نتایج جستجو برای: molar tooth sign

تعداد نتایج: 170795  

2011
Maha S Zaki Shifteh Sattar Rustin A Massoudi Joseph G Gleeson

Disorders within the "ciliopathy" spectrum include Joubert (JS), Bardet-Biedl syndromes (BBS), and nephronophthisis (NPHP). Although mutations in single ciliopathy genes can lead to these different syndromes between families, there have been no reports of phenotypic discordance within a single family. We report on two consanguineous families with discordant ciliopathies in sibling. In Ciliopath...

2014
Shinji Makino Hironobu Tampo

We describe two brothers with Joubert syndrome (JS). JS diagnosis was made on the basis of neurological findings and the presence of the characteristic "molar tooth sign", which was subsequently confirmed by magnetic resonance imaging. Both brothers demonstrated ptosis, hypotropia, exotropia, and horizontal pendular nystagmus. The younger brother had mild chorioretinal discoloration at the peri...

Journal: :American journal of human genetics 2008
Vincent Cantagrel Jennifer L Silhavy Stephanie L Bielas Dominika Swistun Sarah E Marsh Julien Y Bertrand Sophie Audollent Tania Attié-Bitach Kenton R Holden William B Dobyns David Traver Lihadh Al-Gazali Bassam R Ali Tom H Lindner Tamara Caspary Edgar A Otto Friedhelm Hildebrandt Ian A Glass Clare V Logan Colin A Johnson Christopher Bennett Francesco Brancati Enza Maria Valente C Geoffrey Woods Joseph G Gleeson

Joubert syndrome (JS) and related disorders are a group of autosomal-recessive conditions sharing the "molar tooth sign" on axial brain MRI, together with cerebellar vermis hypoplasia, ataxia, and psychomotor delay. JS is suggested to be a disorder of cilia function and is part of a spectrum of disorders involving retinal, renal, digital, oral, hepatic, and cerebral organs. We identified mutati...

2011
Harjinder Gill Brinda Muthusamy Denize Atan Cathy Williams Matthew Ellis

We describe two sisters who presented in early childhood with motor delay and unusual eye movements. Both demonstrated hypotonia and poor visual attention. The older girl at 14 weeks of age showed fine pendular horizontal nystagmus more pronounced on lateral gaze, but despite investigation with cranial MRI no diagnosis was reached. The birth of her younger sister four years later with a similar...

Journal: :JPMA. The Journal of the Pakistan Medical Association 2014
Ekrem Karakas Nesat Cullu Omer Karakas Mustafa Calik Fatima Nurefsan Boyaci Sema Yildiz Hasan Cece Ali Akal

Joubert syndrome is a rare disease characterised by clinical and radiological findings. Among the classic clinical findings of JS are hypotonia, ataxia, mental-motor retardation, respiratory and opthalmological findings. The paediatric cases included in the study comprised nine patients. There was familial consanguinty in seven cases. Clinically, all cases had mental-motor retardation and hypot...

Journal: :American journal of human genetics 2007
Francesco Brancati Giuseppe Barrano Jennifer L Silhavy Sarah E Marsh Lorena Travaglini Stephanie L Bielas Maria Amorini Dominika Zablocka Hulya Kayserili Lihadh Al-Gazali Enrico Bertini Eugen Boltshauser Marc D'Hooghe Elisa Fazzi Elif Y Fenerci Raoul C M Hennekam Andrea Kiss Melissa M Lees Elysa Marco Shubha R Phadke Luciana Rigoli Stephane Romano Carmelo D Salpietro Elliott H Sherr Sabrina Signorini Petter Stromme Bernard Stuart Laszlo Sztriha David H Viskochil Adnan Yuksel Bruno Dallapiccola Enza Maria Valente Joseph G Gleeson

Joubert syndrome-related disorders (JSRDs) are a group of clinically and genetically heterogeneous conditions that share a midbrain-hindbrain malformation, the molar tooth sign (MTS) visible on brain imaging, with variable neurological, ocular, and renal manifestations. Mutations in the CEP290 gene were recently identified in families with the MTS-related neurological features, many of which sh...

2018
Chelsea L Hickey Janet C Sherman Paula Goldenberg Amy Kritzer Paul Caruso Jeremy D Schmahmann Mary K Colvin

Background Joubert syndrome (JS) is a rare, autosomal recessively inherited genetic disorder characterized morphologically by unique developmental malformations of the cerebellum and brainstem (the molar tooth sign), and clinically by impaired motor functions and intellectual disability. Patients with JS often face multiple cognitive challenges, but the neuropsychological profile of this condit...

2014
Richa Arora

BACKGROUND Joubert Syndrome (JS) is a rare autosomal recessive disorder characterised clinically by neonatal breathing dysregulation, developmental delay, intellectual disability, hypotonia, ataxia, nystagmus. CASE REPORT We present another case of this uncommon syndrome in a 12 years old patient presenting with classical complaints of developmental delay, intellectual impairment, weakness in...

Journal: :AJNR. American journal of neuroradiology 2017
F Arrigoni R Romaniello D Peruzzo A De Luca C Parazzini E M Valente R Borgatti F Triulzi

In Joubert syndrome, the "molar tooth" sign can be associated with several additional supra- and infratentorial malformations. Here we report on 3 subjects (2 siblings, 8-14 years of age) with Joubert syndrome, showing an abnormal thick bulging of the anterior profile of the mesencephalon causing a complete obliteration of the interpeduncular fossa. DTI revealed that the abnormal tissue consist...

2013
Aamir Rashid Purra Mubashir Mushtaq Irfan Robbani Riyaz Farooq

The vast majority of mandibular second molars have two roots with three root canals; however, variations in molar root canal anatomy are not uncommon. To the best of our knowledge, four rooted mandibular second molar with three mesial roots and one distal root has never been reported. Herein, we present the endodontic management of a four rooted mandibular second molar tooth, diagnosed with the...

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