نتایج جستجو برای: npc2

تعداد نتایج: 199  

Journal: :Proceedings of the National Academy of Sciences 2008

2014
Richard W. D. Welford Marco Garzotti Charles Marques Lourenço Eugen Mengel Thorsten Marquardt Janine Reunert Yasmina Amraoui Stefan A. Kolb Olivier Morand Peter Groenen

Niemann-Pick disease type C (NP-C) is a devastating, neurovisceral lysosomal storage disorder which is characterised by variable manifestation of visceral signs, progressive neuropsychiatric deterioration and premature death, caused by mutations in the NPC1 and NPC2 genes. Due to the complexity of diagnosis and the availability of an approved therapy in the EU, improved detection of NP-C may ha...

2017
Elena-Raluca Nicoli David Smith Lauren Morris Frances M Platt

Niemann-Pick disease type C (NPC) disease is a neurodegenerative lysosomal storage disease caused by mutations in the NPC1 or NPC2 genes. Liver disease is also a common feature of NPC that can present as cholestatic jaundice in the neonatal period. Liver enzymes can remain elevated above the normal range in some patients as they age. We recently reported suppression of the P450 detoxification s...

2016
Jian Li Suzanne R Pfeffer

LAMP1 and LAMP2 proteins are highly abundant, ubiquitous, mammalian proteins that line the lysosome limiting membrane, and protect it from lysosomal hydrolase action. LAMP2 deficiency causes Danon's disease, an X-linked hypertrophic cardiomyopathy. LAMP2 is needed for chaperone-mediated autophagy, and its expression improves tissue function in models of aging. We show here that human LAMP1 and ...

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