نتایج جستجو برای: harlequin ichthyosis

تعداد نتایج: 2442  

Journal: :Ultrasound in Obstetrics and Gynecology 2007

Journal: :International Journal of Ayurveda and Pharma Research 2023

Ichthyosis are a heterogeneous group of Hereditary and acquired disorders keratinization characterized by the presence visible scales on skin surface. The word is derived from Greek root for fish – icthys. There two major types ichthyosis that Congenital Acquired. vulgaris one among congenital most common with an estimated incidence rate 1 in 250 births, onset early childhood fine, whitish whic...

2011
Masashi Akiyama

ABCA12 is a member of the large superfamily of ATP-binding cassette (ABC) transporters, which bind and hydrolyze ATP to transport various molecules across limiting membranes or into vesicles. The ABCA subfamily members are thought to be lipid transporters. ABCA12 is a keratinocyte transmembrane lipid transporter protein associated with the transport of lipids in lamellar granules to the apical ...

2010
Agneta Gånemo

Congenital ichthyosis encompasses a large group of keratinizing disorders with widespread scaling and a variable degree of erythema. Little is known about the quality of life in children with congenital ichthyosis and the impact of the disease on their family. Fifteen children aged 5-16 years with lamellar ichthyosis, Netherton's syndrome, epidermolytic hyperkeratosis or Harlequin ichthyosis, w...

Journal: :International Journal of Reproduction, Contraception, Obstetrics and Gynecology 2015

Journal: :Archives of Hand and Microsurgery 2018

2016
Lei Zhang Michael Ferreyros Weiguo Feng Melanie Hupe Debra A Crumrine Jiang Chen Peter M Elias Walter M Holleran Lee Niswander Daniel Hohl Trevor Williams Enrique C Torchia Dennis R Roop

Harlequin Ichthyosis is a severe skin disease caused by mutations in the human gene encoding ABCA12. Here, we characterize a novel mutation in intron 29 of the mouse Abca12 gene that leads to the loss of a 5' splice donor site and truncation of the Abca12 RNA transcript. Homozygous mutants of this smooth skin or smsk allele die perinatally with shiny translucent skin, typical of animal models o...

Journal: :East African medical journal 2010
A N Migowa C W Murungi B W Gatinu J Mbithe E Kimani P Okiro F S Rana R Ochieng R Nduati

Severe congenital skin abnormalities are a rare event. This case is unique in that it is a case of harlequin ichthyosis in sub-sahara Africa in a child of African origin and elaborates the challenges faced in its management. We present a neonate who was managed for this condition at Chogoria Mission Hospital. In presenting this case, we aim to sensitise healthcare providers to promptly recognis...

Journal: :Dhaka Shishu (Children) Hospital Journal 2020

Journal: :Journal of Investigative Dermatology 2022

The ABCA12 gene encodes an ATP-binding cassette transporter vital to skin barrier function. In keratinocytes, transports ceramides into the lumen of lamellar bodies as part widely conserved water system. Alterations in are associated with autosomal recessive congenital ichthyoses: harlequin ichthyosis, non-bullous ichthyosiform erythroderma, and ichthyosis. We report a 4-month-old female who pr...

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