نتایج جستجو برای: oculomotor apraxia

تعداد نتایج: 7081  

2013
Hee Jae Huh Kyoo-ho Cho Ji Eun Lee Min-Jung Kwon Chang-Seok Ki Phil Hyu Lee

Ataxia-telangiectasia (A-T) is a rare autosomal recessive neurodegenerative disorder. It is characterized by early-onset, progressive cerebellar ataxia, oculomotor apraxia, choreoathetosis, conjunctival telangiectasias, immunodeficiency, and an increased risk of malignancy. Although A-T is known to be the most common cause of progressive cerebellar ataxia in childhood, there have been no confir...

Journal: :Orphanet Journal of Rare Diseases 2006
Francesc Palau Carmen Espinós

Autosomal recessive cerebellar ataxias (ARCA) are a heterogeneous group of rare neurological disorders involving both central and peripheral nervous system, and in some case other systems and organs, and characterized by degeneration or abnormal development of cerebellum and spinal cord, autosomal recessive inheritance and, in most cases, early onset occurring before the age of 20 years. This g...

2011
Tyler Mark Pierson David Adams Florian Bonn Paola Martinelli Praveen F. Cherukuri Jamie K. Teer Nancy F. Hansen Pedro Cruz James C. Mullikin for the NISC Comparative Sequencing Program Robert W. Blakesley Gretchen Golas Justin Kwan Anthony Sandler Karin Fuentes Fajardo Thomas Markello Cynthia Tifft Craig Blackstone Elena I. Rugarli Thomas Langer William A. Gahl Camilo Toro

We report an early onset spastic ataxia-neuropathy syndrome in two brothers of a consanguineous family characterized clinically by lower extremity spasticity, peripheral neuropathy, ptosis, oculomotor apraxia, dystonia, cerebellar atrophy, and progressive myoclonic epilepsy. Whole-exome sequencing identified a homozygous missense mutation (c.1847G>A; p.Y616C) in AFG3L2, encoding a subunit of an...

2012
Peter Klivényi Dezso Nemeth Tamas Sefcsik Karolina Janacsek Ildiko Hoffmann Gabor Peter Haden Zsuzsa Londe Laszlo Vecsei

BACKGROUND Ataxia with oculomotor apraxia type 2 (AOA2) is characterized by cerebellar atrophy, peripheral neuropathy, oculomotor apraxia, and elevated serum alpha-fetoprotein (AFP) levels. The disease is caused by a recessive mutation in the senataxin gene. Since it is a very rare cerebellar disorder, no detailed examination of cognitive functions in AOA2 has been published to date. The aim of...

2013
Solène Frismand Hannoun Salem Muriel Panouilleres Denis Pélisson Stéphane Jacobs Alain Vighetto François Cotton Caroline Tilikete

Ataxia with Oculomotor Apraxia type 2 (AOA2) is one of the most frequent types of autosomal degenerative cerebellar ataxia. The first objective of this work was to identify specific cerebellar atrophy using MRI in patients with AOA2. Since increased iron deposits have been reported in degenerative diseases, our second objective was to report iron deposits signals in the dentate nuclei in AOA2. ...

Journal: :European journal of paediatric neurology : EJPN : official journal of the European Paediatric Neurology Society 2009
Christophe Orssaud Isabelle Ingster-Moati Olivier Roche Emmanuel Bui Quoc Jean Louis Dufier

The electro-oculographic (EOG) features of both horizontal and vertical eye movements in congenital oculomotor apraxia (COMA) were not previously reported. A girl referred to the ophthalmologic department for abnormal eye movements was diagnosed as COMA. The same abnormal ocular movements were observed in her younger sister and her father who was unaware of his difficulties to initiate voluntar...

2012
Hok Khim Fam Miraj K. Chowdhury Cornelius F. Boerkoel

Spinocerebellar ataxias (SCAs) are a group of progressive and irreversible neurological diseases affecting gait and movement coordination. Many result from cerebellar degeneration or the impairment of a portion of the neuroaxis that contributes to cerebellar inflow or outflow (Embirucu et al., 2009). In the cerebellum, the dysfunction and death of Purkinje cells, granule cells or interneurons c...

Journal: :Arquivos de neuro-psiquiatria 2010
Emília Katiane Embiruçu Leão Marcília Martyn Lima Otacílio de Oliveira Maia Juliana Parizotto Fernando Kok

Joubert syndrome (JS) is an autosomal recessive inherited disorder characterized by hypotonia, cerebellar vermis hypoplasia, ocular abnormalities (e.g, pigmentary retinopathy, oculomotor apraxia and nystagmus), renal cysts and hepatic fibrosis. Respiratory abnormalities, as apnea and hyperpnea, may be present, as well as mental retardation. At least seven JS loci have been determined and five g...

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