نتایج جستجو برای: congenital retinal macrovessels

تعداد نتایج: 199422  

2014
Mina Laghmari Omar Lezrek

A 20-year-old woman presented for a routine eye examination. Her best-corrected visual acuity was 20/20 in the right eye and 20/25 in the left eye. Fundus examination revealed in both eyes the presence of multiple egg-shaped hyperpigmented retinal lesions (at least 4), sur-rounded by a depigmented halo(figure 1, black arrows). The appearance of these lesions was suggestive of congenital hypertr...

Journal: :Human molecular genetics 2014
Stylianos Michalakis Lior Shaltiel Vithiyanjali Sothilingam Susanne Koch Verena Schludi Stefanie Krause Christina Zeitz Isabelle Audo Marie-Elise Lancelot Christian Hamel Isabelle Meunier Markus N Preising Christoph Friedburg Birgit Lorenz Nawal Zabouri Silke Haverkamp Marina Garcia Garrido Naoyuki Tanimoto Mathias W Seeliger Martin Biel Christian A Wahl-Schott

Mutations in CACNA1F encoding the α1-subunit of the retinal Cav1.4 L-type calcium channel have been linked to Cav1.4 channelopathies including incomplete congenital stationary night blindness type 2A (CSNB2), Åland Island eye disease (AIED) and cone-rod dystrophy type 3 (CORDX3). Since CACNA1F is located on the X chromosome, Cav1.4 channelopathies are typically affecting male patients via X-chr...

2013
Celso Henrique Alves Koen Bossers Rogier M. Vos Anke H. W. Essing Sigrid Swagemakers Peter J. van der Spek Joost Verhaagen Jan Wijnholds

In humans, the Crumbs homologue-1 (CRB1) gene is mutated in progressive types of autosomal recessive retinitis pigmentosa and Leber congenital amaurosis. The severity of the phenotype due to human CRB1 or mouse Crb1 mutations is dependent on the genetic background. Mice on C57BL/6J background with Crb1 mutations show late onset of retinal spotting phenotype or no phenotype. Recently, we showed ...

Journal: :Compendium 2009
Shelby Reinstein Amy Rankin Rachel Allbaugh

Canine glaucoma encompasses a diverse group of diseases associated with an increase in intraocular pressure that results in retinal ganglion cell death and eventual blindness. Dogs may have congenital, primary, or secondary glaucoma. The diagnosis is made by recognizing clinical signs, interpreting ophthalmic examination findings, and determining intraocular pressure. Identifying the underlying...

Journal: :Advances in experimental medicine and biology 2006
Sylvain Hanein Isabelle Perrault Sylvie Gerber Hélène Dollfus Jean-Louis Dufier Josué Feingold Arnold Munnich Shomi Bhattacharya Josseline Kaplan José-Alain Sahel Jean-Michel Rozet Thierry Leveillard

Leber congenital amaurosis (LCA) is the most early and severe form of all inherited retinal dystrophies, responsible for congenital blindness. The genetic heterogeneity of LCA has been accepted for a long time but it turned out to be largely higher than all odds. So far, 11genes have been mapped on human chromosomes and eight identified. i) the retinal specific guanylate cyclase gene (GUCY2D, r...

Journal: :Investigative ophthalmology & visual science 2010
Sirichai Pasadhika Gerald A Fishman Edwin M Stone Martin Lindeman Ruth Zelkha Irma Lopez Robert K Koenekoop Mahnaz Shahidi

PURPOSE To evaluate genotypic and macular morphologic correlations in patients with RPE65-, CEP290-, GUCY2D-, or AIPL1-related Leber congenital amaurosis (LCA) using spectral-domain optical coherence tomography (SD-OCT). METHODS SD-OCT macular scans were performed in 21 patients, including 10 with RPE65, 7 with CEP290, 3 with GUCY2D, and 1 with AIPL1 mutations. An image processing software wa...

2014
Sarah Saab Bénédicte Buteau Laurent Leclère Alain M. Bron Catherine P. Creuzot-Garcher Lionel Bretillon Niyazi Acar

OBJECTIVE Proper development of retinal blood vessels is essential to ensure sufficient oxygen and nutrient supplies to the retina. It was shown that polyunsaturated fatty acids (PUFAs) could modulate factors involved in tissue vascularization. A congenital deficiency in ether-phospholipids, also termed "plasmalogens", was shown to lead to abnormal ocular vascularization. Because plasmalogens a...

Journal: :Human molecular genetics 2012
Alejandro Estrada-Cuzcano Ronald Roepman Frans P M Cremers Anneke I den Hollander Dorus A Mans

Homozygosity mapping and exome sequencing have accelerated the discovery of gene mutations and modifier alleles implicated in inherited retinal degeneration in humans. To date, 158 genes have been found to be mutated in individuals with retinal dystrophies. Approximately one-third of the gene defects underlying retinal degeneration affect the structure and/or function of the 'connecting cilium'...

Journal: :JAMA ophthalmology 2014
Shiqiang Li Li Huang Xueshan Xiao Xiaoyun Jia Xiangming Guo Qingjiong Zhang

IMPORTANCE Mutations in CNGA3 are the most common cause of achromatopsia and cone-rod dystrophies. OBJECTIVE To identify CNGA3 mutations in patients with cone dystrophies or Leber congenital amaurosis. DESIGN, SETTING, AND PARTICIPANTS Clinical data and genomic DNA in 267 Chinese probands from 138 families with cone dystrophies and 129 families with Leber congenital amaurosis collected at t...

Journal: :The Journal of pediatrics 2005
Marie L Landry Praveen Mullangi Paul Nee Betty R Klein

Many cases of acute retinal necrosis caused by HSV-2 have been reported in children, teenagers, and young adults as a result of reactivation of congenital or neonatal infections, which may have been subclinical. Pediatricians should be aware of this entity and alert to recurrences that may be delayed by years.

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