نتایج جستجو برای: neurofibromatosis nf2

تعداد نتایج: 7346  

Journal: :Genes & development 1999
M Giovannini E Robanus-Maandag M Niwa-Kawakita M van der Valk J M Woodruff L Goutebroze P Mérel A Berns G Thomas

Specific mutations in some tumor suppressor genes such as p53 can act in a dominant fashion. We tested whether this mechanism may also apply for the neurofibromatosis type-2 gene (NF2) which, when mutated, leads to schwannoma development. Transgenic mice were generated that express, in Schwann cells, mutant NF2 proteins prototypic of natural mutants observed in humans. Mice expressing a NF2 pro...

Journal: :Neuro-oncology 2014
Marco Giovannini Nicolas-Xavier Bonne Jeremie Vitte Fabrice Chareyre Karo Tanaka Rocky Adams Laurel M Fisher Laurence Valeyrie-Allanore Pierre Wolkenstein Stephane Goutagny Michel Kalamarides

BACKGROUND Neurofibromatosis type 2 (NF2) is a rare autosomal dominant genetic disorder, resulting in a variety of neural tumors, with bilateral vestibular schwannomas as the most frequent manifestation. Recently, merlin, the NF2 tumor suppressor, has been identified as a novel negative regulator of mammalian target of rapamycin complex 1 (mTORC1); functional loss of merlin was shown to result ...

Journal: :Genes, chromosomes & cancer 2005
Lan Kluwe Anders O H Nygren Abdellatif Errami Bianca Heinrich Cordula Matthies Marcos Tatagiba Victor Mautner

Neurofibromatosis 2 (NF2) is a genetic disorder caused by mutational inactivation of the NF2 gene and is characterized by bilateral vestibular schwannomas, spinal tumors, and other benign tumors of the nervous system. Previously, we found intragenic NF2 mutations in 99 of 188 unrelated NF2 patients by exon-scanning-based methods. Tumor analysis of 22 de novo NF2 patients led to the identificati...

Journal: :Arquivos de neuro-psiquiatria 2015
Pollyanna Barros Batista Eny Maria Goloni Bertollo Danielle de Souza Costa Lucas Eliam Karin Soares Gonçalves Cunha José Renan Cunha-Melo Luiz Guilherme Darrigo Junior Mauro Geller Ingrid Faria Gianordoli-Nascimento Luciana Gonçalves Madeira Hérika Martins Mendes Débora Marques de Miranda Nikolas Andre Mata-Machado Eric Grossi Morato Érika Cristina Pavarino Luciana Baptista Pereira Nilton Alves de Rezende Luíza de Oliveira Rodrigues Jorge Bezerra Cavalcanti Sette

Part 1 of this guideline addressed the differential diagnosis of the neurofibromatoses (NF): neurofibromatosis type 1 (NF1), neurofibromatosis type 2 (NF2) and schwannomatosis (SCH). NF shares some features such as the genetic origin of the neural tumors and cutaneous manifestations, and affects nearly 80 thousand Brazilians. Increasing scientific knowledge on NF has allowed better clinical man...

2015
Reeta Dhar Shilpi Sahu Kuldeep singh

Schwannomas are benign,slowly growing, encapsulated peripheral nerve tumors. Schwannomas are homogenous tumors and consist of only Schwann cells. They develop outside of the nerve, but may push it aside or against adjacent structure causing damage to the nerve. Most schwannomas occur as solitary lesions. Presence of multiple schwannomas in a single patient suggeststumorogenesis and a possible a...

Journal: :Acta neurologica Scandinavica 2016
S Farschtschi V L Merker D Wolf M Schuhmann J Blakeley S R Plotkin C Hagel V F Mautner

BACKGROUND Neurofibromatosis type 2 (NF2) is a tumor suppressor syndrome associated with vestibular schwannomas, meningiomas, and spinal ependymomas. There have been anecdotal reports of radiographic response of spinal ependymomas in NF2 patients being treated for progressive vestibular schwannomas with bevacizumab, a monoclonal antibody against vascular endothelial growth factor (VEGF). AIMS...

Journal: :Journal of medical genetics 2005
M E Baser L Kuramoto R Woods H Joe J M Friedman A J Wallace R T Ramsden S Olschwang E Bijlsma M Kalamarides L Papi R Kato J Carroll C Lázaro F Joncourt D M Parry G A Rouleau D G R Evans

Neurofibromatosis 2 (NF2) patients with constitutional splice site NF2 mutations have greater variability in disease severity than NF2 patients with other types of mutations; the cause of this variability is unknown. We evaluated genotype-phenotype correlations, with particular focus on the location of splice site mutations, using mutation and clinical information on 831 patients from 528 NF2 f...

Journal: :American journal of medical genetics. Part A 2012
Jaishri O Blakeley D Gareth Evans John Adler Derald Brackmann Ruihong Chen Rosalie E Ferner C Oliver Hanemann Gordon Harris Susan M Huson Abraham Jacob Michel Kalamarides Matthias A Karajannis Bruce R Korf Victor-Felix Mautner Andrea I McClatchey Harry Miao Scott R Plotkin William Slattery Anat O Stemmer-Rachamimov D Bradley Welling Patrick Y Wen Brigitte Widemann Kim Hunter-Schaedle Marco Giovannini

Neurofibromatosis type 2 (NF2) is a tumor suppressor syndrome characterized by bilateral vestibular schwannomas (VS) which often result in deafness despite aggressive management. Meningiomas, ependymomas, and other cranial nerve and peripheral schwannomas are also commonly found in NF2 and collectively lead to major neurologic morbidity and mortality. Traditionally, the overall survival rate in...

Journal: :Human molecular genetics 1998
D H Gutmann R T Geist H m Xu J S Kim S Saporito-Irwin

Neurofibromatosis 2 (NF2) is an inherited cancer syndrome resulting from mutations in the NF2 tumor suppressor gene. Analysis of NF2 mutations has revealed some general genotype-phenotype correlations. Severe disease has been associated with mutations that produce a premature termination while more mild disease has been associated with missense mutations. Here, we provide experimental proof for...

Journal: :Archives of ophthalmology 2006
Martina M Bosch Werner W Wichmann Eugen Boltshauser Klara Landau

OBJECTIVE To determine the prevalence of optic nerve sheath meningiomas (ONSMs) in patients with neurofibromatosis type 2 (NF2). METHODS An observational retrospective case series of 30 consecutive patients with NF2 referred to an academic ophthalmology unit from November 1, 1991, through August 31, 2003. Twenty-six patients were followed up for a mean of 93 months (range, 3-150 months). One ...

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