors Gisela M Terwindt Louise H Eunson Rune R Frants Joost Haan Michel D Ferrari Peter J Goadsby Michael G Hanna Arn M J M van den Maagdenberg Dimitri M Kullmann

Premature stop codons in CACNA1A, which encodes the alpha(1A) subunit of neuronal P/Q-type (Ca(V)2.1) Ca(2+) channels, cause episodic ataxia type 2 (EA2). CACNA1A undergoes extensive alternative splicing, which contributes to the pharmacological and kinetic heterogeneity of Ca(V)2.1-mediated Ca(2+) currents. We identified three novel heterozygous stop codon mutations associated with EA2 in an a...

Journal: :European journal of paediatric neurology : EJPN : official journal of the European Paediatric Neurology Society 2009
D I Zafeiriou F Lehmann-Horn E Vargiami E Teflioudi A Ververi K Jurkat-Rott

Autosomal dominant episodic ataxia type 2 (EA2) results from mutations of the CACNA1A gene. We describe EA2 with unusual features in a father and daughter with a novel CACNA1A mutation coding for Y248C. Both patients showed severe cerebellar atrophy in MRI and clinical signs of progressive spinocerebellar atrophy type 6. Most disabling were the very frequent episodes of ataxia with migraine (wi...

2017
Elizabeth A. Ferrick-Kiddie Joshua J. C. Rosenthal Gregory D. Ayers Ronald B. Emeson

Adenosine-to-inosine RNA editing in transcripts encoding the voltage-gated potassium channel Kv1.1 converts an isoleucine to valine codon for amino acid 400, speeding channel recovery from inactivation. Numerous Kv1.1 mutations have been associated with the human disorder Episodic Ataxia Type-1 (EA1), characterized by stress-induced ataxia, myokymia, and increased prevalence of seizures. Three ...

Journal: :Human molecular genetics 1997
C Jodice E Mantuano L Veneziano F Trettel G Sabbadini L Calandriello A Francia M Spadaro F Pierelli F Salvi R A Ophoff R R Frants M Frontali

Point mutations of the CACNA1A gene coding for the alpha 1A voltage-dependent calcium channel subunit are responsible for familial hemiplegic migraine (FHM) and episodic ataxia type 2 (EA2). In addition, expansions of the CAG repeat motif at the 3' end of the gene, smaller than those responsible for dynamic mutation disorders, were found in patients with a progressive spinocerebellar ataxia, na...

2014
Albert Leung Yi Zhao Shivshil Shukla

BACKGROUND Empirical acupuncture treatment paradigm for acute pain utilizing Tendinomuscular Meridians (TMM) calls for the stimulation of Ting Points (TPs) and Gathering point(GP). This study aims to compare the supraspinal neuronal mechanisms associated with both TPs and GP needling (EA3), and TPs needling alone (EA2) with fMRI. RESULTS A significant (P < 0.01) difference between pre-scan (h...

2013
Charalampos Tzoulis Stefan Johansson Bjørn Ivar Haukanes Helge Boman Per Morten Knappskog Laurence A. Bindoff

We employed whole exome sequencing to investigate three Norwegian siblings with an autosomal recessive spastic ataxia and epilepsy. All patients were compound heterozygous (c.13352T>C, p.Leu4451Pro; c.6890T>G, p.Leu2297Trp) for mutations in the SACS gene establishing the diagnosis of autosomal recessive spastic ataxia of Charlevoix-Saguenay (ARSACS). The clinical features shown by our patients ...

Journal: :Muscle & nerve 2014
Saskia Lassche Sergio Lainez Bastiaan R Bloem Bart P C van de Warrenburg Jeannette Hofmeijer Henny H Lemmink Joost G J Hoenderop René J M Bindels Gea Drost

We describe the clinical phenotype of a novel de novo KNCA1 mutation, and functional characterization of the effects of the mutation on Kv1.1 channel function. HEK293 cells were transfected transiently with either wild-type or mutant channels. Representative currents were evoked after application of a series of square voltage steps from -80 mV to +50 mV in 200-ms intervals from Vh = -80 mV. Ext...

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