نتایج جستجو برای: iduronidase enzyme deficiency

تعداد نتایج: 368943  

Journal: :Molecular therapy : the journal of the American Society of Gene Therapy 2007
Xiucui Ma Yuli Liu Mindy Tittiger Anne Hennig Attila Kovacs Sarah Popelka Baomei Wang Ramin Herati Mark Bigg Katherine P Ponder

Mucopolysaccharidosis I (MPS I) is caused by deficient alpha-L-iduronidase (IDUA) activity and results in the accumulation of glycosaminoglycans and multisystemic disease. Gene therapy could program cells to secrete mannose 6-phosphate-modified IDUA, and enzyme in blood could be taken up by other cells. Neonatal retroviral vector (RV)-mediated gene therapy has been shown to reduce the manifesta...

Journal: :Molecular genetics and metabolism 2007
Sarah Chung Xiucui Ma Yuli Liu David Lee Mindy Tittiger Katherine P Ponder

Mucopolysaccharidosis I (MPS I) due to deficient alpha-L-iduronidase (IDUA) activity results in accumulation of glycosaminoglycans in many cells. Gene therapy could program cells to secrete IDUA modified with mannose 6-phosphate (M6P), and enzyme could be taken up by other cells via the M6P receptor. We previously reported that newborn MPS I mice that were injected intravenously with 10(9) (hig...

2014
Naveen Kumar Chennamaneni Arun Babu Kumar Mariana Barcenas Zdeněk Spáčil C. Ronald Scott František Tureček Michael H. Gelb

Tandem mass spectrometry for the multiplex and quantitative analysis of enzyme activities in dried blood spots on newborn screening cards has emerged as a powerful technique for early assessment of lysosomal storage diseases. Here we report the design and process-scale synthesis of substrates for the enzymes α-l-iduronidase, iduronate-2-sulfatase, and N-acetylgalactosamine-4-sulfatase that are ...

Journal: :research in pharmaceutical sciences 0
sz samsam shariat n alinejad

ceruloplasmin (cp) is a human plasma protein with multiple physiological functions including ferroxidase and oxidase activities. deficiency or inhibition of the enzyme may lead to some abnormalities, including iron deposition in several tissues and causes various pathological conditions in the body. direct interaction of cadmium (cd), a widespread, highly toxic environmental pollutant, with hum...

نمودار تعداد نتایج جستجو در هر سال

با کلیک روی نمودار نتایج را به سال انتشار فیلتر کنید