نتایج جستجو برای: pyridoxine depended seizures

تعداد نتایج: 88326  

2016
Banu Güzel Nur Gamze Çelmeli Esra Manguoğlu Erdoğan Soyucen İffet Bircan Ercan Mıhçı

Hypophosphatasia is a rare inherited disorder of bone and mineral metabolism caused by a number of loss-of-function mutations in the ALPL gene. It is characterized by defective bone and tooth mineralisation associated with low serum and bone alkaline phosphatase activity. The clinical presentation of this disease is extremely variable. For this reason, the diagnosis can be difficult and is ofte...

Journal: :Archives of disease in childhood 2005
H-S Wang M-F Kuo M-L Chou P-C Hung K-L Lin M-Y Hsieh M-Y Chang

AIM To study the difference between pyridoxine (PN) and its active form, pyridoxal phosphate, (PLP) in control of idiopathic intractable epilepsy in children. METHODS Among 574 children with active epilepsy, 94 (aged 8 months to 15 years) were diagnosed with idiopathic intractable epilepsy for more than six months. All received intravenous PLP 10 mg/kg, then 10 mg/kg/day in four divided doses...

Journal: :Pediatrics 2014
Shailly Jain-Ghai Navin Mishra Cecil Hahn Susan Blaser Saadet Mercimek-Mahmutoglu

Pyridoxine dependent epilepsy (PDE) is caused by mutations in the ALDH7A1 gene encoding α-aminoadipic semialdehyde dehydrogenase. The classic clinical presentation is neonatal seizures responsive only to pyridoxine therapy. White matter abnormalities, corpus callosum agenesis or hypoplasia, megacisterna magna, cortical dysplasia, neuronal heterotopias, intracerebral hemorrhage, and hydrocephalu...

2017
Lily Wong-Kisiel

A 2-day-old male neonate became increasingly irritable and developed repetitive twitching in the eyelids, face, and limbs around 24 h of life. He was the full-term product of nonconsanguineous parents following a normal pregnancy and uneventful spontaneous vaginal delivery. Investigations for infectious etiologies including blood and urine cultures as well as cerebrospinal fl uid analysis were ...

2016
Eleonora Parisi Antonio Nicotera Antonella Alagna Gabriella Di Rosa

Early identification of an underlying inborn error of metabolism in newborns with otherwise unexplained seizures may address appropriate disease-specific treatment and provide important tools about the choice of the antiepileptic drugs. Neonatal seizures usually present as prolonged or recurrent, often configuring epileptic status. Striking features of an underlying metabolic disorder include a...

Journal: :iranian journal of child neurology 0
ali akabar asadi-pooya 1.neurosciences research center, shiraz university of medical sciences, shiraz, iran 2.jefferson comprehensive epilepsy center, department of neurology, thomas jefferson university, philadelphia, usa mohaddese sharifzade neurosciences research center, shiraz university of medical sciences, shiraz, iran

how to cite this article: asadi-pooya aa, sharifzade m. west syndrome in south iran: electro-clinical manifestations. iran j child neurol. 2013 summer; 7(3): 40-44. objective we aimed to determine the clinical and electroencephalographic (eeg) characteristics of the patients with west syndrome (ws) in south iran. materials & methods in this retrospective study, all patients with a clinical diag...

2010
Philippa B. Mills Emma J. Footitt Kevin A. Mills Karin Tuschl Sarah Aylett Sophia Varadkar Cheryl Hemingway Neil Marlow Janet Rennie Peter Baxter Olivier Dulac Rima Nabbout William J. Craigen Bernhard Schmitt François Feillet Ernst Christensen Pascale De Lonlay Mike G. Pike M. Imelda Hughes Eduard A. Struys Cornelis Jakobs Sameer M. Zuberi Peter T. Clayton

Pyridoxine-dependent epilepsy was recently shown to be due to mutations in the ALDH7A1 gene, which encodes antiquitin, an enzyme that catalyses the nicotinamide adenine dinucleotide-dependent dehydrogenation of l-alpha-aminoadipic semialdehyde/L-Delta1-piperideine 6-carboxylate. However, whilst this is a highly treatable disorder, there is general uncertainty about when to consider this diagnos...

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