نتایج جستجو برای: myofibrillar myopathy

تعداد نتایج: 14255  

Journal: :Circulation 1990
A Keren S Gottlieb D Tzivoni S Stern R Yarom M E Billingham R L Popp

Prognosis in classically described dilated congestive cardiomyopathy has been reported to be related to ventricular size. Mildly dilated congestive cardiomyopathy (MDCM) has been defined as end-stage heart failure of unknown etiology (New York Heart Association class IV, left ventricular ejection fraction less than 30%), occurring with neither typical hemodynamic signs of restrictive myopathy n...

Journal: :Brain : a journal of neurology 2004
Duygu Selcen Kinji Ohno Andrew G Engel

The term myofibrillar myopathy (MFM) was proposed in 1996 as a non-committal term for a pathological pattern of myofibrillar dissolution associated with accumulation of myofibrillar degradation products and ectopic expression of multiple proteins that include desmin, alphaB-crystallin (alphaBC), dystrophin and congophilic amyloid material. Subsequent studies revealed dominant mutations in desmi...

Journal: :Muscle & nerve 2009
Mohammad Salajegheh Jack L Pinkus J Paul Taylor Anthony A Amato Remedios Nazareno Robert H Baloh Steven A Greenberg

The nucleic acid binding protein TDP-43 was recently identified in normal myonuclei and in the sarcoplasm of inclusion body myositis (IBM) muscle. Here we found TDP-43 sarcoplasmic immunoreactivity in 23% of IBM myofibers, while other reported IBM biomarkers were less frequent, with rimmed vacuoles in 2.8%, fluorescent Congo red material in 0.57%, SMI-31 immunoreactivity in 0.83%, and focal R12...

2012
Teet Seene Priit Kaasik

Changes in skeletal muscle quantity and quality lead to disability in the aging population. Physiological changes in aging skeletal muscle are associated with a decline in mass, strength, and inability to maintain balance. Glucocorticoids, which are in wide exploitation in various clinical scenarios, lead to the loss of the myofibrillar apparatus, changes in the extracellular matrix, and a decr...

Journal: :Orphanet journal of rare diseases 2014
Anna-Lena Semmler Sabrina Sacconi J Elisa Bach Claus Liebe Jan Bürmann Rudolf A Kley Andreas Ferbert Roland Anderheiden Peter Van den Bergh Jean-Jacques Martin Peter De Jonghe Eva Neuen-Jacob Oliver Müller Marcus Deschauer Markus Bergmann J Michael Schröder Matthias Vorgerd Jörg B Schulz Joachim Weis Wolfram Kress Kristl G Claeys

BACKGROUND Myofibrillar myopathies (MFM) are a group of phenotypically and genetically heterogeneous neuromuscular disorders, which are characterized by protein aggregations in muscle fibres and can be associated with multisystemic involvement. METHODS We screened a large cohort of 38 index patients with MFM for mutations in the nine thus far known causative genes using Sanger and next genera...

2004
Céline F. Costa Heidi Rommelaere Davy Waterschoot Kamaljit K. Sethi Kristen J. Nowak Nigel G. Laing Christophe Ampe Laura M. Machesky

Congenital myopathies resulting from mutations in the gene encoding α-skeletal-muscle actin, ACTA1, show various phenotypes that have been divided into three classes based on the morphology observed in patient muscle biopsies (Sparrow et al., 2003). These myopathies have a range of severity, from mild (with long-term survival and only minor muscle weakness), to severe (with lethality shortly af...

Journal: :Chemical communications 2016
B Bonsch V Belt C Bartel N Duensing M Koziol C M Lazarus A M Bailey T J Simpson R J Cox

A gene cluster responsible for the biosynthesis of squalestatin S1 (SQS1, 1) was identified by full genome sequencing of two SQS1-producing ascomycetes: Phoma sp. C2932 and unidentified fungus MF5453. A transformation protocol was established and a subsequent knockout of one PKS gene from the cluster led to loss of SQS1 production and enhanced concentration of an SQS1 precursor. An acyltransfer...

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