نتایج جستجو برای: mucolipidosis

تعداد نتایج: 464  

1994
David H. Wolpert

The evidence procedure for setting hyperparameters is essentially the same as the techniques of ML II and generalized maximumlikelihood Unlike those older techniques however the evidence procedure has been justi ed and used as an approximation to the hierarchical Bayesian calculation We use several examples to explore the validity of this justi cation Then we derive upper and often large lower ...

Journal: :Proceedings of the National Academy of Sciences 1999

2005
Stephan Tiede Nicole Muschol Gert Reutter Michael Cantz Kurt Ullrich Thomas Braulke

Rapid Publication Missense Mutations in N-Acetylglucosamine-1Phosphotransferase a/b Subunit Gene in a Patient With Mucolipidosis III and a Mild Clinical Phenotype Stephan Tiede, Nicole Muschol, Gert Reutter, Michael Cantz, Kurt Ullrich, and Thomas Braulke* Department of Biochemistry, Children’s Hospital, University Hospital Hamburg Eppendorf, Hamburg, Germany Department of Rheumatology, Childre...

Journal: :Archives of ophthalmology 2008
Rohit S Adyanthaya Howard S Ying James T Handa Michael X Repka

symmetric changes, and lack of symptoms, we suspected a metabolic storage disorder. Laboratory test results showed normal levels of -galactosidase, arylsulfatase A, hexosaminidase A and B, and -galactocerebrosidase.However, sialic acid levelswere elevated in the urine. Examination results of a skin biopsy specimen revealed a fibroblast -neuraminidase level of 0.5 nmoles/h per milligram of prote...

Journal: :Proceedings of the National Academy of Sciences of the United States of America 1998
R Schiffmann N K Dwyer I A Lubensky M Tsokos V E Sutliff J S Latimer K P Frei R O Brady N W Barton E J Blanchette-Mackie E Goldin

Mucolipidosis type IV is an autosomal recessive lysosomal storage disease of unknown etiology that causes severe neurological and ophthalmological abnormalities. In an attempt to obtain insight into the nature of the metabolic abnormality in this disorder, we prospectively evaluated 15 consecutive patients, aged 2 to 23 years, over a period of 22 months. The finding of iron deficiency in some o...

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