نتایج جستجو برای: nefl

تعداد نتایج: 100  

2011
Jonathan Baets Tine Deconinck Els De Vriendt Magdalena Zimoń Laetitia Yperzeele Kim Van Hoorenbeeck Kristien Peeters Ronen Spiegel Yesim Parman Berten Ceulemans Patrick Van Bogaert Adolf Pou-Serradell Günther Bernert Argirios Dinopoulos Michaela Auer-Grumbach Satu-Leena Sallinen Gian Maria Fabrizi Fernand Pauly Peter Van den Bergh Birdal Bilir Esra Battaloglu Ricardo E. Madrid Dagmara Kabzińska Andrzej Kochanski Haluk Topaloglu Geoffrey Miller Albena Jordanova Vincent Timmerman Peter De Jonghe

Early onset hereditary motor and sensory neuropathies are rare disorders encompassing congenital hypomyelinating neuropathy with disease onset in the direct post-natal period and Dejerine-Sottas neuropathy starting in infancy. The clinical spectrum, however, reaches beyond the boundaries of these two historically defined disease entities. De novo dominant mutations in PMP22, MPZ and EGR2 are kn...

2011
Hongyang Li Xiuqin Ao Juan Jia Qingzhong Wang Zhongzhi Zhang

PURPOSE Optineurin is a pathogenic gene associated with primary open angle glaucoma (POAG), in which the retinal ganglion cells (RGCs) are targeted. However, the functions of optineurin, particularly in RGCs, are currently not clear. We introduced optineurin siRNA into cultured retinal ganglion cell 5 (RGC-5) and PC12 cells to determine the cellular and molecular mechanisms underlying the role ...

Journal: :Journal of medical genetics 2004
E Nelis J Berciano N Verpoorten K Coen I Dierick V Van Gerwen O Combarros P De Jonghe V Timmerman

C harcot-Marie-Tooth (CMT) disease is a clinically and genetically heterogeneous group of disorders that involve the peripheral nervous system. It is characterised by progressive distal neurogenic muscular atrophy and weakness that initially affects the peroneal muscles and later the hands. Charcot-Marie-Tooth disease type 1 (CMT1), also called hereditary motor and sensory neuropathy type I (HM...

Journal: :Drug design, development and therapy 2016
Ramin Khanabdali Anbarieh Saadat Maizatul Fazilah Khairul Fidaa' Khairul Bazli Rida-e-Maria Qazi Ramla Sana Khalid Durriyyah Sharifah Hasan Adli Soheil Zorofchian Moghadamtousi Nadia Naeem Irfan Khan Asmat Salim ShamsulAzlin Ahmad Shamsuddin Gokula Mohan

Small molecules, growth factors, and cytokines have been used to induce differentiation of stem cells into different lineages. Similarly, demethylating agents can trigger differentiation in adult stem cells. Here, we investigated the in vitro differentiation of rat bone marrow mesenchymal stem cells (MSCs) into cardiomyocytes by a demethylating agent, zebularine, as well as neuronal-like cells ...

Journal: :Neurology 2015
Chiara Pisciotta Yunhong Bai Kathryn M Brennan Xingyao Wu Tiffany Grider Shawna Feely Suola Wang Steven Moore Carly Siskind Michael Gonzalez Stephan Zuchner Michael E Shy

OBJECTIVE To investigate the effects of NEFL Glu396Lys mutation on the expression and assembly of neurofilaments (NFs) in cutaneous nerve fibers of patients with Charcot-Marie-Tooth disease type 2E (CMT2E). METHODS A large family with CMT2E underwent clinical, electrophysiologic, and skin biopsy studies. Biopsies were processed by indirect immunofluorescence (IF), electron microscopy (EM), an...

Journal: :Molecular vision 2006
Chan Y Kim Markus H Kuehn Abbot F Clark Young H Kwon

PURPOSE Pathophysiological events in the retinal ganglion cell layer (GCL) are a prominent feature of several optic neuropathies including glaucoma. The purpose of this study was to identify and catalog genes whose expression in the human retina is restricted to the GCL. METHODS Laser capture microdissection (LCM) technology was used to isolate tissue from the perimacular retina of three huma...

2004
E Nelis J Berciano N Verpoorten K Coen I Dierick V Van Gerwen O Combarros P De Jonghe V Timmerman

C harcot-Marie-Tooth (CMT) disease is a clinically and genetically heterogeneous group of disorders that involve the peripheral nervous system. It is characterised by progressive distal neurogenic muscular atrophy and weakness that initially affects the peroneal muscles and later the hands. Charcot-Marie-Tooth disease type 1 (CMT1), also called hereditary motor and sensory neuropathy type I (HM...

Journal: :The Journal of clinical investigation 1996
D A Wu X Bu C H Warden D D Shen C Y Jeng W H Sheu M M Fuh T Katsuya V J Dzau G M Reaven A J Lusis J I Rotter Y D Chen

Resistance to insulin-mediated glucose disposal is a common finding in patients with non-insulin-dependent diabetes mellitus (NIDDM), as well as in nondiabetic individuals with hypertension. In an effort to identify the generic loci responsible for variations in blood pressure in individuals at increased risk of insulin resistance, we studied the distribution of blood pressure in 48 Taiwanese f...

Journal: :PloS one 2016
Radouil Tzekov Clint Dawson Megan Orlando Benoit Mouzon Jon Reed James Evans Gogce Crynen Michael Mullan Fiona Crawford

Repetitive mild traumatic brain injury (r-mTBI) results in neuropathological and biochemical consequences in the human visual system. Using a recently developed mouse model of r-mTBI, with control mice receiving repetitive anesthesia alone (r-sham) we assessed the effects on the retina and optic nerve using histology, immunohistochemistry, proteomic and lipidomic analyses at 3 weeks post injury...

Journal: :Cancer research 1996
S A Becker Y Z Zhou B L Slagle

The majority of hepatocellular carcinomas (HCCs) from hepatitis B virus (HBV)-endemic areas contain integrated viral sequences. To better understand the role of HBV DNA insertion in tumorigenesis, we examined the integration site of a HCC harboring a single insert. Cellular DNAs flanking the viral sequences were mapped to chromosomes 17 and 8, indicating a translocation had occurred at the site...

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