نتایج جستجو برای: spastic paraplegia 18

تعداد نتایج: 361983  

Journal: :Brain & development 2010
Carlo Fusco Daniele Frattini Enrico Farnetti Davide Nicoli Bruno Casali Francesco Fiorentino Andrea Nuccitelli Elvio Della Giustina

Mutations in the SPG3A gene (atlastin protein) cause approximately 10% of autosomal-dominant hereditary spastic paraplegia. Most patients with an SPG3A mutation present with a pure phenotype and early-onset disease, although complicated forms with peripheral neuropathy are also reported. We report a new heterozygous S398F mutation in exon 12 of the SPG3A gene causing a very early-onset spastic ...

2016
Eleanna Kara Arianna Tucci Claudia Manzoni David S. Lynch Marilena Elpidorou Conceicao Bettencourt Viorica Chelban Andreea Manole Sherifa A. Hamed Nourelhoda A. Haridy Monica Federoff Elisavet Preza Deborah Hughes Alan Pittman Zane Jaunmuktane Sebastian Brandner Georgia Xiromerisiou Sarah Wiethoff Lucia Schottlaender Christos Proukakis Huw Morris Tom Warner Kailash P. Bhatia L.V. Prasad Korlipara Andrew B. Singleton John Hardy Nicholas W. Wood Patrick A. Lewis Henry Houlden

The hereditary spastic paraplegias are a heterogeneous group of degenerative disorders that are clinically classified as either pure with predominant lower limb spasticity, or complex where spastic paraplegia is complicated with additional neurological features, and are inherited in autosomal dominant, autosomal recessive or X-linked patterns. Genetic defects have been identified in over 40 dif...

2011
Sanjeev Rajakulendran Coro Paisán-Ruiz Henry Houlden

BACKGROUND Mutations in the spatacsin gene are associated with spastic paraplegia type 11 (SPG11), which is the most-common cause of autosomal recessive hereditary spastic paraplegia. Although SPG11 has diverse phenotypes, thinning of the corpus callosum is an important feature. CASE REPORT Clinical, genetic, and radiological evaluations were undertaken in a large family from Gujarat in North...

2013
Ji Seon Kim Jong Min Kim Yu Kyeong Kim Sang Eun Kim Ji Young Yun Beom S. Jeon

Sporadic spastic paraplegia (SSP) and hereditary spastic paraplegia (HSP) belong to a clinical and genetically heterogeneous group of disorders characterized by progressive spasticity and weakness in the lower extremities. The symptoms are associated with pyramidal tract dysfunction and degeneration of the corticospinal tracts. Parkinsonism is uncommon in SSP/HSP patients. However, both disorde...

2014
Filipa Flor-de-Lima Mafalda Sampaio Nahid Nahavandi Susana Fernandes Miguel Leão

Mutations in the ALS2 gene cause three distinct disorders: infantile ascending hereditary spastic paraplegia, juvenile primary lateral sclerosis, and autosomal recessive juvenile amyotrophic lateral sclerosis. We present a review of the literature and the case of a 16-year-old boy who is, to the best of our knowledge, the first Portuguese case with infantile ascending hereditary spastic paraple...

2013
Hao Zhang Yong-Chun Song Cheng-Xue Dang

BACKGROUND Analysis of aberrant hypermethylation in stool DNA might provide a novel strategy for noninvasive detection of colorectal cancer. AIMS To explore the feasibility of detecting hypermethylation in Spastic paraplegia-20 promoter as a stool-based DNA marker for detection of colorectal cancer. METHODS We collected 96 tissue and stool samples from patients with colorectal cancer and 30...

2015
YANMIN SONG YUNHAI LIU NING ZHANG LILI LONG

The aim of the present study was to conduct a familial investigation and provide a genetic diagnosis to a family presenting with spastic paraplegia and clinically diagnosed with hereditary spastic paraplegia (HSP). Blood samples were obtained from the family, and mutations in the gene causing spinocerebellar ataxia type 3 (SCA3)/Machado-Joseph disease (MJD), known as MJD1, were analyzed using t...

Journal: :Experimental Neurology 2014
Temistocle Lo Giudice Federica Lombardi Filippo Maria Santorelli Toshitaka Kawarai Antonio Orlacchio

Hereditary spastic paraplegia (HSP) is a group of clinically and genetically heterogeneous neurological disorders characterized by pathophysiologic hallmark of length-dependent distal axonal degeneration of the corticospinal tracts. The prominent features of this pathological condition are progressive spasticity and weakness of the lower limbs. To date, 72 spastic gait disease-loci and 55 spast...

Journal: :Journal of neurology, neurosurgery, and psychiatry 1983
R R Tuck B P O'Neill H Gharib D W Mulder

A sibship is reported in which two males have spastic paraparesis and Kallmann's syndrome (hypogonadotrophic hypogonadism and anosmia). One of the brothers also is color blind. The association of familial spastic paraplegia and Kallmann's syndrome has not been described previously.

Journal: :Archives of neurology 2007
Neviana Ivanova Kristl G Claeys Tine Deconinck Ivan Litvinenko Albena Jordanova Michaela Auer-Grumbach Jana Haberlova Ann Löfgren Gisele Smeyers Eva Nelis Rudy Mercelis Barbara Plecko Josef Priller Josef Zámecník Berten Ceulemans Anne Kjersti Erichsen Erik Björck Garth Nicholson Michael W Sereda Pavel Seeman Ivo Kremensky Vanio Mitev Peter De Jonghe

OBJECTIVE To study the frequency and distribution of mutations in SPG3A in a large cohort of patients with hereditary spastic paraplegia. DESIGN We screened a large cohort of 182 families and isolated cases with pure or complex hereditary spastic paraplegia phenotypes, which were negative for mutations in SPG4. RESULTS In 12 probands (6.6%), we identified 12 different SPG3A mutations (11 mi...

نمودار تعداد نتایج جستجو در هر سال

با کلیک روی نمودار نتایج را به سال انتشار فیلتر کنید