نتایج جستجو برای: spinal muscular atrophy sma

تعداد نتایج: 194162  

آیرملو, هرمز, امین بخش, محمد, برزگر, محمد, جبارپور بنیادی, مرتضی, خندقی, رضا, شیمیا, محمد, عمرانی, امید, نداف نیا, حسین,

Background: Spinal muscular atrophy includes a group of neuromuscular disorders characterized by degeneration of anterior horn cells in the spinal cord, and leads to progressive muscular weakness. NAIP is one of the genes that inhibits motor neuron apoptosis. Deletion of this gene is usually observed in type I SMI. The aim of this study was to investigate the frequency and pathogenicity of NAIP...

Journal: :The Journal of neuroscience : the official journal of the Society for Neuroscience 2016
Claudia Fallini Paul G Donlin-Asp Jeremy P Rouanet Gary J Bassell Wilfried Rossoll

UNLABELLED Spinal muscular atrophy (SMA) is a neurodegenerative disease primarily affecting spinal motor neurons. It is caused by reduced levels of the survival of motor neuron (SMN) protein, which plays an essential role in the biogenesis of spliceosomal small nuclear ribonucleoproteins in all tissues. The etiology of the specific defects in the motor circuitry in SMA is still unclear, but SMN...

Journal: :Arquivos De Neuro-psiquiatria 2023

Background: Spinal muscular atrophy (SMA) is a disorder caused by homozygous loss of function the SMN1 gene. This gene produces survival motor neuron (SMN) protein, which important in homeostasis. The SMN2 has homology with SMN1, but only expresses 10% functional full-length SMN protein. treatment available Brazilian public health system Nusinersen, an antisense oligonucleotide that increases p...

2014
Vaidehi Jobanputra Ali Naini

Neuromuscular disorders (NMDs) are a group of genetic disorders that affect the peripheral nervous system and muscle, consequently leading to a significant disability in children as well as in adults. NMDs include more than 200 monogenic disorders with a total incidence exceeding 1 in 3,000 [1]. Some of the more extreme diseases in the spectrum include amyotrophic lateral sclerosis (ALS), conge...

برزگر, محمد, جبارپور بنیادی, مرتضی, عمرانی, امید,

Background and Objectives: The neuromuscular degenerative disorder, known as spinal muscular atrophy (SMA), is a common fatal disease in neonates. In most patients with SMA, exon 7 and/or exon 8 of SMN1 gene is deleted. It is reported that the deletion of exon 5 from NAIP gene may be involved in the severity of SMA disease. The present study was aimed to evaluate the genotype- phenotype correla...

Journal: :Cell 1995
Suzie Lefebvre Lydie Bürglen Sophie Reboullet Olivier Clermont Philippe Burlet Louis Viollet Bernard Benichou Corinne Cruaud Philippe Millasseau Massimo Zeviani Denis Le Paslier Jean Frézal Daniel Cohen Jean Weissenbach Arnold Munnich Judith Melki

Spinal muscular atrophy (SMA) is a common fatal autosomal recessive disorder characterized by degeneration of lower motor neurons, leading to progressive paralysis with muscular atrophy. The gene for SMA has been mapped to chromosome 5q13, where large-scale deletions have been reported. We describe here the inverted duplication of a 500 kb element in normal chromosomes and narrow the critical r...

2017
Marc-Olivier Deguise Rashmi Kothary

Spinal muscular atrophy (SMA) is a neuromuscular disorder characterized by motor neuron degeneration, although defects in multiple cell types and tissues have also been implicated. Three independent laboratories recently identified immune organ defects in SMA. We therefore propose a novel pathogenic mechanism contributory to SMA, resulting in higher susceptibility to infection and exacerbated d...

Journal: :The Kobe journal of medical sciences 2002
Tomoko Akutsu Hisahide Nishio Kimiaki Sumino Yasuhiro Takeshima Syuichi Tsuneishi Hiroko Wada Satoshi Takada Masafumi Matsuo Hajime Nakamura

Spinal muscular atrophy (SMA) is one of the most common autosomal recessive disorders characterized by degeneration of anterior horn cells in the spinal cord, and leads to progressive muscular weakness and atrophy. At least three SMA-related genes have been identified: SMN1, NAIP and p44t. We analyzed these genes in 32 SMA patients and found that the SMN1 gene was deleted in 30 of 32 patients (...

Journal: :Human molecular genetics 2010
Mélissa Bowerman Ariane Beauvais Carrie L Anderson Rashmi Kothary

Spinal muscular atrophy (SMA) is an inherited disease resulting in the highest mortality of children under the age of two. SMA is caused by mutations or deletions in the survival motor neuron 1 (SMN1) gene, leading to aberrant neuromuscular junction (NMJ) development and the loss of spinal cord alpha-motor neurons. Here, we show that Smn depletion leads to increased activation of RhoA, a major ...

Journal: :Neurology 2007
M Oskoui G Levy C J Garland J M Gray J O'Hagen D C De Vivo P Kaufmann

BACKGROUND Noninvasive ventilation has become increasingly available to spinal muscular atrophy (SMA) patients since the early 1990 s. This is expected to have improved survival for SMA type 1 patients. OBJECTIVE To assess whether there has been a change in survival in patients with SMA type 1 between 1980 and 2006. METHODS We used deidentified, family-reported data from participants in the...

نمودار تعداد نتایج جستجو در هر سال

با کلیک روی نمودار نتایج را به سال انتشار فیلتر کنید