نتایج جستجو برای: pyridoxine dependent epilepsy

تعداد نتایج: 745226  

2006
Robert Surtees Philippa Mills Peter Clayton

Vitamin B 6 is an important vitamin for normal brain function. The metabolism of dietary vitamin B 6 to its active cofactor pyridoxal 5´-phosphate is described. The mechanism of action of pyridoxal 5´-phosphate is described, as are some important functions in the brain. The clinical features and biochemistry of three inborn errors of metabolism affecting brain pyridoxal 5´-phosphate concentrati...

Journal: :European Psychiatry 2023

Introduction Pyridoxine-dependent epilepsy (PDE) is a rare autosomal recessive disease usually associated with neonatal seizures that are sensitive to pyridoxine (vitamin B6). This can have significant impact on family functioning, psychological distress in parents. Post-traumatic stress disorder (PTSD), depression, and anxiety the most common psychiatric outcomes parents of children PDE. Objec...

Journal: :Molecular genetics and metabolism 2015
Curtis R Coughlin Clara D M van Karnebeek Walla Al-Hertani Andrew Y Shuen Sravan Jaggumantri Rhona M Jack Sommer Gaughan Casey Burns David M Mirsky Renata C Gallagher Johan L K Van Hove

Pyridoxine-dependent epilepsy (PDE) is an epileptic encephalopathy characterized by response to pharmacologic doses of pyridoxine. PDE is caused by deficiency of α-aminoadipic semialdehyde dehydrogenase resulting in impaired lysine degradation and subsequent accumulation of α-aminoadipic semialdehyde. Despite adequate seizure control with pyridoxine monotherapy, 75% of individuals with PDE have...

Journal: :Archives of disease in childhood 1983
J B Stephenson K E Byrne

Journal: :Developmental Medicine & Child Neurology 2007

Journal: :The Canadian journal of neurological sciences. Le journal canadien des sciences neurologiques 2012
Majid Alfadhel Sandra Sirrs Paula J Waters András Szeitz Eduard Struys Marion Coulter-Mackie Sylvia Stockler-Ipsiroglu

BACKGROUND Pyridoxine dependent epilepsy (PDE) is characterized by neonatal epileptic encepahalopathy responsive to pharmacological doses of vitamin B6. Recently an autosomal recessive deficiency in Antiquitin (ALDH7A1), a gene involved in the catabolism of lysine has been identified as the underlying cause. CASE REPORT In 21 and 23 year-old sisters, who had presented with neonatal / early in...

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