نتایج جستجو برای: hallervorden

تعداد نتایج: 273  

Journal: :The Turkish journal of pediatrics 2009
Hakan Cangül Ozlem Ozdemir Tahsin Yakut Mehmet Okan Neil V Morgan Birol Baytan Manju A Kurian Ronald Spiegel Eamonn R Maher

Here we report the clinical, neuroimaging, and molecular findings of a classic pantothenate kinase-associated neurodegeneration (PKAN) patient of Turkish origin. Our patient is the first reported case of PKAN in Turkey with molecular genetic confirmation of the diagnosis. The frameshift mutation c.821_822delCT of the PANK2 gene detected in our patient has only been described in such classic pat...

2013
Chih-Hong Lee Chin-Song Lu Wen-Li Chuang Tu-Hsueh Yeh Shih-Ming Jung Chia-Ling Huang Szu-Chia Lai

OBJECTIVES Pantothenate kinase-associated neurodegeneration (PKAN) is a rare disease caused by pantothenate kinase 2 (PANK2, OMIM 606157) mutations. This study is aimed to investigate clinical presentations, pathologies, and genetics in patients with PKAN. METHODS Two patients with PKAN were reported. We reviewed the literature to include additional 19 patients with PKAN in Eastern Asia. Thes...

Journal: :The Journal of neuroscience : the official journal of the Society for Neuroscience 2011
Julien Dusonchet Olexiy Kochubey Klodjan Stafa Samuel M Young Romain Zufferey Darren J Moore Bernard L Schneider Patrick Aebischer

The G2019S mutation in the leucine-rich repeat kinase 2 (LRRK2) gene is the most common genetic cause of Parkinson's disease (PD), accounting for a significant proportion of both autosomal dominant familial and sporadic PD cases. Our aim in the present study is to generate a mammalian model of mutant G2019S LRRK2 pathogenesis, which reproduces the robust nigral neurodegeneration characteristic ...

2016
Anamika Giri Gamze Guven Hasmet Hanagasi Ann-Kathrin Hauser Nihan Erginul-Unaltuna Basar Bilgic Hakan Gurvit Peter Heutink Thomas Gasser Ebba Lohmann Javier Simón-Sánchez

BACKGROUND PLA2G6-associated neurodegeneration (PLAN) is a recessive neurodegenerative disorder characterized by three distinct phenotypes: infantile neuroaxonal dystrophy (INAD), atypical neuroaxonal dystrophy (atypical NAD), and PLA2G6-related dystonia-parkinsonism. METHODS A consanguineous index case from Turkey was diagnosed with early-onset Parkinsonism at the Istanbul Faculty of Medicin...

2016
Jae-Hyeok Lee Jongkyu Park Ho-Sung Ryu Hyeyoung Park Young Eun Kim Jin Yong Hong Sang Ook Nam Young-Hee Sung Seung-Hwan Lee Jee-Young Lee Myung Jun Lee Tae-Hyoung Kim Chul Hyoung Lyoo Sun Ju Chung Seong Beom Koh Phil Hyu Lee Jin Whan Cho Mee Young Park Yun Joong Kim Young H. Sohn Beom Seok Jeon Myung Sik Lee

OBJECTIVE Neurodegeneration with brain iron accumulation (NBIA) represents a group of inherited movement disorders characterized by iron accumulation in the basal ganglia. Recent advances have included the identification of new causative genes and highlighted the wide phenotypic variation between and within the specific NBIA subtypes. This study aimed to investigate the current status of NBIA i...

2016
Francesca Magrinelli Alessandro Picelli Pierluigi Tocco Angela Federico Laura Roncari Nicola Smania Giampietro Zanette Stefano Tamburin

Cardinal motor features of Parkinson's disease (PD) include bradykinesia, rest tremor, and rigidity, which appear in the early stages of the disease and largely depend on dopaminergic nigrostriatal denervation. Intermediate and advanced PD stages are characterized by motor fluctuations and dyskinesia, which depend on complex mechanisms secondary to severe nigrostriatal loss and to the problems ...

Journal: :BMJ case reports 2011
Claudio Crisci Marcello Esposito

1 of 1 DESCRIPTION Our patient is a girl with pantothenate kinase associated neurodegeneration 1 and autosomal recessive transmission. She has marked contractions of the lower facial muscles and severe contraction of calf muscles, with both feet in a crooked position, more evident on the right side. Since infancy, she walked abnormally and was unstable when standing, due to progressive hyperton...

Journal: :European journal of neurology 2015
M Romani I Kraoua A Micalizzi H Klaa H Benrhouma C Drissi I Turki S Castellana T Mazza E M Valente N Gouider-Khouja

BACKGROUND AND PURPOSE Mutations in the PLA2G6 gene are causative of PLA2G6-associated neurodegeneration (PLAN), a spectrum of neurodegenerative conditions including infantile, childhood and adult onset forms. METHODS Seventeen North African patients with a clinical suspicion of infantile-onset PLAN underwent clinical, neurophysiological and neuroimaging examinations, and PLA2G6 sequencing. H...

2015
Jasmin Schiessl-Weyer Pedro Roa Franco Laccone Britta Kluge Alexander Tichy Euripedes De Almeida Ribeiro Rainer Prohaska Peter Stoeter Claudia Siegl Ulrich Salzer

Pantothenate Kinase-Associated Neurodegeneration (PKAN) is a form of Neurodegeneration with Brain Iron Accumulation (NBIA) associated with mutations in the pantothenate kinase 2 gene (PANK2). Pantothenate kinases catalyze the rate-limiting step of coenzyme A synthesis and Pank2 is the only pantothenate kinase isoform in humans that is localized to mitochondria. Acanthocytosis, the occurrence of...

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