نتایج جستجو برای: deafness autosomal recessive 59

تعداد نتایج: 115286  

Journal: :American journal of human genetics 2014
Gabriela Petrof Arti Nanda Jake Howden Takuya Takeichi James R McMillan Sophia Aristodemou Linda Ozoemena Lu Liu Andrew P South Celine Pourreyron Dimitra Dafou Laura E Proudfoot Hejab Al-Ajmi Masashi Akiyama W H Irwin McLean Michael A Simpson Maddy Parsons John A McGrath

Grainyhead-like 2, encoded by GRHL2, is a member of a highly conserved family of transcription factors that play essential roles during epithelial development. Haploinsufficiency for GRHL2 has been implicated in autosomal-dominant deafness, but mutations have not yet been associated with any skin pathology. We investigated two unrelated Kuwaiti families in which a total of six individuals have ...

Journal: :BMC Medical Genomics 2021

Abstract Background Autosomal recessive non-syndromic hearing loss (ARNSHL) is genetically and phenotypically heterogeneous with over 110 genes causally implicated in syndromic loss. Here, we investigate the genetic etiology of deafness two GJB2 GJB6 negative patients presenting pre-lingual, progressive, severe Methods Targeted exome sequencing (TES) using Next Generation Illumina Sequencing wa...

Journal: :international journal of pediatrics 0
shruti saraswat department of paediatrics, hi tech medical college, utkal university, bhubaneswar, odisha, india. satish mohanty department of paediatrics, hi tech medical college, utkal university, bhubaneswar, odisha, india.

background robinow syndrome is a rare congenital disorder with phenotypically heterogeneous abnormalities. two modes of inheritances are known for this syndrome namely autosomal recessive and autosomal dominant. case report we describe here an eighteen-month-old child who had mesomelic short stature, abnormal facial features, clinodactyly, micropenis and vertebral changes which were further sup...

Journal: :basic and clinical neuroscience 0
sunil gothwal department of pediatrics, all india institute of medical science, new delhi, india. swati nayan sms mc

hallervorden-spatz syndrome is a disorder characterized by dystonia, parkinsonism, and iron accumulation in the brain. the disease is caused by mutations in gene encoding pantothenate kinase 2 (pank2) and patients have pantothenate kinase-associated neurodegeneration. we present an 8-year-old boy with progressive muscle dystonia, neuroregression, frequent fall and multiple injury marks of diffe...

Journal: :American journal of human genetics 1999
M J Kovach J P Lin S Boyadjiev K Campbell L Mazzeo K Herman L A Rimer W Frank B Llewellyn E W Jabs D Gelber V E Kimonis

Charcot-Marie-Tooth disease (CMT) with deafness is clinically distinct among the genetically heterogeneous group of CMT disorders. Molecular studies in a large family with autosomal dominant CMT and deafness have not been reported. The present molecular study involves a family with progressive features of CMT and deafness, originally reported by Kousseff et al. Genetic analysis of 70 individual...

2012
Samir Kumar PRAHARAJ Mahima ACHARYA Arul SARVANAN Sreejayan KONGASSERI Samir Kumar Praharaj

Usher syndrome (or Hallgren syndrome) is an autosomal recessive genetic disorder characterized by sensorineural deafness, retinitis pigmentosa, and variable vestibular deficit; Usher syndrome type II is the most common form. Various neuropsychiatric disorders have been reported to occur in those with Usher syndrome, including schizophrenia-like disorder, atypical psychosis, recurrent depressive...

Journal: :Journal of medical genetics 2003
S Naz F Alasti A Mowjoodi S Riazuddin M H Sanati T B Friedman A J Griffith E R Wilcox

Genetic factors are thought to account for approximately one half of cases of childhood hearing loss, the majority of which is non-syndromic and not associated with other abnormalities. Seventy-seven percent of hereditary, non-syndromic, prelingual deafness is autosomal recessive, 22% is autosomal dominant, and 1% is transmitted as a matrilineal or X linked trait. So far, more than 30 distinct ...

Journal: :Jornal de pediatria 2002
Marta W Vieira Vera L G S Lopes Hiromi Teruya Leonardo Guimarães-Lamonato Lucila C L Oliveira Clóvis Duarte Costa

OBJECTIVE To promote a clinical entity that could be part of differential diagnosis of most disorders that affect the pediatric age group. DESCRIPTION We describe a Brazilian girl affected by Johanson-Blizzard syndrome and review the literature. COMMENTS Johanson-Blizzard syndrome is an autosomal recessive condition characterized by hypoplastic alae nasi, scalp defect, deafness and pancreat...

Journal: :Indian journal of dermatology, venereology and leprology 2007
Maryam Akhyani Katrin Kiavash

The ectodermal dysplasias are a heterogeneous group of disorders with primary defect in hair, teeth, nail and sweat gland function. Numerous types have been described and several classifications exist. Here, we present a patient with ectodermal dysplasia with alopecia, dysplastic nails, hypohidrosis, sensorineural deafness, palmoplantar keratoderma, abnormal teeth and dry skin. To our knowledge...

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