نتایج جستجو برای: mucopolysaccharidosis

تعداد نتایج: 2370  

2014
KERRY E. SIEH

_______________________________ 155 Introduction ______________________________ 155 Observations _______________________________ 155 Comparison with 1968 slippage __________________ 157 Similarities ______________________________ 157 Differences ________________________________ 157 Discussion ________________________________ 157 Acknowledgments -_________________________^_ 159 References cited ...

Journal: :AJNR. American journal of neuroradiology 2013
A Sen

Journal: :Clinical chemistry 1972
A Calatroni

A simple method is described for measurement of urinary glycosaminoglycans (GAG) in normal and pathological urine: a fixed fraction of the 24-h urine is passed over a small plug of ECTEOLA-modified cellulose and the GAG are eluted with a few milliliters of NaCI solution (3 mol/liter) and measured as hexuronic acid. Because results are compared for equal aliquots of complete 24-h urines, GAG are...

Journal: :Neurology 2016
Wladimir Bocca Vieira de Rezende Pinto Paulo Victor Sgobbi de Souza Gabriel Novaes de Rezende Batistella Acary Souza Bulle Oliveira

A 2-year-old boy presented with delayed motor skills and language since birth. Family history disclosed consanguineous parents. Examination showed global muscular hypotonia, optic atrophy, oculomotor apraxia, and normal head circumference. Brain MRI showed optic atrophy and macrocerebellum (figure). Laboratory tests revealed deficient activity of a-L-iduronidase in peripheral blood leukocytes a...

2010
Gauri Shankar Shah Tania Mahal Subodh Sharma

INTRODUCTION We present a very rare case of mucopolysaccharidosis with atypical presentation such as mild mental retardation, an acrocephalic head and no corneal clouding. The purpose of presenting this case is to highlight the distinctive manifestation of mucopolysaccharidosis type II (Hunter syndrome). CASE PRESENTATION A 10-year-old East Asian boy presented with abdominal distension of fiv...

Journal: :Journal of the Chinese Medical Association : JCMA 2009
Ying-Lun Chen Kuo-Hwa Wu

BACKGROUND Airway management for patients with craniofacial abnormalities poses many challenges. It potentially has a high rate of morbidity and even mortality. METHODS We reviewed our experience in administering anesthesia to patients with a diagnosis of mucopolysaccharidosis or Pierre Robin sequence in the past 10 years (July 1998 to October 2008). The anesthetic procedures, methods of airw...

2013
Carole A. Vogler Babette Gwynn

We have characterized a new mutant mouse that has virtually no /-glucuronidase activity. This biochemical defect causes a murine lysosomal storage disease that has many interesting similarities to human mucopolysaccharidosis type VII (MPS VII; Sly syndrome; fl-glucuronidase deficiency). Genetic analysis showed that the mutation is inherited as an autosomal recessive that maps to the fl-glucuron...

Journal: :The Journal of clinical investigation 1993
M Yoshida J Noguchi H Ikadai M Takahashi S Nagase

A rat colony with mucopolysaccharidosis VI was established and the clinical, pathological, and biochemical features were characterized. Affected rats had facial dysmorphia, dysostosis multiplex, and increased urinary excretion of glucosaminoglycans (GAGs). Ultrastructural studies revealed storage of GAGs throughout the reticuloendothelial cells, cartilage, and other connective tissues, but no d...

Journal: :Human mutation 2011
Francesca Bertola Mirella Filocamo Giorgio Casati Matthew Mort Camillo Rosano Anna Tylki-Szymanska Beyhan Tüysüz Orazio Gabrielli Serena Grossi Maurizio Scarpa Giancarlo Parenti Daniela Antuzzi Jaime Dalmau Maja Di Rocco Carlo Dionisi Vici Ilyas Okur Jordi Rosell Attilio Rovelli Francesca Furlan Miriam Rigoldi Andrea Biondi David N Cooper Rossella Parini

Mutational analysis of the IDUA gene was performed in a cohort of 102 European patients with mucopolysaccharidosis type I. A total of 54 distinct mutant IDUA alleles were identified, 34 of which were novel including 12 missense mutations, 2 nonsense mutations, 12 splicing mutations, 5 micro-deletions, 1 micro-duplication 1 translational initiation site mutation, and 1 'no-stop' change (p.X654Re...

Mucopolysaccharidosis type IIIC (MPSIIIC) is a rare subtype of mucopolysaccharidosis disorder family caused by mutations in heparan-alpha-glucosaminide N-acetyltransferase (HGSNAT) gene. MPSIIIC is subdivided into four subtypes which have overlapping features, and are indistinguishable at clinical level. In populations with high consanguineous marriage rate, homozygosity mapping can be a good c...

نمودار تعداد نتایج جستجو در هر سال

با کلیک روی نمودار نتایج را به سال انتشار فیلتر کنید