نتایج جستجو برای: fabry disease

تعداد نتایج: 1493456  

2010
Omid Motabar Ellen Sidransky Ehud Goldin Wei Zheng

Fabry disease is a rare inherited lysosomal storage disorder caused by a partial or complete deficiency of α-galactosidase A (GLA), resulting in the storage of excess cellular glycosphingolipids. Enzyme replacement therapy is available for the treatment of Fabry disease, but it is a costly, intravenous treatment. Alternative therapeutic approaches, including small molecule chaperone therapy, ar...

2013
Martina Gaggl Renate Kain Peter Jaksch Dominik Haider Gerald Mundigler Till Voigtländer Raute Sunder-Plassmann Paulus Rommer Walter Klepetko Gere Sunder-Plassmann

Introduction. Fabry disease is a rare X-linked lysosomal storage disorder, characterized by an α-galactosidase A deficiency resulting in globotriaosylceramide storage within cells. Subsequently, various organ systems are involved, clinically the most important are kidneys, the heart, and the peripheral and central nervous systems. Although obstructive lung disease is a common pathological findi...

2013
Frank Weidemann Maria D Sanchez-Niño Juan Politei João-Paulo Oliveira Christoph Wanner David G Warnock Alberto Ortiz

Fabry disease is a rare X-linked hereditary disease caused by mutations in the AGAL gene encoding the lysosomal enzyme alpha-galactosidase A. Enzyme replacement therapy (ERT) is the current cornerstone of Fabry disease management. Involvement of kidney, heart and the central nervous system shortens life span, and fibrosis of these organs is a hallmark of the disease. Fibrosis was initially thou...

2011
Alessandro P Burlina Katherine B Sims Juan M Politei Gary J Bennett Ralf Baron Claudia Sommer Anette Torvin Møller Max J Hilz

BACKGROUND Fabry disease is an inherited metabolic disorder characterized by progressive lysosomal accumulation of lipids in a variety of cell types, including neural cells. Small, unmyelinated nerve fibers are particularly affected and small fiber peripheral neuropathy often clinically manifests at young age. Peripheral pain can be chronic and/or occur as provoked attacks of excruciating pain....

Journal: :Genetics in Medicine 2016

Journal: :Nihon Naika Gakkai Zasshi 2014

Journal: :Journal of the American Society of Nephrology 2014

Journal: :Archives of Neurology 2006

2017
Ju Huang Aneal Khan Bryan C. Au Dwayne L. Barber Lucía López-Vásquez Nicole L. Prokopishyn Michel Boutin Michael Rothe Jack W. Rip Mona Abaoui Murtaza S. Nagree Shaalee Dworski Axel Schambach Armand Keating Michael L. West John Klassen Patricia V. Turner Sandra Sirrs C. Anthony Rupar Christiane Auray-Blais Ronan Foley Jeffrey A. Medin

Fabry disease is a rare lysosomal storage disorder (LSD). We designed multiple recombinant lentivirus vectors (LVs) and tested their ability to engineer expression of human α-galactosidase A (α-gal A) in transduced Fabry patient CD34+ hematopoietic cells. We further investigated the safety and efficacy of a clinically directed vector, LV/AGA, in both ex vivo cell culture studies and animal mode...

2010
Willy Aasebø Erik H. Strøm Torstein Hovig Liv H. Undset Arvid Heiberg Trond Jenssen

Enzyme replacement therapy (ERT) has been introduced for Fabry disease and has been reported to clear some renal cell types of accumulated glycolipids and to reduce the accumulation in other cell types. We describe two patients without Fabry disease who were transplanted with kidney allografts from a male donor with Fabry disease. Biopsies were taken at transplantation and after 3 years in the ...

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