نتایج جستجو برای: clinical exome sequencing

تعداد نتایج: 1271061  

2014
Elizabeth G. Phimister Leslie G. Biesecker

From the National Human Genome Research Institute, National Institutes of Health, Bethesda, MD (L.G.B.); and the Division of Genetics, Department of Medicine, Brigham and Women’s Hospital and Harvard Medical School, and Partners Healthcare Personalized Medicine — all in Boston (R.C.G.). Address reprint requests to Dr. Biesecker at 49 Convent Dr., Rm. 4A56, Bethesda, MD 20892-4472, or at lesb@ma...

Journal: :American Journal of Medical Genetics Part A 2013

2018
Karen L Stals Matthew Wakeling Júlia Baptista Richard Caswell Andrew Parrish Julia Rankin Carolyn Tysoe Garan Jones Adam C Gunning Hana Lango Allen Lisa Bradley Angela F Brady Helena Carley Jenny Carmichael Bruce Castle Deirdre Cilliers Helen Cox Charu Deshpande Abhijit Dixit Jacqueline Eason Frances Elmslie Andrew E Fry Alan Fryer Muriel Holder Tessa Homfray Emma Kivuva Victoria McKay Ruth Newbury-Ecob Michael Parker Ravi Savarirayan Claire Searle Nora Shannon Deborah Shears Sarah Smithson Ellen Thomas Peter D Turnpenny Vinod Varghese Pradeep Vasudevan Emma Wakeling Emma L Baple Sian Ellard

OBJECTIVE Rare genetic disorders resulting in prenatal or neonatal death are genetically heterogeneous, but testing is often limited by the availability of fetal DNA, leaving couples without a potential prenatal test for future pregnancies. We describe our novel strategy of exome sequencing parental DNA samples to diagnose recessive monogenic disorders in an audit of the first 50 couples referr...

2017
David S. Lynch Anderson Rodrigues Brandão de Paiva Wei Jia Zhang Enrico Bugiardini Fernando Freua Leandro Tavares Lucato Lucia Inês Macedo-Souza Rahul Lakshmanan Justin A. Kinsella Aine Merwick Alexander M. Rossor Nin Bajaj Brian Herron Paul McMonagle Patrick J. Morrison Deborah Hughes Alan Pittman Matilde Laurà Mary M Reilly Jason D Warren Catherine J Mummery Jonathan M. Schott Matthew Adams Nick C. Fox Elaine Murphy Indran Davagnanam Fernando Kok Jeremy Chataway Henry Houlden

Leukodystrophies and genetic leukoencephalopathies are a rare group of disorders leading to progressive degeneration of cerebral white matter. They are associated with a spectrum of clinical phenotypes dominated by dementia, psychiatric changes, movement disorders and upper motor neuron signs. Mutations in at least 60 genes can lead to leukoencephalopathy with often overlapping clinical and rad...

2013
Zuoheng Wang Xiangtao Liu Bao-Zhu Yang Joel Gelernter

Recent advances in next-generation sequencing technologies have transformed the genetics study of human diseases; this is an era of unprecedented productivity. Exome sequencing, the targeted sequencing of the protein-coding portion of the human genome, has been shown to be a powerful and cost-effective method for detection of disease variants underlying Mendelian disorders. Increasing effort ha...

Journal: :The New England journal of medicine 2013
Yaping Yang Donna M Muzny Jeffrey G Reid Matthew N Bainbridge Alecia Willis Patricia A Ward Alicia Braxton Joke Beuten Fan Xia Zhiyv Niu Matthew Hardison Richard Person Mir Reza Bekheirnia Magalie S Leduc Amelia Kirby Peter Pham Jennifer Scull Min Wang Yan Ding Sharon E Plon James R Lupski Arthur L Beaudet Richard A Gibbs Christine M Eng

BACKGROUND Whole-exome sequencing is a diagnostic approach for the identification of molecular defects in patients with suspected genetic disorders. METHODS We developed technical, bioinformatic, interpretive, and validation pipelines for whole-exome sequencing in a certified clinical laboratory to identify sequence variants underlying disease phenotypes in patients. RESULTS We present data...

2013
Reuben J Pengelly Jane Gibson Gaia Andreoletti Christopher J Mattocks Andrew Collins Sarah Ennis

Whole-exome sequencing provides a cost-effective means to sequence protein coding regions within the genome, which are significantly enriched for etiological variants. We describe a panel of single nucleotide polymorphisms (SNPs) to facilitate the validation of data provenance in whole-exome sequencing studies. This is particularly significant where multiple processing steps necessitate transfe...

2017
Erica D. Smith Kelly Radtke Mari Rossi Deepali N. Shinde Sourat Darabi Dima El‐Khechen Zöe Powis Katherine Helbig Kendra Waller Dorothy K. Grange Sha Tang Kelly D. Farwell Hagman

Ascertaining a diagnosis through exome sequencing can provide potential benefits to patients, insurance companies, and the healthcare system. Yet, as diagnostic sequencing is increasingly employed, vast amounts of human genetic data are produced that need careful curation. We discuss methods for accurately assessing the clinical validity of gene-disease relationships to interpret new research f...

2016
Jonatan Halvardson Jin J Zhao Ammar Zaghlool Christian Wentzel Patrik Georgii-Hemming Else Månsson Helena Ederth Sävmarker Göran Brandberg Cecilia Soussi Zander Ann-Charlotte Thuresson Lars Feuk

BACKGROUND De novo mutations are a frequent cause of disorders related to brain development. We report the results of screening patients diagnosed with both epilepsy and intellectual disability (ID) using exome sequencing to identify known and new causative de novo mutations relevant to these conditions. METHODS Exome sequencing was performed on 39 patient-parent trios to identify de novo mut...

2014
Ga Won Jeon Mi-Na Lee Ji Mi Jung Seong Yeon Hong Young Nam Kim Jong Beom Sin Chang-Seok Ki

BACKGROUND Atelosteogenesis type I (AO-I) is a rare lethal skeletal dysplastic disorder characterized by severe short-limbed dwarfism and dislocated hips, knees, and elbows. AO-I is caused by mutations in the filamin B (FLNB) gene; however, several other genes can cause AO-like lethal skeletal dysplasias. METHODS In order to screen all possible genes associated with AO-like lethal skeletal dy...

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