نتایج جستجو برای: meleda disease

تعداد نتایج: 1490125  

2015
Sabine Duchatelet Alain Hovnanian

Olmsted syndrome (OS) is a rare genodermatosis classically characterized by the combination of bilateral mutilating transgredient palmoplantar keratoderma (PPK) and periorificial keratotic plaques, but which shows considerable clinical heterogeneity. The disease starts usually at birth or in early childhood. About 73 cases have been reported worldwide. OS is observed in both sexes, although mal...

2014
Oludotun Adeyo Bernard B. Allan Richard H. Barnes Chris N. Goulbourne Angelica Tatar Yiping Tu Lorraine C. Young Michael Weinstein Peter Tontonoz Loren G. Fong Anne P. Beigneux Stephen G. Young

Mutations in SLURP1 cause mal de Meleda, a rare palmoplantar keratoderma (PPK). SLURP1 is a secreted protein that is expressed highly in keratinocytes but has also been identified elsewhere (e.g., spinal cord neurons). Here, we examined Slurp1-deficient mice (Slurp1(-/-)) created by replacing exon 2 with β-gal and neo cassettes. Slurp1(-/-) mice developed severe PPK characterized by increased k...

Journal: :Human molecular genetics 2001
J Fischer B Bouadjar R Heilig M Huber C Lefèvre F Jobard F Macari A Bakija-Konsuo F Ait-Belkacem J Weissenbach M Lathrop D Hohl J F Prud'homme

Mal de Meleda (MDM) is a rare autosomal recessive skin disorder, characterized by transgressive palmoplantar keratoderma (PPK), keratotic skin lesions, perioral erythema, brachydactyly and nail abnormalities. We report the refinement of our previously described interval of MDM on chromosome 8qter, and the identification of mutations in affected individuals in the ARS (component B) gene, encodin...

2016
Jia Zhang Guolong Zhang Cheng Ni Ruhong Cheng Jianying Liang Ming Li Zhirong Yao

Nagashima-type palmoplantar keratosis (NPPK) is an autosomal recessive form of palmoplantar keratoderma (PPK), which is caused by mutations in the SERPINB7 gene. NPPK has only been reported in Japanese and Chinese populations. The present study was conducted on 12 unrelated Chinese patients who were clinically predicted to suffer from NPPK. Mutation screening was performed by direct sequencing ...

پایان نامه :دانشگاه آزاد اسلامی - دانشگاه آزاد اسلامی واحد تهران (پزشکی) - دانشکده پزشکی 1388

چکیده ندارد.

2011
Kristiaan Lenos Aart G. Jochemsen

The MDM family proteins MDM2 and MDMX are two critical regulators of the p53 tumor suppressor protein. Expression of both proteins is necessary for allowing the embryonal development by keeping the activity of p53 in check. Upon stresses that need to activate p53 to perform its function as guardian of the genome, p53 has to be liberated from these two inhibitors. In this review, we will discuss...

2014
Benson J. Edagwa Dongwei Guo Pavan Puligujja Han Chen JoEllyn McMillan Xinming Liu Howard E. Gendelman Prabagaran Narayanasamy

Eradication of Mycobacterium tuberculosis (MTB) infection requires daily administration of combinations of rifampin (RIF), isoniazid [isonicotinylhydrazine (INH)], pyrazinamide, and ethambutol, among other drug therapies. To facilitate and optimize MTB therapeutic selections, a mononuclear phagocyte (MP; monocyte, macrophage, and dendritic cell)-targeted drug delivery strategy was developed. Lo...

2010
Christina Priest Carol Prives Masha V. Poyurovsky

Mdm2, a central negative regulator of the p53 tumor suppressor, possesses a Really Interesting New Gene (RING) domain within its C-terminus. In addition to E3 ubiquitin ligase activity, the Mdm2 RING preferentially binds adenine base nucleotides, and such binding leads to a conformational change in the Mdm2 C-terminus. Here, we present further biochemical analysis of the nucleotide-Mdm2 interac...

پایان نامه :دانشگاه آزاد اسلامی - دانشگاه آزاد اسلامی واحد گرمسار - دانشکده دامپزشکی 1391

after test and review results and analysis of farm data, the following results were obtained. the review examined farms was done and the results obtained in this study was to determine the effectiveness of vaccines hatchpak avinew (frozen) and hatchpak ib h120 with spray in broilers a day in factories incubation and at least,they can be as vaccines avinew and bioral h120 ability to create saf...

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