نتایج جستجو برای: inherited neurodevelopmental disease

تعداد نتایج: 1517926  

نجفی, مهری ,

Cystic Fibrosis (CF) is an inherited disease that affects multiple organ systems. It is the most common cause of severe progressive lung disease and exocrine panceratic insufficiency. In our investigation 67 patients had CF. Of these, 79% had panceratic insufficiency and 92% had lung disease under 2 years age. Also 67% of patients were < 2 percentile and 28% between 3-10 percentile weight for a...

Journal: :Mental retardation and developmental disabilities research reviews 2001
M Hornig W I Lipkin

Both genetic and environmental factors contribute to the pathogenesis of a wide variety of neurodevelopmental disorders, including autism, mental retardation, and schizophrenia. Some heritable disorders approach 100% penetrance; nonetheless, even in these disorders, subtle aspects of clinical disease expression may be influenced by the environment. In other disorders with genetic influences, ex...

2016
Jonatan Halvardson Jin J Zhao Ammar Zaghlool Christian Wentzel Patrik Georgii-Hemming Else Månsson Helena Ederth Sävmarker Göran Brandberg Cecilia Soussi Zander Ann-Charlotte Thuresson Lars Feuk

BACKGROUND De novo mutations are a frequent cause of disorders related to brain development. We report the results of screening patients diagnosed with both epilepsy and intellectual disability (ID) using exome sequencing to identify known and new causative de novo mutations relevant to these conditions. METHODS Exome sequencing was performed on 39 patient-parent trios to identify de novo mut...

2015
Marta Codina-Solà Benjamín Rodríguez-Santiago Aïda Homs Javier Santoyo Maria Rigau Gemma Aznar-Laín Miguel del Campo Blanca Gener Elisabeth Gabau María Pilar Botella Armand Gutiérrez-Arumí Guillermo Antiñolo Luis Alberto Pérez-Jurado Ivon Cuscó

BACKGROUND Autism spectrum disorders (ASD) are a group of neurodevelopmental disorders with high heritability. Recent findings support a highly heterogeneous and complex genetic etiology including rare de novo and inherited mutations or chromosomal rearrangements as well as double or multiple hits. METHODS We performed whole-exome sequencing (WES) and blood cell transcriptome by RNAseq in a s...

Journal: :Human molecular genetics 2013
Anath C Lionel Andrea K Vaags Daisuke Sato Matthew J Gazzellone Elyse B Mitchell Hong Yang Chen Gregory Costain Susan Walker Gerald Egger Bhooma Thiruvahindrapuram Daniele Merico Aparna Prasad Evdokia Anagnostou Eric Fombonne Lonnie Zwaigenbaum Wendy Roberts Peter Szatmari Bridget A Fernandez Lyudmila Georgieva Linda M Brzustowicz Katharina Roetzer Wolfgang Kaschnitz John B Vincent Christian Windpassinger Christian R Marshall Rosario R Trifiletti Salman Kirmani George Kirov Erwin Petek Jennelle C Hodge Anne S Bassett Stephen W Scherer

The GPHN gene codes for gephyrin, a key scaffolding protein in the neuronal postsynaptic membrane, responsible for the clustering and localization of glycine and GABA receptors at inhibitory synapses. Gephyrin has well-established functional links with several synaptic proteins that have been implicated in genetic risk for neurodevelopmental disorders such as autism spectrum disorder (ASD), sch...

Journal: :acta medica iranica 0
z moinfar f. davari tanha z. moinfar m. kaveh s. eftekhari s. eftekhari z. khalilpour

short rib polydactyly syndrome (srps) is a very rare congenital anomaly that is classified into four subtypes. it is an autosomal recessive inherited disease. we report a case of this syndrome without a previous family history of congenital defects.

2012
Amel Al-Murrani Fern Ashton Salim Aftimos Alice M. George Donald R. Love

The contactin-associated protein-like 2 (CNTNAP2) gene is highly expressed in the frontal lobe circuits in the developing human brain. Mutations in this gene have been associated with several neurodevelopmental disorders such as autism and specific language impairment. Here we describe a 450 kb deletion within the CNTNAP2 gene that is maternally inherited in two male siblings, but with a variab...

Journal: :Trends in neurosciences 2011
Angela M Mabb Matthew C Judson Mark J Zylka Benjamin D Philpot

Angelman syndrome (AS) is a severe genetic disorder caused by mutations or deletions of the maternally inherited UBE3A gene. UBE3A encodes an E3 ubiquitin ligase that is expressed biallelically in most tissues but is maternally expressed in almost all neurons. In this review, we describe recent advances in understanding the expression and function of UBE3A in the brain and the etiology of AS. W...

2012
Carol Potera

Study Examines Epigenetic Effects of Fungicide Exposure A mother’s environmental exposure can result in transgenerational effects that are inherited through successive generations, even in the absence of exposure of the offspring. A new proof-of-principle study reports that great-grandchildren of rats exposed to the common fungicide vinclozolin showed a more profound behavioral and neurodevelop...

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