نتایج جستجو برای: adrenal hypoplasia

تعداد نتایج: 62877  

  Cartilage hair hypoplasia (CHH), is a rare cause of metaphyseal chondrodysplasia and short stature. Other features included hair abnormality, immunodeficiency, anemia, gastrointestinal disorders (Hirschsprung disease, celiac, …) and increased risk of cancer. The disease is an autosomal recessive disorder and previously has not been reported in Iran. We report a 9-year-old boy diagnosed as car...

Journal: :The Journal of clinical endocrinology and metabolism 1999
J C Achermann W X Gu T J Kotlar J J Meeks L P Sabacan S B Seminara R L Habiby P C Hindmarsh D P Bick R J Sherins W F Crowley L C Layman J L Jameson

Although delayed puberty is relatively common and often familial, its molecular and pathophysiologic basis is poorly understood. In contrast, the molecular mechanisms underlying some forms of hypogonadotropic hypogonadism (HH) are clearer, following the description of mutations in the genes KAL, GNRHR, and PROP1. Mutations in another gene, DAX1 (AHC), cause X-linked adrenal hypoplasia congenita...

Journal: :The Journal of clinical endocrinology and metabolism 2003
Gokhan Ozisik Giovanna Mantovani John C Achermann Luca Persani Anna Spada Jeffrey Weiss Paolo Beck-Peccoz J Larry Jameson

Mutations in DAX1 [dosage-sensitive sex reversal-adrenal hypoplasia congenita (AHC) critical region on the X chromosome gene 1; NR0B1] cause X-linked AHC, a disease characterized by primary adrenal failure in infancy or childhood and reproductive abnormalities later in life. Most of these patients have nonsense or frameshift mutations that cause premature truncation of the DAX1 protein, thereby...

Journal: :The Journal of clinical endocrinology and metabolism 2001
J C Achermann M Ito B L Silverman R L Habiby S Pang A Rosler J L Jameson

DAX-1 is an orphan nuclear receptor that plays a key role in the development and function of the adrenal gland and hypothalamic-pituitary gonadal axis. Mutations in the gene encoding DAX-1 result in X-linked adrenal hypoplasia congenita (AHC). Affected boys typically present with primary adrenal failure in infancy or childhood and hypogonadotropic hypogonadism at the time of puberty. The majori...

Journal: :The Journal of clinical endocrinology and metabolism 1999
A T Reutens J C Achermann M Ito W X Gu R L Habiby P A Donohoue S Pang P C Hindmarsh J L Jameson

Adrenal hypoplasia congenita (AHC) is an X-linked disorder caused by mutations in a gene referred to as DAX-1. AHC is characterized by adrenal insufficiency and failure to undergo puberty because of hypogonadotropic hypogonadism. The DAX-1 protein is structurally related to orphan nuclear receptors, although it lacks the characteristic zinc finger DNA-binding domain that is highly conserved in ...

Journal: :The Journal of clinical investigation 2000
A Tabarin J C Achermann D Recan V Bex X Bertagna S Christin-Maitre M Ito J L Jameson P Bouchard

Mutations in the DAX1 gene cause X-linked adrenal hypoplasia congenita (AHC) and hypogonadotropic hypogonadism (HHG). In affected boys, primary adrenal insufficiency occurs soon after birth or during early childhood; HHG is recognized at the expected time of puberty. In this report, we describe the novel phenotype of a man who presented with apparently isolated adrenal insufficiency at 28 years...

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