نتایج جستجو برای: link recessive

تعداد نتایج: 212740  

2017

A single gene defect leads to differing degrees of renal and hepatic involvement, with very different phenotypes and clinical outcome within even one affected family. [2] Kidneys are bilaterally enlarged and contain large numbers of cysts throughout the organ, due to the dilatation and elongation of renal collecting ducts. At birth, the interstitium and the rest of the tubules are normal but th...

Journal: :Journal of medical genetics 1982
E O Da Silva

In 1912, Klippel and Feill reported the first clinical details and necropsy findings of a syndrome characterised by the triad short or absent neck, severe limitation of head movement, and low posterior hairline. An Egyptian mummy (from 500 BC) is the oldest subject in whom Klippel-Feil syndrome has been seen.2 Another interesting observation is the similarity between the figure of an old man de...

Journal: :The Journal of Cell Biology 2003
Luigia Atorino Laura Silvestri Mirko Koppen Laura Cassina Andrea Ballabio Roberto Marconi Thomas Langer Giorgio Casari

Mmutations in paraplegin, a putative mitochondrial metallopeptidase of the AAA family, cause an autosomal recessive form of hereditary spastic paraplegia (HSP). Here, we analyze the function of paraplegin at the cellular level and characterize the phenotypic defects of HSP patients' cells lacking this protein. We demonstrate that paraplegin coassembles with a homologous protein, AFG3L2, in the ...

Journal: :Cell 2012
Moumita Chaki Rannar Airik Amiya K. Ghosh Rachel H. Giles Rui Chen Gisela G. Slaats Hui Wang Toby W. Hurd Weibin Zhou Andrew Cluckey Heon Yung Gee Gokul Ramaswami Chen-Jei Hong Bruce A. Hamilton Igor Červenka Ranjani Sri Ganji Vitezslav Bryja Heleen H. Arts Jeroen van Reeuwijk Machteld M. Oud Stef J.F. Letteboer Ronald Roepman Hervé Husson Oxana Ibraghimov-Beskrovnaya Takayuki Yasunaga Gerd Walz Lorraine Eley John A. Sayer Bernhard Schermer Max C. Liebau Thomas Benzing Stephanie Le Corre Iain Drummond Sabine Janssen Susan J. Allen Sivakumar Natarajan John F. O’Toole Massimo Attanasio Sophie Saunier Corinne Antignac Robert K. Koenekoop Huanan Ren Irma Lopez Ahmet Nayir Corinne Stoetzel Helene Dollfus Rustin Massoudi Joseph G. Gleeson Sharon P. Andreoli Dan G. Doherty Anna Lindstrad Christelle Golzio Nicholas Katsanis Lars Pape Emad B. Abboud Ali A. Al-Rajhi Richard A. Lewis Heymut Omran Eva Y.-H.P. Lee Shaohui Wang JoAnn M. Sekiguchi Rudel Saunders Colin A. Johnson Elizabeth Garner Katja Vanselow Jens S. Andersen Joseph Shlomai Gudrun Nurnberg Peter Nurnberg Shawn Levy Agata Smogorzewska Edgar A. Otto Friedhelm Hildebrandt

Nephronophthisis-related ciliopathies (NPHP-RC) are degenerative recessive diseases that affect kidney, retina, and brain. Genetic defects in NPHP gene products that localize to cilia and centrosomes defined them as "ciliopathies." However, disease mechanisms remain poorly understood. Here, we identify by whole-exome resequencing, mutations of MRE11, ZNF423, and CEP164 as causing NPHP-RC. All t...

Journal: :Cell 2002
Toshiyasu Taniguchi Irene Garcia-Higuera Bo Xu Paul R. Andreassen Richard C. Gregory Seong-Tae Kim William S. Lane Michael B. Kastan Alan D. D'Andrea

Fanconi anemia (FA) and ataxia telangiectasia (AT) are clinically distinct autosomal recessive disorders characterized by spontaneous chromosome breakage and hematological cancers. FA cells are hypersensitive to mitomycin C (MMC), while AT cells are hypersensitive to ionizing radiation (IR). Here, we identify the Fanconi anemia protein, FANCD2, as a link between the FA and ATM damage response p...

2006
Marc Ialenti

Werner Syndrome (WS) is an autosomal recessive disease that leads to the premature manifestation of clinical symptoms associated with normal aging. Clinical symptoms include: short stature, graying/loss of hair, osteoporosis, cataracts, atherosclerosis, type II diabetes, hypogonadism, skin ulcers, reduced fertility, and high incidence of malignant neoplasms. They appear in one’s 20’s and 30’s, ...

Journal: :Proceedings of the National Academy of Sciences of the United States of America 2004
Dongdong Yao Zezong Gu Tomohiro Nakamura Zhong-Qing Shi Yuliang Ma Benjamin Gaston Lisa A Palmer Edward M Rockenstein Zhuohua Zhang Eliezer Masliah Takashi Uehara Stuart A Lipton

Many hereditary and sporadic neurodegenerative disorders are characterized by the accumulation of aberrant proteins. In sporadic Parkinson's disease, representing the most prevalent movement disorder, oxidative and nitrosative stress are believed to contribute to disease pathogenesis, but the exact molecular basis for protein aggregation remains unclear. In the case of autosomal recessive-juven...

Journal: :Cell 1998
James P Carney Richard S Maser Heidi Olivares Elizabeth M Davis Michelle Le Beau John R Yates Lara Hays William F Morgan John H.J Petrini

Nijmegen breakage syndrome (NBS) is an autosomal recessive disorder characterized by increased cancer incidence, cell cycle checkpoint defects, and ionizing radiation sensitivity. We have isolated the gene encoding p95, a member of the hMre11/hRad50 double-strand break repair complex. The p95 gene mapped to 8q21.3, the region that contains the NBS locus, and p95 was absent from NBS cells establ...

Journal: :Neuron 2010
Joshua J. Buchman Huan-Chung Tseng Ying Zhou Christopher L. Frank Zhigang Xie Li-Huei Tsai

Primary autosomal-recessive microcephaly (MCPH) and Majewski osteodysplastic primordial dwarfism type II (MOPDII) are both genetic diseases that result in decreased brain size at birth. MCPH is thought to arise from alterations in the size of the neural progenitor pool, but the cause of this defect has not been thoroughly explored. We find that one of the genes associated with MCPH, Cdk5rap2, i...

Journal: :American journal of human genetics 2014
Rosalind Law Tracy Dixon-Salazar Julie Jerber Na Cai Ansar A Abbasi Maha S Zaki Kirti Mittal Stacey B Gabriel Muhammad Arshad Rafiq Valeed Khan Maria Nguyen Ghazanfar Ali Brett Copeland Eric Scott Nasim Vasli Anna Mikhailov Muhammad Nasim Khan Danielle M Andrade Muhammad Ayaz Muhammad Ansar Muhammad Ayub John B Vincent Joseph G Gleeson

Dendritic spines represent the major site of neuronal activity in the brain; they serve as the receiving point for neurotransmitters and undergo rapid activity-dependent morphological changes that correlate with learning and memory. Using a combination of homozygosity mapping and next-generation sequencing in two consanguineous families affected by nonsyndromic autosomal-recessive intellectual ...

نمودار تعداد نتایج جستجو در هر سال

با کلیک روی نمودار نتایج را به سال انتشار فیلتر کنید