نتایج جستجو برای: maroteaux

تعداد نتایج: 191  

Journal: :Journal of medical genetics 2000
L Faivre M Le Merrer A Megarbane B Gilbert G Mortier V Cusin A Munnich P Maroteaux V Cormier-Daire

Acromesomelic dysplasia Maroteaux type (AMDM) is an autosomal recessive disorder belonging to the group of acromesomelic dysplasias. AMDM is characterised by severe dwarfism with shortening of the middle and distal segments of the limbs. An AMDM gene has recently been mapped to human chromosome 9p13-q12 by homozygosity mapping in four consanguineous families. Here, we show linkage of the diseas...

Journal: :Pediatrics 2007
Roberto Giugliani Paul Harmatz James E Wraith

Mucopolysaccharidosis VI (Maroteaux-Lamy syndrome) is a lysosomal storage disease that is characterized by systemic clinical manifestations and significant functional impairment. Diagnosis and management are often challenging because of the considerable variability in symptom presentation and rate of progression. The optimal standard of care should be based on evidence from randomized, controll...

2013
Anuj Bahl Farouk Olubajo Daniel J Connolly Chris D Rittey Neil Rogers Nick Bishop Saurabh Sinha

Introduction Pycnodysostosis (PDO) is a rare autosomal recessive lysosomal storage disease of the bone caused by a mutation in a gene mapped to chromosome 1q21 that codes for the enzyme cathepsin K (CTSK). Pycnodysostosis (Greek: pycnos = dense; dys = defective; osteon = bone) was first coined in 1962 by Maroteaux and Lamy [1], although the first case fitting the description may have been repor...

2015
Marta Gómez-Grau Elena Garrido Mónica Cozar Víctor Rodriguez-Sureda Carmen Domínguez Concepción Arenas Richard A. Gatti Bru Cormand Daniel Grinberg Lluïsa Vilageliu Andrea Dardis

Nonsense mutations are quite prevalent in inherited diseases. Readthrough drugs could provide a therapeutic option for any disease caused by this type of mutation. Geneticin (G418) and gentamicin were among the first to be described. Novel compounds have been generated, but only a few have shown improved results. PTC124 is the only compound to have reached clinical trials. Here we first investi...

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