نتایج جستجو برای: cerebrotendinous xanthomatosis

تعداد نتایج: 1043  

Journal: :Journal of lipid research 1981
H Oftebro I Björkhem F C Størmer J I Pedersen

Oxidation of the side chain of 5 beta-cholestane-3 alpha, 7 alpha-diol, 7 alpha-hydroxy-4-cholesten-3-one, and 5-cholestene-3 beta, 7 alpha-diol has been studied in subcellular fractions of liver from a patient with cerebrotendinous xanthomatosis (CTX) and a control subject. All intermediates were efficiently 26-hydroxylated and further converted to the corresponding 26-carboxylated derivatives...

Journal: :European journal of neurology 2011
B Pilo-de-la-Fuente A Jimenez-Escrig J R Lorenzo J Pardo M Arias A Ares-Luque J Duarte S Muñiz-Pérez M J Sobrido

BACKGROUND AND PURPOSE Cerebrotendinous xanthomatosis (CTX) is a rare autosomal recessive disorder caused by mutations in the CYP27A1 gene resulting in sterol-27-hydroxylase deficiency. Current information about CTX is based mainly on case reports, with only few large series reported. Although perceived as a potentially treatable condition, efficacy of chenodeoxycholic acid plus statin therapy ...

2016
Masaru Yanagihashi Osamu Kano Tomoya Terashima Yuji Kawase Sayori Hanashiro Masahiro Sawada Yuichi Ishikawa Nobuyuki Shiraga Ken Ikeda Yasuo Iwasaki

BACKGROUND Cerebrotendinous xanthomatosis (CTX) is a rare autosomal recessive sterol storage disease caused by a mutated sterol 27-hydroxylase (CYP27A1) gene. Patients with typical CTX show neurological dysfunction including bilateral cataracts, paresis, cerebral ataxia, dementia, and psychiatric disorders, and magnetic resonance imaging (MRI) has revealed symmetrical lesions in the cerebellar ...

Journal: :The Journal of clinical investigation 1989
I Tabas S J Feinmark N Beatini

The acyl-CoA: cholesterol acyl transferase (ACAT) reaction in macrophages is a critical step in atherosclerotic foam cell formation, but little is known about the reaction's sterol substrate specificity. In this report we examine the macrophage ACAT reactivity of the shellfish sterol, desmosterol, and other sterols found in man because of shellfish ingestion or in association with the foam cell...

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