نتایج جستجو برای: oculodentodigital dysplasia

تعداد نتایج: 28629  

Journal: :Molecular Genetics & Genomic Medicine 2019

2017
Kye Won Park Ho-Sung Ryu Juyeon Kim Sun Ju Chung

Oculodentodigital dysplasia (ODDD) is a rare autosomal dominant inherited disease caused by mutations of the human gap junction alpha 1 gene, which encodes the protein Connexin-43. Patients with ODDD may present with neurological deficits with a typical pleiotropic combination of characteristic craniofacial, ophthalmological, phalangeal, and dental anomalies. In this report, we describe the fir...

Journal: :Archivos de la Sociedad Espanola de Oftalmologia 2011
P Tejada Y W Eduardo E Gutiérrez A Barceló J Sánchez

CASE REPORT A newborn evaluated at 20 days old due to occasional nystagmus. Her mother had presented with oculodentodigital dysplasia (ODDD) and glaucoma. The physical examination revealed opaque micro-corneas, and horizontal nystagmus. The tonometry showed 35 mm Hg in OD and 40 mm Hg in OS and the fundus examination was normal. She had a narrow nasal bridge with narrow nostrils, and fourth and...

Journal: :The Journal of biological chemistry 2005
Wendi Roscoe Gregory I L Veitch Xiang-Qun Gong Emily Pellegrino Donglin Bai Elizabeth McLachlan Qing Shao Gerald M Kidder Dale W Laird

Oculodentodigital dysplasia, a rare condition displaying congenital craniofacial deformities and limb abnormalities, has been associated with over 20 known human connexin43 (Cx43) mutations. The localization of two of these mutants, G21R and G138R, was examined in Cx43-positive normal rat kidney cells (NRK) and Cx43-negative gap junctional intercellular communication-deficient HeLa cells. Green...

Journal: :Internal medicine 2012
Natsumi Furuta Masaki Ikeda Kimitoshi Hirayanagi Yukio Fujita Makoto Amanuma Koichi Okamoto

Oculodentodigital dysplasia (ODDD) is a rare autosomal dominant inherited disorder mainly affecting the development of the face, eyes, dentition, limbs, hair and heart. GJA1 (the gap junction protein α-1) has been determined to be a causative gene of ODDD, mapped to chromosome 6q22-24 identified as the connexin 43 gene (Cx43). We found a novel GJA1 mutation (W25C) as the possible causative gene...

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