نتایج جستجو برای: lysosomal disorders

تعداد نتایج: 684439  

Journal: :Journal of Cell Science 2023

ABSTRACT First Person is a series of interviews with the first authors selection papers published in Journal Cell Science, helping researchers promote themselves alongside their papers. Felicity Sterling author on ‘ StARD9 novel lysosomal kinesin required for membrane tubulation, cholesterol transport and Purkinje cell survival’, JCS. conducted research described this article while PhD student ...

Journal: :Journal of inborn errors of metabolism and screening 2023

Mucopolysaccharidosis (MPS) is a group of metabolic disorders caused by the deficiency or complete absence certain lysosomal enzymes responsible for breakdown mucopolysaccharides, causing an accumulation glycosaminoglycans (GAGs) throughout body. type I (MPS I), also called Hurler syndrome, autosomal recessive storage disorder resulting from enzyme α-L-iduronidase. This report aims to present c...

Journal: :Human molecular genetics 2011
Michela Palmieri Soren Impey Hyojin Kang Alberto di Ronza Carl Pelz Marco Sardiello Andrea Ballabio

In metazoans, lysosomes are the center for the degradation of macromolecules and play a key role in a variety of cellular processes, such as autophagy, exocytosis and membrane repair. Defects of lysosomal pathways are associated with lysosomal storage disorders and with several late onset neurodegenerative diseases. We recently discovered the CLEAR (Coordinated Lysosomal Expression and Regulati...

Journal: :Human molecular genetics 2015
Anastasia G Henry Soheil Aghamohammadzadeh Harry Samaroo Yi Chen Kewa Mou Elie Needle Warren D Hirst

Lysosomal dysfunction plays a central role in the pathogenesis of several neurodegenerative disorders, including Parkinson's disease (PD). Several genes linked to genetic forms of PD, including leucine-rich repeat kinase 2 (LRRK2), functionally converge on the lysosomal system. While mutations in LRRK2 are commonly associated with autosomal-dominant PD, the physiological and pathological functi...

Journal: :Nature communications 2012
Dongbiao Shen Xiang Wang Xinran Li Xiaoli Zhang Zepeng Yao Shannon Dibble Xian-ping Dong Ting Yu Andrew P Lieberman Hollis D Showalter Haoxing Xu

Lysosomal lipid accumulation, defects in membrane trafficking and altered Ca(2+) homoeostasis are common features in many lysosomal storage diseases. Mucolipin transient receptor potential channel 1 (TRPML1) is the principle Ca(2+) channel in the lysosome. Here we show that TRPML1-mediated lysosomal Ca(2+) release, measured using a genetically encoded Ca(2+) indicator (GCaMP3) attached directly...

Journal: :Wiley Interdisciplinary Reviews: Nanomedicine and Nanobiotechnology 2010

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