نتایج جستجو برای: hypohidrotic ectodermal dysplasia

تعداد نتایج: 30775  

2016
Binghui Zeng Xue Xiao Sijie Li Hui Lu Jiaxuan Lu Ling Zhu Dongsheng Yu Wei Zhao

Hypohidrotic ectodermal dysplasia (HED) is characterized by abnormal development of the teeth, hair, and sweat glands. Ectodysplasin A (EDA), Ectodysplasin A receptor (EDAR), and EDAR-associated death domain (EDARADD) are candidate genes for HED, but the relationship between WNT10A and HED has not yet been validated. In this study, we included patients who presented at least two of the three ec...

Journal: :Human molecular genetics 2008
Johanna Pispa Marja Pummila Philip A Barker Irma Thesleff Marja L Mikkola

The development of ectodermal organs requires signalling by ectodysplasin (Eda), a tumor necrosis factor (TNF) family member, its receptor Edar and downstream activation of the nuclear factor kappaB (NF-kappaB) transcription factor. In humans, mutations in the Eda pathway components cause hypohidrotic ectodermal dysplasia, a syndrome characterized by missing teeth, sparse hair and defects in sw...

Journal: :Journal of Indian Society of Pedodontics and Preventive Dentistry 2005

Journal: :Iranian Journal of Pediatrics 2021

: Hypohidrotic ectodermal dysplasia (HED) is the most common type of that result faulty development leading to such defects as hypotrichosis, anodontia or hypodontia, and hypohidrosis anhidrosis. X-linked HED caused by mutations in ectodysplasin A (EDA) gene accounts for 90% all cases. Autosomal other involved genes, EDA-receptor (EDAR) gene. In this study, we included two distinct families wit...

Journal: :The Journal of biological chemistry 2011
Christine Kowalczyk Nathalie Dunkel Laure Willen Margret L Casal Elizabeth A Mauldin Olivier Gaide Aubry Tardivel Giovanna Badic Anne-Lise Etter Manuel Favre Douglas M Jefferson Denis J Headon Stéphane Demotz Pascal Schneider

The TNF family ligand ectodysplasin A (EDA) and its receptor EDAR are required for proper development of skin appendages such as hair, teeth, and eccrine sweat glands. Loss of function mutations in the Eda gene cause X-linked hypohidrotic ectodermal dysplasia (XLHED), a condition that can be ameliorated in mice and dogs by timely administration of recombinant EDA. In this study, several agonist...

2016
Armine Darbinyan Eugene O. Major Susan Morgello Steven Holland Caroline Ryschkewitsch Maria Chiara Monaco Thomas P. Naidich Joshua Bederson Joanna Malaczynska Fei Ye Ronald Gordon Charlotte Cunningham-Rundles Mary Fowkes Nadejda M. Tsankova

Human BK polyomavirus (BKV) is reactivated under conditions of immunosuppression leading most commonly to nephropathy or cystitis; its tropism for the brain is rare and poorly understood. We present a unique case of BKV-associated encephalopathy in a man with hypohidrotic ectodermal dysplasia and immunodeficiency (HED-ID) due to IKK-gamma (NEMO) mutation, who developed progressive neurological ...

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