نتایج جستجو برای: ocular coloboma

تعداد نتایج: 56254  

Journal: :Journal of medical genetics 1975
C K Ho R L Kaufman S M Podos

An association of ocular colobomata and congenital heart disease was observed in seven patients. Two of these were maternal half sisters whose mother also had ocular colobomata. All the patients had normal karyotypes. There was a high incidence of other associated abnormalities involving the central nervous, skeletal, and urogenital systems. Discovery of an ocular coloboma should alert the clin...

2014
Daniel Kelberman Lily Islam Jörn Lakowski Chiara Bacchelli Estelle Chanudet Francesco Lescai Aara Patel Elia Stupka Anja Buck Stephan Wolf Philip L. Beales Thomas S. Jacques Maria Bitner-Glindzicz Alki Liasis Ordan J. Lehmann Jürgen Kohlhase Ken K. Nischal Jane C. Sowden

Ocular coloboma is a congenital defect resulting from failure of normal closure of the optic fissure during embryonic eye development. This birth defect causes childhood blindness worldwide, yet the genetic etiology is poorly understood. Here, we identified a novel homozygous mutation in the SALL2 gene in members of a consanguineous family affected with non-syndromic ocular coloboma variably af...

Journal: :Journal of the Chinese Medical Association : JCMA 2004
Kuo-Fang Hsueh Chang-Sue Yang Jen-Her Lu Wen-Ming Hsu

CHARGE syndrome is a specific collection of non-randomly occurring congenital anomalies. The patient of CHARGE syndrome may be presented to ophthalmologists due to ocular coloboma. The acronym CHARGE stands for the major features of this syndrome: Coloboma of the eye, Heart defects, Atresia of the choanae, Retarded growth and development, Genital hypoplasia, and Ear anomalies and/or deafness. T...

Journal: :Archives of Disease in Childhood 1991

Journal: :Development 2013
Zhigang Cai Chenqi Tao Hongge Li Raj Ladher Noriko Gotoh Gen-Sheng Feng Fen Wang Xin Zhang

FGF signaling plays a pivotal role in eye development. Previous studies using in vitro chick models and systemic zebrafish mutants have suggested that FGF signaling is required for the patterning and specification of the optic vesicle, but due to a lack of genetic models, its role in mammalian retinal development remains elusive. In this study, we show that specific deletion of Fgfr1 and Fgfr2 ...

Journal: :JAMA ophthalmology 2013
Simon E Skalicky Andrew J R White John R Grigg Frank Martin Jeremy Smith Michael Jones Craig Donaldson James E H Smith Maree Flaherty Robyn V Jamieson

IMPORTANCE Microphthalmia, anophthalmia, and coloboma form an interrelated spectrum of congenital eye abnormalities. OBJECTIVE To document the ocular and systemic findings and inheritance patterns in patients with microphthalmia, anophthalmia, and coloboma disease to gain insight into the underlying developmental etiologies. DESIGN, SETTING, AND PARTICIPANTS This retrospective consecutive c...

Journal: :Investigative ophthalmology & visual science 2015
Vincent D Venincasa Yasha S Modi Hassan A Aziz Bernadette Ayres Claus Zehetner Wei Shi Timothy G Murray Harry W Flynn Audina M Berrocal

PURPOSE We reported the clinical and echographic features of colobomas, prevalence of retinal detachment, and associated visual acuity in these patients. METHODS The study is a nonrandomized consecutive case series of 140 colobomatous eyes in 98 patients (age range, 0-83 years). Coloboma depth, width, volume, and relative coloboma excavation (coloboma depth/axial length) were measured using s...

2003
S J Hornby L Dandona R B Jones H Stewart C E Gilbert

Aims: To identify the proportion of familial cases of isolated ocular colobomatous malformations in a case series from south India. Methods: Children with ocular coloboma without systemic features were recruited from multiple sources in Andhra Pradesh, India. Their families were traced, pedigrees drawn, and family members examined. Results: 56 probands, 25 females (44.6%) and 31 males (57.4%) w...

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